African glucose-6-phosphate dehydrogenase alleles associated with protection from severe malaria in heterozygous females in Tanzania.

X-linked Glucose-6-phosphate dehydrogenase (G6PD) A- deficiency is prevalent in sub-Saharan Africa populations, and has been associated with protection from severe malaria. Whether females and/or males are protected by G6PD deficiency is uncertain, due in part to G6PD and malaria phenotypic complexi...

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Main Authors: Alphaxard Manjurano, Nuno Sepulveda, Behzad Nadjm, George Mtove, Hannah Wangai, Caroline Maxwell, Raimos Olomi, Hugh Reyburn, Eleanor M Riley, Christopher J Drakeley, Taane G Clark, MalariaGEN Consortium
Format: Article
Language:English
Published: Public Library of Science (PLoS) 2015-02-01
Series:PLoS Genetics
Online Access:https://journals.plos.org/plosgenetics/article/file?id=10.1371/journal.pgen.1004960&type=printable
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author Alphaxard Manjurano
Nuno Sepulveda
Behzad Nadjm
George Mtove
Hannah Wangai
Caroline Maxwell
Raimos Olomi
Hugh Reyburn
Eleanor M Riley
Christopher J Drakeley
Taane G Clark
MalariaGEN Consortium
author_facet Alphaxard Manjurano
Nuno Sepulveda
Behzad Nadjm
George Mtove
Hannah Wangai
Caroline Maxwell
Raimos Olomi
Hugh Reyburn
Eleanor M Riley
Christopher J Drakeley
Taane G Clark
MalariaGEN Consortium
author_sort Alphaxard Manjurano
collection DOAJ
description X-linked Glucose-6-phosphate dehydrogenase (G6PD) A- deficiency is prevalent in sub-Saharan Africa populations, and has been associated with protection from severe malaria. Whether females and/or males are protected by G6PD deficiency is uncertain, due in part to G6PD and malaria phenotypic complexity and misclassification. Almost all large association studies have genotyped a limited number of G6PD SNPs (e.g. G6PD202 / G6PD376), and this approach has been too blunt to capture the complete epidemiological picture. Here we have identified 68 G6PD polymorphisms and analysed 29 of these (i.e. those with a minor allele frequency greater than 1%) in 983 severe malaria cases and controls in Tanzania. We establish, across a number of SNPs including G6PD376, that only female heterozygotes are protected from severe malaria. Haplotype analysis reveals the G6PD locus to be under balancing selection, suggesting a mechanism of protection relying on alleles at modest frequency and avoiding fixation, where protection provided by G6PD deficiency against severe malaria is offset by increased risk of life-threatening complications. Our study also demonstrates that the much-needed large-scale studies of severe malaria and G6PD enzymatic function across African populations require the identification and analysis of the full repertoire of G6PD genetic markers.
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institution Kabale University
issn 1553-7390
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language English
publishDate 2015-02-01
publisher Public Library of Science (PLoS)
record_format Article
series PLoS Genetics
spelling doaj-art-e9353f36c7a5467982dfadb0b1bd646c2025-08-20T03:46:13ZengPublic Library of Science (PLoS)PLoS Genetics1553-73901553-74042015-02-01112e100496010.1371/journal.pgen.1004960African glucose-6-phosphate dehydrogenase alleles associated with protection from severe malaria in heterozygous females in Tanzania.Alphaxard ManjuranoNuno SepulvedaBehzad NadjmGeorge MtoveHannah WangaiCaroline MaxwellRaimos OlomiHugh ReyburnEleanor M RileyChristopher J DrakeleyTaane G ClarkMalariaGEN ConsortiumX-linked Glucose-6-phosphate dehydrogenase (G6PD) A- deficiency is prevalent in sub-Saharan Africa populations, and has been associated with protection from severe malaria. Whether females and/or males are protected by G6PD deficiency is uncertain, due in part to G6PD and malaria phenotypic complexity and misclassification. Almost all large association studies have genotyped a limited number of G6PD SNPs (e.g. G6PD202 / G6PD376), and this approach has been too blunt to capture the complete epidemiological picture. Here we have identified 68 G6PD polymorphisms and analysed 29 of these (i.e. those with a minor allele frequency greater than 1%) in 983 severe malaria cases and controls in Tanzania. We establish, across a number of SNPs including G6PD376, that only female heterozygotes are protected from severe malaria. Haplotype analysis reveals the G6PD locus to be under balancing selection, suggesting a mechanism of protection relying on alleles at modest frequency and avoiding fixation, where protection provided by G6PD deficiency against severe malaria is offset by increased risk of life-threatening complications. Our study also demonstrates that the much-needed large-scale studies of severe malaria and G6PD enzymatic function across African populations require the identification and analysis of the full repertoire of G6PD genetic markers.https://journals.plos.org/plosgenetics/article/file?id=10.1371/journal.pgen.1004960&type=printable
spellingShingle Alphaxard Manjurano
Nuno Sepulveda
Behzad Nadjm
George Mtove
Hannah Wangai
Caroline Maxwell
Raimos Olomi
Hugh Reyburn
Eleanor M Riley
Christopher J Drakeley
Taane G Clark
MalariaGEN Consortium
African glucose-6-phosphate dehydrogenase alleles associated with protection from severe malaria in heterozygous females in Tanzania.
PLoS Genetics
title African glucose-6-phosphate dehydrogenase alleles associated with protection from severe malaria in heterozygous females in Tanzania.
title_full African glucose-6-phosphate dehydrogenase alleles associated with protection from severe malaria in heterozygous females in Tanzania.
title_fullStr African glucose-6-phosphate dehydrogenase alleles associated with protection from severe malaria in heterozygous females in Tanzania.
title_full_unstemmed African glucose-6-phosphate dehydrogenase alleles associated with protection from severe malaria in heterozygous females in Tanzania.
title_short African glucose-6-phosphate dehydrogenase alleles associated with protection from severe malaria in heterozygous females in Tanzania.
title_sort african glucose 6 phosphate dehydrogenase alleles associated with protection from severe malaria in heterozygous females in tanzania
url https://journals.plos.org/plosgenetics/article/file?id=10.1371/journal.pgen.1004960&type=printable
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