Castleman disease of stomach treated by endoscopic submucosal dissection: a case report and literature review

BackgroundCastleman disease (CD) is a relatively rare benign lymphoproliferative disorder of the lymphoid tissue. According to clinical manifestations, it is classified into two types: unicentric CD (UCD) and multicentric CD (MCD). Pathological subtypes include hyaline-vascular (HV), plasma cell (PC...

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Main Authors: Ting-Ting Sun, Xue-Guo Sun, Ti-Dong Shan, Peng Zhao, Yan-Yan Lu, Qian Li, Fu-Guo Liu
Format: Article
Language:English
Published: Frontiers Media S.A. 2025-04-01
Series:Frontiers in Oncology
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Online Access:https://www.frontiersin.org/articles/10.3389/fonc.2025.1563545/full
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author Ting-Ting Sun
Ting-Ting Sun
Xue-Guo Sun
Ti-Dong Shan
Peng Zhao
Yan-Yan Lu
Qian Li
Fu-Guo Liu
author_facet Ting-Ting Sun
Ting-Ting Sun
Xue-Guo Sun
Ti-Dong Shan
Peng Zhao
Yan-Yan Lu
Qian Li
Fu-Guo Liu
author_sort Ting-Ting Sun
collection DOAJ
description BackgroundCastleman disease (CD) is a relatively rare benign lymphoproliferative disorder of the lymphoid tissue. According to clinical manifestations, it is classified into two types: unicentric CD (UCD) and multicentric CD (MCD). Pathological subtypes include hyaline-vascular (HV), plasma cell (PC), and mixed (MV). Gastrointestinal CD is extremely rare, and limited information is available regarding its clinical presentation and management.Case SummaryWe report a case of a patient who presented with paroxysmal epigastric pain for 4 years. Laboratory tests showed no remarkable abnormalities, whereas CT revealed endogenous occupancy on the side of the greater curvature of the stomach. Ultrasonographic endoscopy demonstrated hypoechoic, well-defined foci. The lesion initially suspected to be an inflammatory fibroma was subsequently pathologically confirmed as HV-UCD following endoscopic submucosal dissection. The lesion was completely resected, and the patient showed no signs of recurrence during 7 months of follow-up.ConclusionGastrointestinal CD is rare and should be differentiated from other occupying lesions. Its definitive diagnosis relies on histopathology.
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language English
publishDate 2025-04-01
publisher Frontiers Media S.A.
record_format Article
series Frontiers in Oncology
spelling doaj-art-ffab38475dad457da3aa90c1d894184e2025-08-20T01:51:55ZengFrontiers Media S.A.Frontiers in Oncology2234-943X2025-04-011510.3389/fonc.2025.15635451563545Castleman disease of stomach treated by endoscopic submucosal dissection: a case report and literature reviewTing-Ting Sun0Ting-Ting Sun1Xue-Guo Sun2Ti-Dong Shan3Peng Zhao4Yan-Yan Lu5Qian Li6Fu-Guo Liu7Department of Gastroenterology, The Affiliated Hospital of Qingdao University, Qingdao, Shandong, ChinaGastroenterology, Qingdao Medical College of Qingdao University, Qingdao, Shandong, ChinaDepartment of Gastroenterology, The Affiliated Hospital of Qingdao University, Qingdao, Shandong, ChinaDepartment of Gastroenterology, The Affiliated Hospital of Qingdao University, Qingdao, Shandong, ChinaDepartment of Pathology, The Affiliated Hospital of Qingdao University, Qingdao, Shandong, ChinaDepartment of Gastroenterology, The Affiliated Hospital of Qingdao University, Qingdao, Shandong, ChinaDepartment of Gastroenterology, The Affiliated Hospital of Qingdao University, Qingdao, Shandong, ChinaDepartment of Gastroenterology, The Affiliated Hospital of Qingdao University, Qingdao, Shandong, ChinaBackgroundCastleman disease (CD) is a relatively rare benign lymphoproliferative disorder of the lymphoid tissue. According to clinical manifestations, it is classified into two types: unicentric CD (UCD) and multicentric CD (MCD). Pathological subtypes include hyaline-vascular (HV), plasma cell (PC), and mixed (MV). Gastrointestinal CD is extremely rare, and limited information is available regarding its clinical presentation and management.Case SummaryWe report a case of a patient who presented with paroxysmal epigastric pain for 4 years. Laboratory tests showed no remarkable abnormalities, whereas CT revealed endogenous occupancy on the side of the greater curvature of the stomach. Ultrasonographic endoscopy demonstrated hypoechoic, well-defined foci. The lesion initially suspected to be an inflammatory fibroma was subsequently pathologically confirmed as HV-UCD following endoscopic submucosal dissection. The lesion was completely resected, and the patient showed no signs of recurrence during 7 months of follow-up.ConclusionGastrointestinal CD is rare and should be differentiated from other occupying lesions. Its definitive diagnosis relies on histopathology.https://www.frontiersin.org/articles/10.3389/fonc.2025.1563545/fullunicentric Castleman diseasegastrointestinal tractCastleman diseaseendoscopic submucosal dissectionhistopathologycase report
spellingShingle Ting-Ting Sun
Ting-Ting Sun
Xue-Guo Sun
Ti-Dong Shan
Peng Zhao
Yan-Yan Lu
Qian Li
Fu-Guo Liu
Castleman disease of stomach treated by endoscopic submucosal dissection: a case report and literature review
Frontiers in Oncology
unicentric Castleman disease
gastrointestinal tract
Castleman disease
endoscopic submucosal dissection
histopathology
case report
title Castleman disease of stomach treated by endoscopic submucosal dissection: a case report and literature review
title_full Castleman disease of stomach treated by endoscopic submucosal dissection: a case report and literature review
title_fullStr Castleman disease of stomach treated by endoscopic submucosal dissection: a case report and literature review
title_full_unstemmed Castleman disease of stomach treated by endoscopic submucosal dissection: a case report and literature review
title_short Castleman disease of stomach treated by endoscopic submucosal dissection: a case report and literature review
title_sort castleman disease of stomach treated by endoscopic submucosal dissection a case report and literature review
topic unicentric Castleman disease
gastrointestinal tract
Castleman disease
endoscopic submucosal dissection
histopathology
case report
url https://www.frontiersin.org/articles/10.3389/fonc.2025.1563545/full
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