A Fatal Case of Cor Pulmonale with Undetected Chronic Hypoventilation in an Infant with a Known Congenital Myopathy

The authors of this paper wish to present a case of fatal cor pulmonale with right ventricular hypertrophy complicated by a congenital myopathy. It is our intention to demonstrate the importance of vigilant clinical assessment of children with a congenital myopathy, regardless of the exact etiology...

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Main Authors: John M. Holst, Mary J. Willis
Format: Article
Language:English
Published: Wiley 2012-01-01
Series:Case Reports in Pediatrics
Online Access:http://dx.doi.org/10.1155/2012/836420
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author John M. Holst
Mary J. Willis
author_facet John M. Holst
Mary J. Willis
author_sort John M. Holst
collection DOAJ
description The authors of this paper wish to present a case of fatal cor pulmonale with right ventricular hypertrophy complicated by a congenital myopathy. It is our intention to demonstrate the importance of vigilant clinical assessment of children with a congenital myopathy, regardless of the exact etiology of their disease, or family history of disease severity. This case highlights the risk for fatal complications if hypoventilation and respiratory insufficiency go unrecognized in myopathic children. Consequently, we recommend respiratory and cardiac monitoring surveillance as well as appropriate referral to specialists in the management of such children.
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spelling doaj-art-e75971a13342486d95c8bacbb20f3f892025-08-20T02:21:10ZengWileyCase Reports in Pediatrics2090-68032090-68112012-01-01201210.1155/2012/836420836420A Fatal Case of Cor Pulmonale with Undetected Chronic Hypoventilation in an Infant with a Known Congenital MyopathyJohn M. Holst0Mary J. Willis1Department of Aviation Medicine, Naval Air Station North Island, Parkville, MD 21234, USADepartment of Genetics, Naval Medical Center San Diego, San Diego, CA 92134, USAThe authors of this paper wish to present a case of fatal cor pulmonale with right ventricular hypertrophy complicated by a congenital myopathy. It is our intention to demonstrate the importance of vigilant clinical assessment of children with a congenital myopathy, regardless of the exact etiology of their disease, or family history of disease severity. This case highlights the risk for fatal complications if hypoventilation and respiratory insufficiency go unrecognized in myopathic children. Consequently, we recommend respiratory and cardiac monitoring surveillance as well as appropriate referral to specialists in the management of such children.http://dx.doi.org/10.1155/2012/836420
spellingShingle John M. Holst
Mary J. Willis
A Fatal Case of Cor Pulmonale with Undetected Chronic Hypoventilation in an Infant with a Known Congenital Myopathy
Case Reports in Pediatrics
title A Fatal Case of Cor Pulmonale with Undetected Chronic Hypoventilation in an Infant with a Known Congenital Myopathy
title_full A Fatal Case of Cor Pulmonale with Undetected Chronic Hypoventilation in an Infant with a Known Congenital Myopathy
title_fullStr A Fatal Case of Cor Pulmonale with Undetected Chronic Hypoventilation in an Infant with a Known Congenital Myopathy
title_full_unstemmed A Fatal Case of Cor Pulmonale with Undetected Chronic Hypoventilation in an Infant with a Known Congenital Myopathy
title_short A Fatal Case of Cor Pulmonale with Undetected Chronic Hypoventilation in an Infant with a Known Congenital Myopathy
title_sort fatal case of cor pulmonale with undetected chronic hypoventilation in an infant with a known congenital myopathy
url http://dx.doi.org/10.1155/2012/836420
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