Generation of induced pluripotent stem cell line, NCHi028-A, from a male child with Prune Belly Syndrome

Prune belly syndrome (PBS) is a rare, multi-system congenital myopathy mainly affecting males, whose genetic basis is still being explored. Phenotypically, its morbidity spans from mild to lethal, and PBS cases manifest three cardinal pathological features: wrinkled, flaccid ventral abdominal wall w...

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Main Authors: Cintia E. Gomez Limia, Karunya Albert, Kusum Basnet, Chaitrali Atre, Hudaa Malik, Darria L. Streeter, Nathalia G. Amado, Linda A. Baker
Format: Article
Language:English
Published: Elsevier 2025-04-01
Series:Stem Cell Research
Online Access:http://www.sciencedirect.com/science/article/pii/S1873506125000315
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author Cintia E. Gomez Limia
Karunya Albert
Kusum Basnet
Chaitrali Atre
Hudaa Malik
Darria L. Streeter
Nathalia G. Amado
Linda A. Baker
author_facet Cintia E. Gomez Limia
Karunya Albert
Kusum Basnet
Chaitrali Atre
Hudaa Malik
Darria L. Streeter
Nathalia G. Amado
Linda A. Baker
author_sort Cintia E. Gomez Limia
collection DOAJ
description Prune belly syndrome (PBS) is a rare, multi-system congenital myopathy mainly affecting males, whose genetic basis is still being explored. Phenotypically, its morbidity spans from mild to lethal, and PBS cases manifest three cardinal pathological features: wrinkled, flaccid ventral abdominal wall with skeletal muscle deficiency, urinary tract dilation with poorly contractile smooth muscle, and intra-abdominal undescended testes. NCHi028-A is an iPSC line derived from skin fibroblasts of a 1-month-old male with PBS using Sendai Virus reprogramming factors. This iPSC line shows typical iPSC morphology, has normal karyotype, expresses undifferentiated hPSC state markers, and can be differentiated into three germ layers.
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issn 1873-5061
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publishDate 2025-04-01
publisher Elsevier
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series Stem Cell Research
spelling doaj-art-ee211a4af7f9447a9dee31d675f837782025-08-20T02:52:21ZengElsevierStem Cell Research1873-50612025-04-018410368110.1016/j.scr.2025.103681Generation of induced pluripotent stem cell line, NCHi028-A, from a male child with Prune Belly SyndromeCintia E. Gomez Limia0Karunya Albert1Kusum Basnet2Chaitrali Atre3Hudaa Malik4Darria L. Streeter5Nathalia G. Amado6Linda A. Baker7The Kidney and Urinary Tract Center, The Abigail Wexner Research Institute, Nationwide Children’s Hospital, Columbus, OH, USAThe Kidney and Urinary Tract Center, The Abigail Wexner Research Institute, Nationwide Children’s Hospital, Columbus, OH, USAThe Kidney and Urinary Tract Center, The Abigail Wexner Research Institute, Nationwide Children’s Hospital, Columbus, OH, USAThe Kidney and Urinary Tract Center, The Abigail Wexner Research Institute, Nationwide Children’s Hospital, Columbus, OH, USAThe Kidney and Urinary Tract Center, The Abigail Wexner Research Institute, Nationwide Children’s Hospital, Columbus, OH, USAThe Kidney and Urinary Tract Center, The Abigail Wexner Research Institute, Nationwide Children’s Hospital, Columbus, OH, USACorresponding authors at: The Kidney and Urinary Tract Center, The Abigail Wexner Research Institute, Nationwide Children’s Hospital, Columbus, OH, USA (N.G. Amado).; The Kidney and Urinary Tract Center, The Abigail Wexner Research Institute, Nationwide Children’s Hospital, Columbus, OH, USACorresponding authors at: The Kidney and Urinary Tract Center, The Abigail Wexner Research Institute, Nationwide Children’s Hospital, Columbus, OH, USA (N.G. Amado).; The Kidney and Urinary Tract Center, The Abigail Wexner Research Institute, Nationwide Children’s Hospital, Columbus, OH, USAPrune belly syndrome (PBS) is a rare, multi-system congenital myopathy mainly affecting males, whose genetic basis is still being explored. Phenotypically, its morbidity spans from mild to lethal, and PBS cases manifest three cardinal pathological features: wrinkled, flaccid ventral abdominal wall with skeletal muscle deficiency, urinary tract dilation with poorly contractile smooth muscle, and intra-abdominal undescended testes. NCHi028-A is an iPSC line derived from skin fibroblasts of a 1-month-old male with PBS using Sendai Virus reprogramming factors. This iPSC line shows typical iPSC morphology, has normal karyotype, expresses undifferentiated hPSC state markers, and can be differentiated into three germ layers.http://www.sciencedirect.com/science/article/pii/S1873506125000315
spellingShingle Cintia E. Gomez Limia
Karunya Albert
Kusum Basnet
Chaitrali Atre
Hudaa Malik
Darria L. Streeter
Nathalia G. Amado
Linda A. Baker
Generation of induced pluripotent stem cell line, NCHi028-A, from a male child with Prune Belly Syndrome
Stem Cell Research
title Generation of induced pluripotent stem cell line, NCHi028-A, from a male child with Prune Belly Syndrome
title_full Generation of induced pluripotent stem cell line, NCHi028-A, from a male child with Prune Belly Syndrome
title_fullStr Generation of induced pluripotent stem cell line, NCHi028-A, from a male child with Prune Belly Syndrome
title_full_unstemmed Generation of induced pluripotent stem cell line, NCHi028-A, from a male child with Prune Belly Syndrome
title_short Generation of induced pluripotent stem cell line, NCHi028-A, from a male child with Prune Belly Syndrome
title_sort generation of induced pluripotent stem cell line nchi028 a from a male child with prune belly syndrome
url http://www.sciencedirect.com/science/article/pii/S1873506125000315
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