VTA dopamine neurons are hyperexcitable in 3xTg-AD mice due to casein kinase 2-dependent SK channel dysfunction

Abstract Alzheimer’s disease (AD) patients exhibit neuropsychiatric symptoms that extend beyond classical cognitive deficits, suggesting involvement of subcortical areas. Here, we investigated the role of midbrain dopamine (DA) neurons in AD using the amyloid + tau-driven 3xTg-AD mouse model. We fou...

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Main Authors: Harris E. Blankenship, Kelsey A. Carter, Kevin D. Pham, Nina T. Cassidy, Andrea N. Markiewicz, Michael I. Thellmann, Amanda L. Sharpe, Willard M. Freeman, Michael J. Beckstead
Format: Article
Language:English
Published: Nature Portfolio 2024-11-01
Series:Nature Communications
Online Access:https://doi.org/10.1038/s41467-024-53891-1
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author Harris E. Blankenship
Kelsey A. Carter
Kevin D. Pham
Nina T. Cassidy
Andrea N. Markiewicz
Michael I. Thellmann
Amanda L. Sharpe
Willard M. Freeman
Michael J. Beckstead
author_facet Harris E. Blankenship
Kelsey A. Carter
Kevin D. Pham
Nina T. Cassidy
Andrea N. Markiewicz
Michael I. Thellmann
Amanda L. Sharpe
Willard M. Freeman
Michael J. Beckstead
author_sort Harris E. Blankenship
collection DOAJ
description Abstract Alzheimer’s disease (AD) patients exhibit neuropsychiatric symptoms that extend beyond classical cognitive deficits, suggesting involvement of subcortical areas. Here, we investigated the role of midbrain dopamine (DA) neurons in AD using the amyloid + tau-driven 3xTg-AD mouse model. We found deficits in reward-based operant learning in AD mice, suggesting possible VTA DA neuron dysregulation. Physiological assessment revealed hyperexcitability and disrupted firing in DA neurons caused by reduced activity of small-conductance calcium-activated potassium (SK) channels. RNA sequencing from contents of single patch-clamped DA neurons (Patch-seq) identified up-regulation of the SK channel modulator casein kinase 2 (CK2), which we corroborated by immunohistochemical protein analysis. Pharmacological inhibition of CK2 restored SK channel activity and normal firing patterns in 3xTg-AD mice. These findings identify a mechanism of ion channel dysregulation in VTA DA neurons that could contribute to behavioral abnormalities in AD, paving the way for novel treatment strategies.
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series Nature Communications
spelling doaj-art-dd82a031eca54bdd80aba860fe826dbc2025-08-20T02:13:28ZengNature PortfolioNature Communications2041-17232024-11-0115112010.1038/s41467-024-53891-1VTA dopamine neurons are hyperexcitable in 3xTg-AD mice due to casein kinase 2-dependent SK channel dysfunctionHarris E. Blankenship0Kelsey A. Carter1Kevin D. Pham2Nina T. Cassidy3Andrea N. Markiewicz4Michael I. Thellmann5Amanda L. Sharpe6Willard M. Freeman7Michael J. Beckstead8Aging and Metabolism Research Program, Oklahoma Medical Research FoundationAging and Metabolism Research Program, Oklahoma Medical Research FoundationGenes and Human Disease Research Program, Oklahoma Medical Research FoundationAging and Metabolism Research Program, Oklahoma Medical Research FoundationAging and Metabolism Research Program, Oklahoma Medical Research FoundationAging and Metabolism Research Program, Oklahoma Medical Research FoundationDepartment of Pharmaceutical Sciences, University of Oklahoma Health Sciences CenterGenes and Human Disease Research Program, Oklahoma Medical Research FoundationAging and Metabolism Research Program, Oklahoma Medical Research FoundationAbstract Alzheimer’s disease (AD) patients exhibit neuropsychiatric symptoms that extend beyond classical cognitive deficits, suggesting involvement of subcortical areas. Here, we investigated the role of midbrain dopamine (DA) neurons in AD using the amyloid + tau-driven 3xTg-AD mouse model. We found deficits in reward-based operant learning in AD mice, suggesting possible VTA DA neuron dysregulation. Physiological assessment revealed hyperexcitability and disrupted firing in DA neurons caused by reduced activity of small-conductance calcium-activated potassium (SK) channels. RNA sequencing from contents of single patch-clamped DA neurons (Patch-seq) identified up-regulation of the SK channel modulator casein kinase 2 (CK2), which we corroborated by immunohistochemical protein analysis. Pharmacological inhibition of CK2 restored SK channel activity and normal firing patterns in 3xTg-AD mice. These findings identify a mechanism of ion channel dysregulation in VTA DA neurons that could contribute to behavioral abnormalities in AD, paving the way for novel treatment strategies.https://doi.org/10.1038/s41467-024-53891-1
spellingShingle Harris E. Blankenship
Kelsey A. Carter
Kevin D. Pham
Nina T. Cassidy
Andrea N. Markiewicz
Michael I. Thellmann
Amanda L. Sharpe
Willard M. Freeman
Michael J. Beckstead
VTA dopamine neurons are hyperexcitable in 3xTg-AD mice due to casein kinase 2-dependent SK channel dysfunction
Nature Communications
title VTA dopamine neurons are hyperexcitable in 3xTg-AD mice due to casein kinase 2-dependent SK channel dysfunction
title_full VTA dopamine neurons are hyperexcitable in 3xTg-AD mice due to casein kinase 2-dependent SK channel dysfunction
title_fullStr VTA dopamine neurons are hyperexcitable in 3xTg-AD mice due to casein kinase 2-dependent SK channel dysfunction
title_full_unstemmed VTA dopamine neurons are hyperexcitable in 3xTg-AD mice due to casein kinase 2-dependent SK channel dysfunction
title_short VTA dopamine neurons are hyperexcitable in 3xTg-AD mice due to casein kinase 2-dependent SK channel dysfunction
title_sort vta dopamine neurons are hyperexcitable in 3xtg ad mice due to casein kinase 2 dependent sk channel dysfunction
url https://doi.org/10.1038/s41467-024-53891-1
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