Microcephaly and developmental delay caused by short-chain acyl-CoA dehydrogenase deficiency

We report a four-year-old girl who presented with intrauterine growth retardation, mild dysmorphism, cleft palate, microcephaly, developmental delay, epilepsy and recurrent lower respiratory tract infection and diagnosed short-chain acyl-CoA dehydrogenase deficiency. Metabolic evaluation and molecu...

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Main Authors: Mustafa Kılıç, Saliha Şenel, Kadri Karaer, Serdar Ceylaner
Format: Article
Language:English
Published: Hacettepe University Institute of Child Health 2017-12-01
Series:The Turkish Journal of Pediatrics
Subjects:
Online Access:https://turkjpediatr.org/article/view/1058
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author Mustafa Kılıç
Saliha Şenel
Kadri Karaer
Serdar Ceylaner
author_facet Mustafa Kılıç
Saliha Şenel
Kadri Karaer
Serdar Ceylaner
author_sort Mustafa Kılıç
collection DOAJ
description We report a four-year-old girl who presented with intrauterine growth retardation, mild dysmorphism, cleft palate, microcephaly, developmental delay, epilepsy and recurrent lower respiratory tract infection and diagnosed short-chain acyl-CoA dehydrogenase deficiency. Metabolic evaluation and molecular analysis confirmed the diagnosis. In spite of many patients already known in literature, this is one of the rarest reports of a Turkish patient. This suggests selective metabolic screening should be done in every patient with unknown etiology of neurological disorder. Furthermore, newborn screening using tandem mass spectrometry may prevent this severe neurological impairment.
format Article
id doaj-art-dd20cc024cfd4ed59af25a4e69e69bd8
institution DOAJ
issn 0041-4301
2791-6421
language English
publishDate 2017-12-01
publisher Hacettepe University Institute of Child Health
record_format Article
series The Turkish Journal of Pediatrics
spelling doaj-art-dd20cc024cfd4ed59af25a4e69e69bd82025-08-20T03:01:14ZengHacettepe University Institute of Child HealthThe Turkish Journal of Pediatrics0041-43012791-64212017-12-0159610.24953/turkjped.2017.06.016Microcephaly and developmental delay caused by short-chain acyl-CoA dehydrogenase deficiencyMustafa Kılıç0Saliha Şenel1Kadri KaraerSerdar CeylanerDivision of Metabolism, Dr. Sami Ulus Children Hospital, 3Intergen Laboratory, Ankara, Turkey.Department of Pediatrics, Dr. Sami Ulus Children Hospital, 3Intergen Laboratory, Ankara, Turkey. We report a four-year-old girl who presented with intrauterine growth retardation, mild dysmorphism, cleft palate, microcephaly, developmental delay, epilepsy and recurrent lower respiratory tract infection and diagnosed short-chain acyl-CoA dehydrogenase deficiency. Metabolic evaluation and molecular analysis confirmed the diagnosis. In spite of many patients already known in literature, this is one of the rarest reports of a Turkish patient. This suggests selective metabolic screening should be done in every patient with unknown etiology of neurological disorder. Furthermore, newborn screening using tandem mass spectrometry may prevent this severe neurological impairment. https://turkjpediatr.org/article/view/1058ACADSSCADdevelopmental delayepilepsymicrocephaly
spellingShingle Mustafa Kılıç
Saliha Şenel
Kadri Karaer
Serdar Ceylaner
Microcephaly and developmental delay caused by short-chain acyl-CoA dehydrogenase deficiency
The Turkish Journal of Pediatrics
ACADS
SCAD
developmental delay
epilepsy
microcephaly
title Microcephaly and developmental delay caused by short-chain acyl-CoA dehydrogenase deficiency
title_full Microcephaly and developmental delay caused by short-chain acyl-CoA dehydrogenase deficiency
title_fullStr Microcephaly and developmental delay caused by short-chain acyl-CoA dehydrogenase deficiency
title_full_unstemmed Microcephaly and developmental delay caused by short-chain acyl-CoA dehydrogenase deficiency
title_short Microcephaly and developmental delay caused by short-chain acyl-CoA dehydrogenase deficiency
title_sort microcephaly and developmental delay caused by short chain acyl coa dehydrogenase deficiency
topic ACADS
SCAD
developmental delay
epilepsy
microcephaly
url https://turkjpediatr.org/article/view/1058
work_keys_str_mv AT mustafakılıc microcephalyanddevelopmentaldelaycausedbyshortchainacylcoadehydrogenasedeficiency
AT salihasenel microcephalyanddevelopmentaldelaycausedbyshortchainacylcoadehydrogenasedeficiency
AT kadrikaraer microcephalyanddevelopmentaldelaycausedbyshortchainacylcoadehydrogenasedeficiency
AT serdarceylaner microcephalyanddevelopmentaldelaycausedbyshortchainacylcoadehydrogenasedeficiency