Targeting PTBP3‐Mediated Alternative Splicing of COX11 Induces Cuproptosis for Inhibiting Gastric Cancer Peritoneal Metastasis

Abstract Numerous aberrant splicing events are implicated in tumor progression, yet comprehensive reports on splicing factors and events associated with peritoneal metastasis in gastric cancer (GCPM) are lacking. In this study, PTBP3 is found to be significantly overexpressed in peritoneal metastati...

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Main Authors: Yajing Zhou, Chao Dong, Xiaochun Shen, Pengbo Wang, Tao Chen, Weikang Li, Xiaotong Sun, Peiyuan Li, Chengxiang Xu, Kaipeng Duan, Dongbao Li, Jin Zhou
Format: Article
Language:English
Published: Wiley 2025-06-01
Series:Advanced Science
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Online Access:https://doi.org/10.1002/advs.202415983
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author Yajing Zhou
Chao Dong
Xiaochun Shen
Pengbo Wang
Tao Chen
Weikang Li
Xiaotong Sun
Peiyuan Li
Chengxiang Xu
Kaipeng Duan
Dongbao Li
Jin Zhou
author_facet Yajing Zhou
Chao Dong
Xiaochun Shen
Pengbo Wang
Tao Chen
Weikang Li
Xiaotong Sun
Peiyuan Li
Chengxiang Xu
Kaipeng Duan
Dongbao Li
Jin Zhou
author_sort Yajing Zhou
collection DOAJ
description Abstract Numerous aberrant splicing events are implicated in tumor progression, yet comprehensive reports on splicing factors and events associated with peritoneal metastasis in gastric cancer (GCPM) are lacking. In this study, PTBP3 is found to be significantly overexpressed in peritoneal metastatic tissues of gastric cancer compared to primary tumor tissues, and higher PTBP3 expression correlates with poorer prognosis. Using gastric cancer cells and patient‐derived organoids (PDO), the role of PTBP3 in promoting tumor invasion and proliferation is investigated. Mechanistically, through full‐length transcriptome sequencing, PTBP3 mediates exon 4 skipping in its target gene COX11, leading to shorter transcripts that impair COX11 protein function, reducing mitochondrial copper content and enabling tumor cells to evade cuproptosis. Antisense oligonucleotide (ASO) drugs targeting the short COX11 transcripts effectively degrade mRNA, disrupting copper homeostasis. In PDO‐based xenograft models, exogenous copper ionophores combined with ASO drugs induce excessive copper accumulation in mitochondria, triggering proteotoxic stress and cuproptosis. Overall, PTBP3‐mediated exon 4 skipping in COX11 pre‐mRNA is critical for tumor cell survival and progression in GCPM, offering potential therapeutic strategies targeting copper metabolism.
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spelling doaj-art-2394a7d421af4d7dab58ff147bd2039c2025-08-20T02:02:58ZengWileyAdvanced Science2198-38442025-06-011221n/an/a10.1002/advs.202415983Targeting PTBP3‐Mediated Alternative Splicing of COX11 Induces Cuproptosis for Inhibiting Gastric Cancer Peritoneal MetastasisYajing Zhou0Chao Dong1Xiaochun Shen2Pengbo Wang3Tao Chen4Weikang Li5Xiaotong Sun6Peiyuan Li7Chengxiang Xu8Kaipeng Duan9Dongbao Li10Jin Zhou11Department of General SurgeryThe First Affiliated Hospital of Soochow University899 Pinghai Road Suzhou Jiangsu Province 215031 ChinaDepartment of General SurgeryThe First Affiliated Hospital of Soochow University899 Pinghai Road Suzhou Jiangsu Province 215031 ChinaDepartment of Pulmonary and Critical Care MedicineThe First Affiliated Hospital of Soochow University899 Pinghai Road Suzhou Jiangsu Province 215031 ChinaDepartment of General SurgeryThe First Affiliated Hospital of Soochow University899 Pinghai Road Suzhou Jiangsu Province 215031 ChinaDepartment of General SurgeryThe First Affiliated Hospital of Soochow University899 Pinghai Road Suzhou Jiangsu Province 215031 ChinaDepartment of General SurgeryThe First Affiliated Hospital of Soochow University899 Pinghai Road Suzhou Jiangsu Province 