Mitochondrial DNA depletion syndrome and its cardiac complication

Mitochondrial depletion syndrome (MTDPS) is a heterogeneous group of genetic disorders characterized by a significant reduction in mitochondrial DNA (mtDNA) copy number, leading to the impaired mitochondrial function. The pathogenesis of MTDPS includes impaired mtDNA replication, damaged nucleotide...

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Main Authors: Shengfang Bao, Jiajun Ye, Jiaqi Zhou, Chen Zheng, Yuejuan Xu, Sun Chen
Format: Article
Language:English
Published: Frontiers Media S.A. 2025-06-01
Series:Frontiers in Cardiovascular Medicine
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Online Access:https://www.frontiersin.org/articles/10.3389/fcvm.2025.1582219/full
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author Shengfang Bao
Shengfang Bao
Jiajun Ye
Jiaqi Zhou
Chen Zheng
Yuejuan Xu
Sun Chen
author_facet Shengfang Bao
Shengfang Bao
Jiajun Ye
Jiaqi Zhou
Chen Zheng
Yuejuan Xu
Sun Chen
author_sort Shengfang Bao
collection DOAJ
description Mitochondrial depletion syndrome (MTDPS) is a heterogeneous group of genetic disorders characterized by a significant reduction in mitochondrial DNA (mtDNA) copy number, leading to the impaired mitochondrial function. The pathogenesis of MTDPS includes impaired mtDNA replication, damaged nucleotide metabolism and dysregulated mitochondrial dynamics. Due to its high energy demands, the heart is sensitive to the mitochondrial dysfunction. And the energy deficiency caused by the MTDPS contributes to the development of the mitochondrial cardiomyopathy. In this review, we summarize the cardiac phenotypes in the MTDPS, and the role of the mitochondrial injury in the myocardial damage. In specific, the association of the MTDPS-causing genes and their cardiac phenotypes are detailed. Moreover, the current treatment strategies for MTDPS are summarized. This review aims to integrate the current knowledge on the MTDPS and its cardiac phenotypes in order to provide insights for the further research and the clinic management.
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publisher Frontiers Media S.A.
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series Frontiers in Cardiovascular Medicine
spelling doaj-art-928c734265c34db18437d565016eeb4f2025-08-20T03:10:20ZengFrontiers Media S.A.Frontiers in Cardiovascular Medicine2297-055X2025-06-011210.3389/fcvm.2025.15822191582219Mitochondrial DNA depletion syndrome and its cardiac complicationShengfang Bao0Shengfang Bao1Jiajun Ye2Jiaqi Zhou3Chen Zheng4Yuejuan Xu5Sun Chen6Department of Pediatric Cardiology, Xinhua Hospital, School of Medicine, Shanghai Jiao Tong University, Shanghai, ChinaDepartment of Rheumatology and Immunology, Shanghai Children’s Medical Center, School of Medicine, Shanghai Jiao Tong University, Shanghai, ChinaDepartment of Pediatric Cardiology, Xinhua Hospital, School of Medicine, Shanghai Jiao Tong University, Shanghai, ChinaDepartment of Pediatric Cardiology, Xinhua Hospital, School of Medicine, Shanghai Jiao Tong University, Shanghai, ChinaDepartment of Pediatric Cardiology, Xinhua Hospital, School of Medicine, Shanghai Jiao Tong University, Shanghai, ChinaDepartment of Pediatric Cardiology, Xinhua Hospital, School of Medicine, Shanghai Jiao Tong University, Shanghai, ChinaDepartment of Pediatric Cardiology, Xinhua Hospital, School of Medicine, Shanghai Jiao Tong University, Shanghai, ChinaMitochondrial depletion syndrome (MTDPS) is a heterogeneous group of genetic disorders characterized by a significant reduction in mitochondrial DNA (mtDNA) copy number, leading to the impaired mitochondrial function. The pathogenesis of MTDPS includes impaired mtDNA replication, damaged nucleotide metabolism and dysregulated mitochondrial dynamics. Due to its high energy demands, the heart is sensitive to the mitochondrial dysfunction. And the energy deficiency caused by the MTDPS contributes to the development of the mitochondrial cardiomyopathy. In this review, we summarize the cardiac phenotypes in the MTDPS, and the role of the mitochondrial injury in the myocardial damage. In specific, the association of the MTDPS-causing genes and their cardiac phenotypes are detailed. Moreover, the current treatment strategies for MTDPS are summarized. This review aims to integrate the current knowledge on the MTDPS and its cardiac phenotypes in order to provide insights for the further research and the clinic management.https://www.frontiersin.org/articles/10.3389/fcvm.2025.1582219/fullmitochondrial DNA depletion syndromecardiomyopathymtDNA replicationnucleotide metabolismmitochondrial dynamicsmitochondrial damage
spellingShingle Shengfang Bao
Shengfang Bao
Jiajun Ye
Jiaqi Zhou
Chen Zheng
Yuejuan Xu
Sun Chen
Mitochondrial DNA depletion syndrome and its cardiac complication
Frontiers in Cardiovascular Medicine
mitochondrial DNA depletion syndrome
cardiomyopathy
mtDNA replication
nucleotide metabolism
mitochondrial dynamics
mitochondrial damage
title Mitochondrial DNA depletion syndrome and its cardiac complication
title_full Mitochondrial DNA depletion syndrome and its cardiac complication
title_fullStr Mitochondrial DNA depletion syndrome and its cardiac complication
title_full_unstemmed Mitochondrial DNA depletion syndrome and its cardiac complication
title_short Mitochondrial DNA depletion syndrome and its cardiac complication
title_sort mitochondrial dna depletion syndrome and its cardiac complication
topic mitochondrial DNA depletion syndrome
cardiomyopathy
mtDNA replication
nucleotide metabolism
mitochondrial dynamics
mitochondrial damage
url https://www.frontiersin.org/articles/10.3389/fcvm.2025.1582219/full
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AT jiaqizhou mitochondrialdnadepletionsyndromeanditscardiaccomplication
AT chenzheng mitochondrialdnadepletionsyndromeanditscardiaccomplication
AT yuejuanxu mitochondrialdnadepletionsyndromeanditscardiaccomplication
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