Charting the future: current and future directions in translational research for individuals with Down syndrome

Abstract The most common genetic cause of intellectual and developmental disability is trisomy of human chromosome 21 (trisomy 21) or Down syndrome. Relative to the general population, individuals with Down syndrome heterogeneously experience atypical morphogenesis, a distinct neurocognitive profile...

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Main Authors: Katherine A. Waugh, Heather M. Wilkins, Keith P. Smith, Lauren T. Ptomey
Format: Article
Language:English
Published: BMC 2025-07-01
Series:Journal of Neurodevelopmental Disorders
Subjects:
Online Access:https://doi.org/10.1186/s11689-025-09630-8
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author Katherine A. Waugh
Heather M. Wilkins
Keith P. Smith
Lauren T. Ptomey
author_facet Katherine A. Waugh
Heather M. Wilkins
Keith P. Smith
Lauren T. Ptomey
author_sort Katherine A. Waugh
collection DOAJ
description Abstract The most common genetic cause of intellectual and developmental disability is trisomy of human chromosome 21 (trisomy 21) or Down syndrome. Relative to the general population, individuals with Down syndrome heterogeneously experience atypical morphogenesis, a distinct neurocognitive profile, and a unique spectrum of diverse medical conditions that impact every major organ system. How trisomy 21 results in the highly variable manifestations of Down syndrome remains largely unknown and an active area of heavy investigation with therapeutic implications. For example, common inflammatory and metabolic signatures have begun to emerge across various co-occurring conditions in Down syndrome with assorted impacts on diverse yet intertwined organ systems that could directly or indirectly impact brain health. Here, we review current progress, resources, knowledge gaps, and bottlenecks for precision medicine approaches to promote brain health across the lifespan among individuals with Down syndrome within the larger context of research efforts geared towards our other distinct yet intertwined organ systems. Within this framework, we advocate for interdisciplinary pursuit of systems-level biomarkers to facilitate holistic intervention strategies that precisely benefit individuals with trisomy 21 each experiencing Down syndrome in their own unique way. To this end, we quantitatively assess clinical studies that are actively recruiting participants with Down syndrome and provide historical context through summary figures sourced to user-friendly tables that have been curated from federal websites to empower efficient exploration of research opportunities for interdisciplinary collaborations.
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spelling doaj-art-e7f59af920e149698c28b70b9893a3992025-08-20T03:42:37ZengBMCJournal of Neurodevelopmental Disorders1866-19552025-07-0117111710.1186/s11689-025-09630-8Charting the future: current and future directions in translational research for individuals with Down syndromeKatherine A. Waugh0Heather M. Wilkins1Keith P. Smith2Lauren T. Ptomey3Kansas Intellectual & Developmental Disabilities Research Center, University of Kansas Medical CenterUniversity of Kansas Alzheimer’s Disease Research CenterUniversity of Kansas Alzheimer’s Disease Research CenterKansas Intellectual & Developmental Disabilities Research Center, University of Kansas Medical CenterAbstract The most common genetic cause of intellectual and developmental disability is trisomy of human chromosome 21 (trisomy 21) or Down syndrome. Relative to the general population, individuals with Down syndrome heterogeneously experience atypical morphogenesis, a distinct neurocognitive profile, and a unique spectrum of diverse medical conditions that impact every major organ system. How trisomy 21 results in the highly variable manifestations of Down syndrome remains largely unknown and an active area of heavy investigation with therapeutic implications. For example, common inflammatory and metabolic signatures have begun to emerge across various co-occurring conditions in Down syndrome with assorted impacts on diverse yet intertwined organ systems that could directly or indirectly impact brain health. Here, we review current progress, resources, knowledge gaps, and bottlenecks for precision medicine approaches to promote brain health across the lifespan among individuals with Down syndrome within the larger context of research efforts geared towards our other distinct yet intertwined organ systems. Within this framework, we advocate for interdisciplinary pursuit of systems-level biomarkers to facilitate holistic intervention strategies that precisely benefit individuals with trisomy 21 each experiencing Down syndrome in their own unique way. To this end, we quantitatively assess clinical studies that are actively recruiting participants with Down syndrome and provide historical context through summary figures sourced to user-friendly tables that have been curated from federal websites to empower efficient exploration of research opportunities for interdisciplinary collaborations.https://doi.org/10.1186/s11689-025-09630-8Down syndromeTrisomy 21Intellectual and Developmental DisabilityPrecision MedicineBrain HealthBiomarkers
spellingShingle Katherine A. Waugh
Heather M. Wilkins
Keith P. Smith
Lauren T. Ptomey
Charting the future: current and future directions in translational research for individuals with Down syndrome
Journal of Neurodevelopmental Disorders
Down syndrome
Trisomy 21
Intellectual and Developmental Disability
Precision Medicine
Brain Health
Biomarkers
title Charting the future: current and future directions in translational research for individuals with Down syndrome
title_full Charting the future: current and future directions in translational research for individuals with Down syndrome
title_fullStr Charting the future: current and future directions in translational research for individuals with Down syndrome
title_full_unstemmed Charting the future: current and future directions in translational research for individuals with Down syndrome
title_short Charting the future: current and future directions in translational research for individuals with Down syndrome
title_sort charting the future current and future directions in translational research for individuals with down syndrome
topic Down syndrome
Trisomy 21
Intellectual and Developmental Disability
Precision Medicine
Brain Health
Biomarkers
url https://doi.org/10.1186/s11689-025-09630-8
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AT keithpsmith chartingthefuturecurrentandfuturedirectionsintranslationalresearchforindividualswithdownsyndrome
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