Kearns-Sayre syndrome with restricted diffusion in subcortical white matter and extraocular muscle atrophy

Kearns-Sayre Syndrome (KSS) is a rare multisystem mitochondrial disorder affecting muscles, the central nervous system, and the endocrine system. KSS is characterized by T2WI/FLAIR hyperintensities in the subcortical white matter, brainstem, globi pallidi, thalami, and middle cerebellar peduncles. H...

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Main Authors: Megumi Matsukawa, MD, Masayuki Maeda, MD, PhD, Fumine Tanaka, MD, PhD, Ryota Kogue, MD, PhD, Maki Umino, MD, PhD, Akisato Nishigaki, MD, Hajime Sakuma, MD, PhD
Format: Article
Language:English
Published: Elsevier 2025-06-01
Series:Radiology Case Reports
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Online Access:http://www.sciencedirect.com/science/article/pii/S193004332500192X
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author Megumi Matsukawa, MD
Masayuki Maeda, MD, PhD
Fumine Tanaka, MD, PhD
Ryota Kogue, MD, PhD
Maki Umino, MD, PhD
Akisato Nishigaki, MD
Hajime Sakuma, MD, PhD
author_facet Megumi Matsukawa, MD
Masayuki Maeda, MD, PhD
Fumine Tanaka, MD, PhD
Ryota Kogue, MD, PhD
Maki Umino, MD, PhD
Akisato Nishigaki, MD
Hajime Sakuma, MD, PhD
author_sort Megumi Matsukawa, MD
collection DOAJ
description Kearns-Sayre Syndrome (KSS) is a rare multisystem mitochondrial disorder affecting muscles, the central nervous system, and the endocrine system. KSS is characterized by T2WI/FLAIR hyperintensities in the subcortical white matter, brainstem, globi pallidi, thalami, and middle cerebellar peduncles. Here, we report a case of KSS with extraocular muscle atrophy in which MRI performed approximately 10 years after the initial MRI examination revealed lesion expansion and diffusion restriction of subcortical white matter affecting U-fibers.
format Article
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publishDate 2025-06-01
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series Radiology Case Reports
spelling doaj-art-e11620fcf0f646d6a2da761ebd3f7ffe2025-08-20T03:09:07ZengElsevierRadiology Case Reports1930-04332025-06-012062646265010.1016/j.radcr.2025.02.088Kearns-Sayre syndrome with restricted diffusion in subcortical white matter and extraocular muscle atrophyMegumi Matsukawa, MD0Masayuki Maeda, MD, PhD1Fumine Tanaka, MD, PhD2Ryota Kogue, MD, PhD3Maki Umino, MD, PhD4Akisato Nishigaki, MD5Hajime Sakuma, MD, PhD6Department of Radiology, Mie University School of Medicine, Tsu, 514-8507, Japan; Corresponding author.Department of Neuroradiology, Mie University School of Medicine, Tsu, 514-8507, JapanDepartment of Radiology, Mie University School of Medicine, Tsu, 514-8507, JapanDepartment of Radiology, Mie University School of Medicine, Tsu, 514-8507, JapanDepartment of Radiology, Mie University School of Medicine, Tsu, 514-8507, JapanDepartment of Neurology, Mie University School of Medicine, Tsu, 514-8507, JapanDepartment of Radiology, Mie University School of Medicine, Tsu, 514-8507, JapanKearns-Sayre Syndrome (KSS) is a rare multisystem mitochondrial disorder affecting muscles, the central nervous system, and the endocrine system. KSS is characterized by T2WI/FLAIR hyperintensities in the subcortical white matter, brainstem, globi pallidi, thalami, and middle cerebellar peduncles. Here, we report a case of KSS with extraocular muscle atrophy in which MRI performed approximately 10 years after the initial MRI examination revealed lesion expansion and diffusion restriction of subcortical white matter affecting U-fibers.http://www.sciencedirect.com/science/article/pii/S193004332500192XBrainDiffusion-weighted imagingKearns-Sayre syndromeMRI
spellingShingle Megumi Matsukawa, MD
Masayuki Maeda, MD, PhD
Fumine Tanaka, MD, PhD
Ryota Kogue, MD, PhD
Maki Umino, MD, PhD
Akisato Nishigaki, MD
Hajime Sakuma, MD, PhD
Kearns-Sayre syndrome with restricted diffusion in subcortical white matter and extraocular muscle atrophy
Radiology Case Reports
Brain
Diffusion-weighted imaging
Kearns-Sayre syndrome
MRI
title Kearns-Sayre syndrome with restricted diffusion in subcortical white matter and extraocular muscle atrophy
title_full Kearns-Sayre syndrome with restricted diffusion in subcortical white matter and extraocular muscle atrophy
title_fullStr Kearns-Sayre syndrome with restricted diffusion in subcortical white matter and extraocular muscle atrophy
title_full_unstemmed Kearns-Sayre syndrome with restricted diffusion in subcortical white matter and extraocular muscle atrophy
title_short Kearns-Sayre syndrome with restricted diffusion in subcortical white matter and extraocular muscle atrophy
title_sort kearns sayre syndrome with restricted diffusion in subcortical white matter and extraocular muscle atrophy
topic Brain
Diffusion-weighted imaging
Kearns-Sayre syndrome
MRI
url http://www.sciencedirect.com/science/article/pii/S193004332500192X
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