Active Cryptococcus neoformans glucuronoxylomannan production prevents elimination of cryptococcal CNS infection in vivo

Abstract Background Cryptococcus neoformans (Cn) causes life-threatening meningoencephalitis in individuals with AIDS. Cn’s polysaccharide capsule is mainly composed of glucuronoxylomannan (GXM) and plays a key role in the dysregulation of immunity, resistance to antifungal drugs, and systemic disse...

Full description

Saved in:
Bibliographic Details
Main Authors: Vanessa Enriquez, Melissa E. Munzen, Luz M. Porras, Claudia L. Charles-Niño, Fahong Yu, Karina Alviña, Raddy L. Ramos, Michael R. Dores, Paola Giusti-Rodriguez, Luis R. Martinez
Format: Article
Language:English
Published: BMC 2025-03-01
Series:Journal of Neuroinflammation
Subjects:
Online Access:https://doi.org/10.1186/s12974-025-03384-9
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1850252092593143808
author Vanessa Enriquez
Melissa E. Munzen
Luz M. Porras
Claudia L. Charles-Niño
Fahong Yu
Karina Alviña
Raddy L. Ramos
Michael R. Dores
Paola Giusti-Rodriguez
Luis R. Martinez
author_facet Vanessa Enriquez
Melissa E. Munzen
Luz M. Porras
Claudia L. Charles-Niño
Fahong Yu
Karina Alviña
Raddy L. Ramos
Michael R. Dores
Paola Giusti-Rodriguez
Luis R. Martinez
author_sort Vanessa Enriquez
collection DOAJ
description Abstract Background Cryptococcus neoformans (Cn) causes life-threatening meningoencephalitis in individuals with AIDS. Cn’s polysaccharide capsule is mainly composed of glucuronoxylomannan (GXM) and plays a key role in the dysregulation of immunity, resistance to antifungal drugs, and systemic dissemination, including CNS invasion. Although recent studies have begun to elucidate the involvement of microglia in cryptococcosis, our knowledge of these CNS resident phagocytes in the control of cryptococcosis is limited. Methods We investigated microglial responses to Cn infection and the effect of active capsular production by comparing wild-type H99 and acapsular mutant cap59 strains using the CX3CR1-EGFP transgenic mouse and a stereotaxic intracerebral infection model. Results Microglia had difficulty combating Cn H99 infection. Active production and secretion of the capsular material altered the morphology and distribution of microglia around cryptococcomas or fungal brain lesions. It also affected the infiltration of peripheral immune cells to CNS fungal infection. Moreover, RNA sequencing analyses supported the importance of capsule production in immune modulation. Chemotaxis assays demonstrated that active capsular production by Cn H99, and especially GXM, impaired microglial motility and fungal phagocytosis. Conclusion Our findings suggest that microglia may not be able to control cryptococcal CNS infection and that active capsular production and release may contribute to the progression and persistence of cerebral cryptococcosis.
format Article
id doaj-art-c7a3864da8d7473fb63afbc7adae950e
institution OA Journals
issn 1742-2094
language English
publishDate 2025-03-01
publisher BMC
record_format Article
series Journal of Neuroinflammation
spelling doaj-art-c7a3864da8d7473fb63afbc7adae950e2025-08-20T01:57:44ZengBMCJournal of Neuroinflammation1742-20942025-03-0122112210.1186/s12974-025-03384-9Active Cryptococcus neoformans glucuronoxylomannan production prevents elimination of cryptococcal CNS infection in vivoVanessa Enriquez0Melissa E. Munzen1Luz M. Porras2Claudia L. Charles-Niño3Fahong Yu4Karina Alviña5Raddy L. Ramos6Michael R. Dores7Paola Giusti-Rodriguez8Luis R. Martinez9Department of Oral Biology, University of Florida College of DentistryDepartment of Oral Biology, University of Florida College of DentistryDepartment of Psychiatry, University of Florida College of MedicineDepartment of Oral Biology, University of Florida College of DentistryInterdisciplinary Center for Biotechnology Research, University of FloridaDepartment of Neuroscience, University of Florida College of MedicineDepartment of Biomedical Sciences, NYIT College of Osteopathic Medicine, New York Institute of TechnologyDepartment of Biology, Hofstra UniversityDepartment of Psychiatry, University of Florida College of MedicineDepartment of Oral Biology, University of Florida College of DentistryAbstract Background