215031 ChinaDepartment of General SurgeryThe First Affiliated Hospital of Soochow University899 Pinghai Road Suzhou Jiangsu Province 215031 ChinaDepartment of General SurgeryThe First Affiliated Hospital of Soochow University899 Pinghai Road Suzhou Jiangsu Province 215031 ChinaDepartment of General SurgeryThe First Affiliated Hospital of Soochow University899 Pinghai Road Suzhou Jiangsu Province 215031 ChinaDepartment of General SurgeryThe First Affiliated Hospital of Soochow University899 Pinghai Road Suzhou Jiangsu Province 215031 ChinaDepartment of General SurgeryThe First Affiliated Hospital of Soochow University899 Pinghai Road Suzhou Jiangsu Province 215031 ChinaDepartment of General SurgeryThe First Affiliated Hospital of Soochow University899 Pinghai Road Suzhou Jiangsu Province 215031 ChinaAbstract Numerous aberrant splicing events are implicated in tumor progression, yet comprehensive reports on splicing factors and events associated with peritoneal metastasis in gastric cancer (GCPM) are lacking. In this study, PTBP3 is found to be significantly overexpressed in peritoneal metastatic tissues of gastric cancer compared to primary tumor tissues, and higher PTBP3 expression correlates with poorer prognosis. Using gastric cancer cells and patient‐derived organoids (PDO), the role of PTBP3 in promoting tumor invasion and proliferation is investigated. Mechanistically, through full‐length transcriptome sequencing, PTBP3 mediates exon 4 skipping in its target gene COX11, leading to shorter transcripts that impair COX11 protein function, reducing mitochondrial copper content and enabling tumor cells to evade cuproptosis. Antisense oligonucleotide (ASO) drugs targeting the short COX11 transcripts effectively degrade mRNA, disrupting copper homeostasis. In PDO‐based xenograft models, exogenous copper ionophores combined with ASO drugs induce excessive copper accumulation in mitochondria, triggering proteotoxic stress and cuproptosis. Overall, PTBP3‐mediated exon 4 skipping in COX11 pre‐mRNA is critical for tumor cell survival and progression in GCPM, offering potential therapeutic strategies targeting copper metabolism.https://doi.org/10.1002/advs.202415983alternative splicingantisense oligonucleotide drugscuproptosisgastric cancer peritoneal metastasispatient‐derived organoids‐based xenograft
spellingShingle Yajing Zhou
Chao Dong
Xiaochun Shen
Pengbo Wang
Tao Chen
Weikang Li
Xiaotong Sun
Peiyuan Li
Chengxiang Xu
Kaipeng Duan
Dongbao Li
Jin Zhou
Targeting PTBP3‐Mediated Alternative Splicing of COX11 Induces Cuproptosis for Inhibiting Gastric Cancer Peritoneal Metastasis
Advanced Science
alternative splicing
antisense oligonucleotide drugs
cuproptosis
gastric cancer peritoneal metastasis
patient‐derived organoids‐based xenograft
title Targeting PTBP3‐Mediated Alternative Splicing of COX11 Induces Cuproptosis for Inhibiting Gastric Cancer Peritoneal Metastasis
title_full Targeting PTBP3‐Mediated Alternative Splicing of COX11 Induces Cuproptosis for Inhibiting Gastric Cancer Peritoneal Metastasis
title_fullStr Targeting PTBP3‐Mediated Alternative Splicing of COX11 Induces Cuproptosis for Inhibiting Gastric Cancer Peritoneal Metastasis
title_full_unstemmed Targeting PTBP3‐Mediated Alternative Splicing of COX11 Induces Cuproptosis for Inhibiting Gastric Cancer Peritoneal Metastasis
title_short Targeting PTBP3‐Mediated Alternative Splicing of COX11 Induces Cuproptosis for Inhibiting Gastric Cancer Peritoneal Metastasis
title_sort targeting ptbp3 mediated alternative splicing of cox11 induces cuproptosis for inhibiting gastric cancer peritoneal metastasis
topic alternative splicing
antisense oligonucleotide drugs
cuproptosis
gastric cancer peritoneal metastasis
patient‐derived organoids‐based xenograft
url https://doi.org/10.1002/advs.202415983
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