Acute Intermittent Porphyria in a Man with Dual Enzyme Deficiencies

Porphyrias are a heterogeneous group of metabolic disorders that result from the altered activity of specific enzymes of the heme biosynthetic pathway and are characterized by accumulation of pathway intermediates. Porphyria cutanea tarda (PCT) is the most common porphyria and is due to deficient ac...

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Main Authors: G. N. Cerbino, L. Abou Assali, L. S. Varela, L. Tomassi, A. Batlle, V. E. Parera, M. V. Rossetti
Format: Article
Language:English
Published: Wiley 2020-01-01
Series:Case Reports in Genetics
Online Access:http://dx.doi.org/10.1155/2020/8873219
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author G. N. Cerbino
L. Abou Assali
L. S. Varela
L. Tomassi
A. Batlle
V. E. Parera
M. V. Rossetti
author_facet G. N. Cerbino
L. Abou Assali
L. S. Varela
L. Tomassi
A. Batlle
V. E. Parera
M. V. Rossetti
author_sort G. N. Cerbino
collection DOAJ
description Porphyrias are a heterogeneous group of metabolic disorders that result from the altered activity of specific enzymes of the heme biosynthetic pathway and are characterized by accumulation of pathway intermediates. Porphyria cutanea tarda (PCT) is the most common porphyria and is due to deficient activity of uroporphyrinogen decarboxylase (UROD). Acute intermittent porphyria (AIP) is the most common of the acute hepatic porphyrias, caused by decreased activity of hydroxymethylbilane synthase (HMBS). An Argentinean man with a family history of PCT who carried the UROD variant c.10_11insA suffered severe abdominal pain. Biochemical testing was consistent with AIP, and molecular analysis of HMBS revealed a de novo variant: c.344 + 2_ + 5delTAAG. This is one of the few cases of porphyria identified with both UROD and HMBS mutations and the first confirmed case of porphyria with dual enzyme deficiencies in Argentina.
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institution Kabale University
issn 2090-6544
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language English
publishDate 2020-01-01
publisher Wiley
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series Case Reports in Genetics
spelling doaj-art-de19d31390a34ee99f897b82a8955fec2025-08-20T03:26:29ZengWileyCase Reports in Genetics2090-65442090-65522020-01-01202010.1155/2020/88732198873219Acute Intermittent Porphyria in a Man with Dual Enzyme DeficienciesG. N. Cerbino0L. Abou Assali1L. S. Varela2L. Tomassi3A. Batlle4V. E. Parera5M. V. Rossetti6Centro de Investigaciones sobre Porfirinas y Porfirias (CIPYP)-CONICET, Hospital de Clínicas-UBA, Buenos Aires, ArgentinaCentro de Investigaciones sobre Porfirinas y Porfirias (CIPYP)-CONICET, Hospital de Clínicas-UBA, Buenos Aires, ArgentinaCentro de Investigaciones sobre Porfirinas y Porfirias (CIPYP)-CONICET, Hospital de Clínicas-UBA, Buenos Aires, ArgentinaHospital General de Agudos, Buenos Aires, ArgentinaCentro de Investigaciones sobre Porfirinas y Porfirias (CIPYP)-CONICET, Hospital de Clínicas-UBA, Buenos Aires, ArgentinaCentro de Investigaciones sobre Porfirinas y Porfirias (CIPYP)-CONICET, Hospital de Clínicas-UBA, Buenos Aires, ArgentinaCentro de Investigaciones sobre Porfirinas y Porfirias (CIPYP)-CONICET, Hospital de Clínicas-UBA, Buenos Aires, ArgentinaPorphyrias are a heterogeneous group of metabolic disorders that result from the altered activity of specific enzymes of the heme biosynthetic pathway and are characterized by accumulation of pathway intermediates. Porphyria cutanea tarda (PCT) is the most common porphyria and is due to deficient activity of uroporphyrinogen decarboxylase (UROD). Acute intermittent porphyria (AIP) is the most common of the acute hepatic porphyrias, caused by decreased activity of hydroxymethylbilane synthase (HMBS). An Argentinean man with a family history of PCT who carried the UROD variant c.10_11insA suffered severe abdominal pain. Biochemical testing was consistent with AIP, and molecular analysis of HMBS revealed a de novo variant: c.344 + 2_ + 5delTAAG. This is one of the few cases of porphyria identified with both UROD and HMBS mutations and the first confirmed case of porphyria with dual enzyme deficiencies in Argentina.http://dx.doi.org/10.1155/2020/8873219
spellingShingle G. N. Cerbino
L. Abou Assali
L. S. Varela
L. Tomassi
A. Batlle
V. E. Parera
M. V. Rossetti
Acute Intermittent Porphyria in a Man with Dual Enzyme Deficiencies
Case Reports in Genetics
title Acute Intermittent Porphyria in a Man with Dual Enzyme Deficiencies
title_full Acute Intermittent Porphyria in a Man with Dual Enzyme Deficiencies
title_fullStr Acute Intermittent Porphyria in a Man with Dual Enzyme Deficiencies
title_full_unstemmed Acute Intermittent Porphyria in a Man with Dual Enzyme Deficiencies
title_short Acute Intermittent Porphyria in a Man with Dual Enzyme Deficiencies
title_sort acute intermittent porphyria in a man with dual enzyme deficiencies
url http://dx.doi.org/10.1155/2020/8873219
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AT abatlle acuteintermittentporphyriainamanwithdualenzymedeficiencies
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