Xeroderma Pigmentosum: Clinical and Genetic Features and Therapeutic Approaches

Xeroderma pigmentosum is rare genetic disorder characterized by increased skin sensitivity to damaging ultraviolet (UV) light. First symptoms manifest at early age in most cases (up to 75%). Chronic damage due to sun exposure is common, it has different stages of changes and risk of further developm...

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Main Authors: Tatyana S. Belysheva, Tatyana V. Nasedkina, Iryna S. Kletskaya, Anastasiya S. Volkova, Vera V. Semenova, Timur T. Valiev
Format: Article
Language:English
Published: "Paediatrician" Publishers LLC 2021-12-01
Series:Вопросы современной педиатрии
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Online Access:https://vsp.spr-journal.ru/jour/article/view/2798
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author Tatyana S. Belysheva
Tatyana V. Nasedkina
Iryna S. Kletskaya
Anastasiya S. Volkova
Vera V. Semenova
Timur T. Valiev
author_facet Tatyana S. Belysheva
Tatyana V. Nasedkina
Iryna S. Kletskaya
Anastasiya S. Volkova
Vera V. Semenova
Timur T. Valiev
author_sort Tatyana S. Belysheva
collection DOAJ
description Xeroderma pigmentosum is rare genetic disorder characterized by increased skin sensitivity to damaging ultraviolet (UV) light. First symptoms manifest at early age in most cases (up to 75%). Chronic damage due to sun exposure is common, it has different stages of changes and risk of further development of malignant tumors that depends on the gene involved. Additionally to skin manifestations there are various neurological disorders such as progressive cognitive dysfunctions, sensorineural hearing loss, ataxia, pyramid and extrapyramidal disorders, areflexia. Treatment of patients with xeroderma pigmentosum is mostly symptomatic and preventive (protection against UV). Nowadays targeted medications for DNA repair and increasing cells resistance to UV light, thus preventing the oncological diseases, are under development.
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publisher "Paediatrician" Publishers LLC
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series Вопросы современной педиатрии
spelling doaj-art-eca47751e5434916bd63aff1220d63c32025-08-20T03:01:17Zeng"Paediatrician" Publishers LLCВопросы современной педиатрии1682-55271682-55352021-12-01206s61161710.15690/vsp.v20i6S.23702002Xeroderma Pigmentosum: Clinical and Genetic Features and Therapeutic ApproachesTatyana S. Belysheva0Tatyana V. Nasedkina1Iryna S. Kletskaya2Anastasiya S. Volkova3Vera V. Semenova4Timur T. Valiev5National Medical Research Center of Oncology named after N.N. BlokhinEngelhardt Institute of Molecular BiologyRussian Children’s Clinical Hospital, Pirogov Russian National Research Medical UniversityNational Medical Research Center of Oncology named after N.N. BlokhinNational Medical Research Center of Oncology named after N.N. Blokhin; Engelhardt Institute of Molecular Biology; Research Center of Pediatric Hematology, Oncology and Immunology named after Dmitry RogachevNational Medical Research Center of Oncology named after N.N. BlokhinXeroderma pigmentosum is rare genetic disorder characterized by increased skin sensitivity to damaging ultraviolet (UV) light. First symptoms manifest at early age in most cases (up to 75%). Chronic damage due to sun exposure is common, it has different stages of changes and risk of further development of malignant tumors that depends on the gene involved. Additionally to skin manifestations there are various neurological disorders such as progressive cognitive dysfunctions, sensorineural hearing loss, ataxia, pyramid and extrapyramidal disorders, areflexia. Treatment of patients with xeroderma pigmentosum is mostly symptomatic and preventive (protection against UV). Nowadays targeted medications for DNA repair and increasing cells resistance to UV light, thus preventing the oncological diseases, are under development.https://vsp.spr-journal.ru/jour/article/view/2798xeroderma pigmentosumoncodermatosisgenetic anomalieschildren
spellingShingle Tatyana S. Belysheva
Tatyana V. Nasedkina
Iryna S. Kletskaya
Anastasiya S. Volkova
Vera V. Semenova
Timur T. Valiev
Xeroderma Pigmentosum: Clinical and Genetic Features and Therapeutic Approaches
Вопросы современной педиатрии
xeroderma pigmentosum
oncodermatosis
genetic anomalies
children
title Xeroderma Pigmentosum: Clinical and Genetic Features and Therapeutic Approaches
title_full Xeroderma Pigmentosum: Clinical and Genetic Features and Therapeutic Approaches
title_fullStr Xeroderma Pigmentosum: Clinical and Genetic Features and Therapeutic Approaches
title_full_unstemmed Xeroderma Pigmentosum: Clinical and Genetic Features and Therapeutic Approaches
title_short Xeroderma Pigmentosum: Clinical and Genetic Features and Therapeutic Approaches
title_sort xeroderma pigmentosum clinical and genetic features and therapeutic approaches
topic xeroderma pigmentosum
oncodermatosis
genetic anomalies
children
url https://vsp.spr-journal.ru/jour/article/view/2798
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AT tatyanavnasedkina xerodermapigmentosumclinicalandgeneticfeaturesandtherapeuticapproaches
AT irynaskletskaya xerodermapigmentosumclinicalandgeneticfeaturesandtherapeuticapproaches
AT anastasiyasvolkova xerodermapigmentosumclinicalandgeneticfeaturesandtherapeuticapproaches
AT veravsemenova xerodermapigmentosumclinicalandgeneticfeaturesandtherapeuticapproaches
AT timurtvaliev xerodermapigmentosumclinicalandgeneticfeaturesandtherapeuticapproaches