A Rare Case of Calciphylaxis: A Case Report

Introduction: Calciphylaxis is a rare and severe disorder characterized by obstructive small vessel disease in the subcutaneous adipose tissue and skin, leading to necrotic skin lesions. The condition poses a significant risk of mortality due to infectious and ischemic complications. Case...

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Main Authors: Maria Lafrid, Narjiss Labioui, Mohamed Hallak, Abdelaali Bahadi, Driss El Kabbaj, Mohamed Allaoui, Yassir Zajjari
Format: Article
Language:English
Published: Karger Publishers 2025-01-01
Series:Biomedicine Hub
Online Access:https://karger.com/article/doi/10.1159/000543604
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author Maria Lafrid
Narjiss Labioui
Mohamed Hallak
Abdelaali Bahadi
Driss El Kabbaj
Mohamed Allaoui
Yassir Zajjari
author_facet Maria Lafrid
Narjiss Labioui
Mohamed Hallak
Abdelaali Bahadi
Driss El Kabbaj
Mohamed Allaoui
Yassir Zajjari
author_sort Maria Lafrid
collection DOAJ
description Introduction: Calciphylaxis is a rare and severe disorder characterized by obstructive small vessel disease in the subcutaneous adipose tissue and skin, leading to necrotic skin lesions. The condition poses a significant risk of mortality due to infectious and ischemic complications. Case Presentation: We present the case of a 60-year-old woman, with a history of renal lithiasis, hypertension, and end-stage renal disease on hemodialysis complicated by hyperparathyroidism and aortic valve replacement. She developed extensive necrotic lesions on both lower limbs and upper extremities, prompting a diagnosis of calciphylaxis. Radiographic and biopsy findings supported the diagnosis, revealing characteristic calcifications. Treatment involved antibiotics, oral thiosulfate, daily hemodialysis, hyperbaric oxygen therapy, and discontinuation of calcium and alfacalcidol, with alendronate initiation. Unfortunately, despite these interventions, the patient experienced a rapid clinical decline, developing septic shock necessitating bilateral leg amputations. Regrettably, she succumbed to the disease 10 days later. Conclusion: This case underscores the challenging prognosis of calciphylaxis and the need for effective therapeutic options, including surgical intervention and access to injectable thiosulfate.
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institution Kabale University
issn 2296-6870
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publishDate 2025-01-01
publisher Karger Publishers
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spelling doaj-art-fad9eca48d07489eb2fccd4b1aa9e89e2025-08-20T03:49:41ZengKarger PublishersBiomedicine Hub2296-68702025-01-01101444910.1159/000543604A Rare Case of Calciphylaxis: A Case ReportMaria LafridNarjiss LabiouiMohamed HallakAbdelaali BahadiDriss El KabbajMohamed AllaouiYassir Zajjari Introduction: Calciphylaxis is a rare and severe disorder characterized by obstructive small vessel disease in the subcutaneous adipose tissue and skin, leading to necrotic skin lesions. The condition poses a significant risk of mortality due to infectious and ischemic complications. Case Presentation: We present the case of a 60-year-old woman, with a history of renal lithiasis, hypertension, and end-stage renal disease on hemodialysis complicated by hyperparathyroidism and aortic valve replacement. She developed extensive necrotic lesions on both lower limbs and upper extremities, prompting a diagnosis of calciphylaxis. Radiographic and biopsy findings supported the diagnosis, revealing characteristic calcifications. Treatment involved antibiotics, oral thiosulfate, daily hemodialysis, hyperbaric oxygen therapy, and discontinuation of calcium and alfacalcidol, with alendronate initiation. Unfortunately, despite these interventions, the patient experienced a rapid clinical decline, developing septic shock necessitating bilateral leg amputations. Regrettably, she succumbed to the disease 10 days later. Conclusion: This case underscores the challenging prognosis of calciphylaxis and the need for effective therapeutic options, including surgical intervention and access to injectable thiosulfate. https://karger.com/article/doi/10.1159/000543604
spellingShingle Maria Lafrid
Narjiss Labioui
Mohamed Hallak
Abdelaali Bahadi
Driss El Kabbaj
Mohamed Allaoui
Yassir Zajjari
A Rare Case of Calciphylaxis: A Case Report
Biomedicine Hub
title A Rare Case of Calciphylaxis: A Case Report
title_full A Rare Case of Calciphylaxis: A Case Report
title_fullStr A Rare Case of Calciphylaxis: A Case Report
title_full_unstemmed A Rare Case of Calciphylaxis: A Case Report
title_short A Rare Case of Calciphylaxis: A Case Report
title_sort rare case of calciphylaxis a case report
url https://karger.com/article/doi/10.1159/000543604
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