Rosai-Dorfman disease of vertebra: Case report and literature review

Rosai-Dorfman disease is a rare benign histiocytic disorder that arises predominantly in lymph nodes with fever and malaise, but can affect various organs, with or without lymphadenopathy. Solitary extranodal skeletal lesions are extremely rare. Herein, we describe a case of isolated disease...

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Main Authors: Zoran Igrutinovic, Rasa Medovic, Slavica Markovic, Gordana Kostic, Zorica Raskovic, Jelena Tanaskovic-Nestorovic, Marija Radovanovic, Biljana Vuletic
Format: Article
Language:English
Published: Hacettepe University Institute of Child Health 2016-10-01
Series:The Turkish Journal of Pediatrics
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Online Access:https://turkjpediatr.org/article/view/1163
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author Zoran Igrutinovic
Rasa Medovic
Slavica Markovic
Gordana Kostic
Zorica Raskovic
Jelena Tanaskovic-Nestorovic
Marija Radovanovic
Biljana Vuletic
author_facet Zoran Igrutinovic
Rasa Medovic
Slavica Markovic
Gordana Kostic
Zorica Raskovic
Jelena Tanaskovic-Nestorovic
Marija Radovanovic
Biljana Vuletic
author_sort Zoran Igrutinovic
collection DOAJ
description Rosai-Dorfman disease is a rare benign histiocytic disorder that arises predominantly in lymph nodes with fever and malaise, but can affect various organs, with or without lymphadenopathy. Solitary extranodal skeletal lesions are extremely rare. Herein, we describe a case of isolated disease of thoracic spine, with vertebral body fracture. A 14-year-old girl presented with cervical back pain for about one month as the only symptom. There was no lymphadenopathy. Results of laboratory tests were within reference ranges. The radiological examinations revealed collapse, osteolytic lesion and compressive fracture, which reduced vertical diameter of C4 vertebral body. The patient made a complete recovery after a limited C4 laminectomy, spondylodesis C3/C5 vertebra and biopsy of the lesion. Histologically, nonspecific cellular milieu and atypical histiocytic proliferation with emperipolesis, with CD68 and S100 positivity, confirmed a diagnosis of Rosai-Dorfman disease. Isolated extranodal skeletal Rosai-Dorfman disease should be considered among the differential diagnoses of similar changes, such as Langerhans cell histiocytosis, Erdheim-Cheister disease, eosinophilic granuloma, osteomyelitis, metastasis and lymphoma.
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publishDate 2016-10-01
publisher Hacettepe University Institute of Child Health
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spelling doaj-art-ddbdd0885e9f472aaee72293f8f269022025-08-20T03:01:11ZengHacettepe University Institute of Child HealthThe Turkish Journal of Pediatrics0041-43012791-64212016-10-0158510.24953/turkjped.2016.05.020Rosai-Dorfman disease of vertebra: Case report and literature reviewZoran IgrutinovicRasa Medovic0Slavica MarkovicGordana KosticZorica RaskovicJelena Tanaskovic-NestorovicMarija RadovanovicBiljana VuleticPediatric Clinic, Clinical Centre Kragujevac; University of Kragujevac, Kragujevac, Serbia. Rosai-Dorfman disease is a rare benign histiocytic disorder that arises predominantly in lymph nodes with fever and malaise, but can affect various organs, with or without lymphadenopathy. Solitary extranodal skeletal lesions are extremely rare. Herein, we describe a case of isolated disease of thoracic spine, with vertebral body fracture. A 14-year-old girl presented with cervical back pain for about one month as the only symptom. There was no lymphadenopathy. Results of laboratory tests were within reference ranges. The radiological examinations revealed collapse, osteolytic lesion and compressive fracture, which reduced vertical diameter of C4 vertebral body. The patient made a complete recovery after a limited C4 laminectomy, spondylodesis C3/C5 vertebra and biopsy of the lesion. Histologically, nonspecific cellular milieu and atypical histiocytic proliferation with emperipolesis, with CD68 and S100 positivity, confirmed a diagnosis of Rosai-Dorfman disease. Isolated extranodal skeletal Rosai-Dorfman disease should be considered among the differential diagnoses of similar changes, such as Langerhans cell histiocytosis, Erdheim-Cheister disease, eosinophilic granuloma, osteomyelitis, metastasis and lymphoma. https://turkjpediatr.org/article/view/1163back painemperipolesislaminectomysinus histiocytosis
spellingShingle Zoran Igrutinovic
Rasa Medovic
Slavica Markovic
Gordana Kostic
Zorica Raskovic
Jelena Tanaskovic-Nestorovic
Marija Radovanovic
Biljana Vuletic
Rosai-Dorfman disease of vertebra: Case report and literature review
The Turkish Journal of Pediatrics
back pain
emperipolesis
laminectomy
sinus histiocytosis
title Rosai-Dorfman disease of vertebra: Case report and literature review
title_full Rosai-Dorfman disease of vertebra: Case report and literature review
title_fullStr Rosai-Dorfman disease of vertebra: Case report and literature review
title_full_unstemmed Rosai-Dorfman disease of vertebra: Case report and literature review
title_short Rosai-Dorfman disease of vertebra: Case report and literature review
title_sort rosai dorfman disease of vertebra case report and literature review
topic back pain
emperipolesis
laminectomy
sinus histiocytosis
url https://turkjpediatr.org/article/view/1163
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AT gordanakostic rosaidorfmandiseaseofvertebracasereportandliteraturereview
AT zoricaraskovic rosaidorfmandiseaseofvertebracasereportandliteraturereview
AT jelenatanaskovicnestorovic rosaidorfmandiseaseofvertebracasereportandliteraturereview
AT marijaradovanovic rosaidorfmandiseaseofvertebracasereportandliteraturereview
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