Cryptococcus neoformans (Cn) causes life-threatening meningoencephalitis in individuals with AIDS. Cn’s polysaccharide capsule is mainly composed of glucuronoxylomannan (GXM) and plays a key role in the dysregulation of immunity, resistance to antifungal drugs, and systemic dissemination, including CNS invasion. Although recent studies have begun to elucidate the involvement of microglia in cryptococcosis, our knowledge of these CNS resident phagocytes in the control of cryptococcosis is limited. Methods We investigated microglial responses to Cn infection and the effect of active capsular production by comparing wild-type H99 and acapsular mutant cap59 strains using the CX3CR1-EGFP transgenic mouse and a stereotaxic intracerebral infection model. Results Microglia had difficulty combating Cn H99 infection. Active production and secretion of the capsular material altered the morphology and distribution of microglia around cryptococcomas or fungal brain lesions. It also affected the infiltration of peripheral immune cells to CNS fungal infection. Moreover, RNA sequencing analyses supported the importance of capsule production in immune modulation. Chemotaxis assays demonstrated that active capsular production by Cn H99, and especially GXM, impaired microglial motility and fungal phagocytosis. Conclusion Our findings suggest that microglia may not be able to control cryptococcal CNS infection and that active capsular production and release may contribute to the progression and persistence of cerebral cryptococcosis.https://doi.org/10.1186/s12974-025-03384-9C. neoformansCryptococcomaMeningoencephalitisMicrogliaPhagocytosis
spellingShingle Vanessa Enriquez
Melissa E. Munzen
Luz M. Porras
Claudia L. Charles-Niño
Fahong Yu
Karina Alviña
Raddy L. Ramos
Michael R. Dores
Paola Giusti-Rodriguez
Luis R. Martinez
Active Cryptococcus neoformans glucuronoxylomannan production prevents elimination of cryptococcal CNS infection in vivo
Journal of Neuroinflammation
C. neoformans
Cryptococcoma
Meningoencephalitis
Microglia
Phagocytosis
title Active Cryptococcus neoformans glucuronoxylomannan production prevents elimination of cryptococcal CNS infection in vivo
title_full Active Cryptococcus neoformans glucuronoxylomannan production prevents elimination of cryptococcal CNS infection in vivo
title_fullStr Active Cryptococcus neoformans glucuronoxylomannan production prevents elimination of cryptococcal CNS infection in vivo
title_full_unstemmed Active Cryptococcus neoformans glucuronoxylomannan production prevents elimination of cryptococcal CNS infection in vivo
title_short Active Cryptococcus neoformans glucuronoxylomannan production prevents elimination of cryptococcal CNS infection in vivo
title_sort active cryptococcus neoformans glucuronoxylomannan production prevents elimination of cryptococcal cns infection in vivo
topic C. neoformans
Cryptococcoma
Meningoencephalitis
Microglia
Phagocytosis
url https://doi.org/10.1186/s12974-025-03384-9
work_keys_str_mv AT vanessaenriquez activecryptococcusneoformansglucuronoxylomannanproductionpreventseliminationofcryptococcalcnsinfectioninvivo
AT melissaemunzen activecryptococcusneoformansglucuronoxylomannanproductionpreventseliminationofcryptococcalcnsinfectioninvivo
AT luzmporras activecryptococcusneoformansglucuronoxylomannanproductionpreventseliminationofcryptococcalcnsinfectioninvivo
AT claudialcharlesnino activecryptococcusneoformansglucuronoxylomannanproductionpreventseliminationofcryptococcalcnsinfectioninvivo
AT fahongyu activecryptococcusneoformansglucuronoxylomannanproductionpreventseliminationofcryptococcalcnsinfectioninvivo
AT karinaalvina activecryptococcusneoformansglucuronoxylomannanproductionpreventseliminationofcryptococcalcnsinfectioninvivo
AT raddylramos activecryptococcusneoformansglucuronoxylomannanproductionpreventseliminationofcryptococcalcnsinfectioninvivo
AT michaelrdores activecryptococcusneoformansglucuronoxylomannanproductionpreventseliminationofcryptococcalcnsinfectioninvivo
AT paolagiustirodriguez activecryptococcusneoformansglucuronoxylomannanproductionpreventseliminationofcryptococcalcnsinfectioninvivo
AT luisrmartinez activecryptococcusneoformansglucuronoxylomannanproductionpreventseliminationofcryptococcalcnsinfectioninvivo