Significance of exome sequencing for diagnosis of epilepsy in children

Introduction. Epilepsy is a neurological disorder characterized by periodic seizure attacks. Around 70–80% of epilepsy cases have a hereditary component.Aim: to identify the genetic factors of pharmacoresistant epilepsy in children.Materials and methods. Fifty two patients with epilepsy and psychomo...

Full description

Saved in:
Bibliographic Details
Main Authors: T. V. Kozhanova, S. S. Zhilina, T. I. Meshheryakova, K. V. Osipova, S. O. Ayvazyan, A. G. Prityko
Format: Article
Language:Russian
Published: IRBIS LLC 2020-01-01
Series:Эпилепсия и пароксизмальные состояния
Subjects:
Online Access:https://www.epilepsia.su/jour/article/view/504
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1849249499104411648
author T. V. Kozhanova
S. S. Zhilina
T. I. Meshheryakova
K. V. Osipova
S. O. Ayvazyan
A. G. Prityko
author_facet T. V. Kozhanova
S. S. Zhilina
T. I. Meshheryakova
K. V. Osipova
S. O. Ayvazyan
A. G. Prityko
author_sort T. V. Kozhanova
collection DOAJ
description Introduction. Epilepsy is a neurological disorder characterized by periodic seizure attacks. Around 70–80% of epilepsy cases have a hereditary component.Aim: to identify the genetic factors of pharmacoresistant epilepsy in children.Materials and methods. Fifty two patients with epilepsy and psychomotor / speech retardation were examined. We used the next generation sequencing (NGS) technique, which is the targeted exome sequencing, the “Hereditary epilepsy” panel of genes, and the whole exome sequencing assay.Results. Mutations were detected in 30 (57.7%) patients, while 22 patients had no mutations. In the latter cases, either epilepsy was of non-hereditary nature or the tested nucleotide sequence was located in the non-coding part of the gene (intron); in addition, a chromosomal rearrangement could be involved.Conclusion. The obtained data illustrate a diagnostic significance of the whole exome sequencing and encourage the interaction between an epileptologist and a geneticist in the diagnostic procedure. Identification of the genetic base of the disease is of great importance for genetic counseling and for selecting an antiepileptic therapy in this group of patients.The authors declare about the absence of conflict of interest with respect to this publication. Authors contributed equally to this article.
format Article
id doaj-art-dc9e5eb4687d4dddb431b70fa74c9dc6
institution Kabale University
issn 2077-8333
2311-4088
language Russian
publishDate 2020-01-01
publisher IRBIS LLC
record_format Article
series Эпилепсия и пароксизмальные состояния
spelling doaj-art-dc9e5eb4687d4dddb431b70fa74c9dc62025-08-20T03:57:32ZrusIRBIS LLCЭпилепсия и пароксизмальные состояния2077-83332311-40882020-01-0111437938710.17749/2077-8333.2019.11.4.379-387470Significance of exome sequencing for diagnosis of epilepsy in childrenT. V. Kozhanova0S. S. Zhilina1T. I. Meshheryakova2K. V. Osipova3S. O. Ayvazyan4A. G. Prityko5St. Luka’s Clinical Research Center for Children; Pirogov Russian National Research Medical UniversitySt. Luka’s Clinical Research Center for Children; Pirogov Russian National Research Medical UniversitySt. Luka’s Clinical Research Center for ChildrenSt. Luka’s Clinical Research Center for ChildrenSt. Luka’s Clinical Research Center for ChildrenSt. Luka’s Clinical Research Center for Children; Pirogov Russian National Research Medical UniversityIntroduction. Epilepsy is a neurological disorder characterized by periodic seizure attacks. Around 70–80% of epilepsy cases have a hereditary component.Aim: to identify the genetic factors of pharmacoresistant epilepsy in children.Materials and methods. Fifty two patients with epilepsy and psychomotor / speech retardation were examined. We used the next generation sequencing (NGS) technique, which is the targeted exome sequencing, the “Hereditary epilepsy” panel of genes, and the whole exome sequencing assay.Results. Mutations were detected in 30 (57.7%) patients, while 22 patients had no mutations. In the latter cases, either epilepsy was of non-hereditary nature or the tested nucleotide sequence was located in the non-coding part of the gene (intron); in addition, a chromosomal rearrangement could be involved.Conclusion. The obtained data illustrate a diagnostic significance of the whole exome sequencing and encourage the interaction between an epileptologist and a geneticist in the diagnostic procedure. Identification of the genetic base of the disease is of great importance for genetic counseling and for selecting an antiepileptic therapy in this group of patients.The authors declare about the absence of conflict of interest with respect to this publication. Authors contributed equally to this article.https://www.epilepsia.su/jour/article/view/504epilepsyepileptic encephalopathyexome sequencinggenetic counselingantiepileptic therapy
spellingShingle T. V. Kozhanova
S. S. Zhilina
T. I. Meshheryakova
K. V. Osipova
S. O. Ayvazyan
A. G. Prityko
Significance of exome sequencing for diagnosis of epilepsy in children
Эпилепсия и пароксизмальные состояния
epilepsy
epileptic encephalopathy
exome sequencing
genetic counseling
antiepileptic therapy
title Significance of exome sequencing for diagnosis of epilepsy in children
title_full Significance of exome sequencing for diagnosis of epilepsy in children
title_fullStr Significance of exome sequencing for diagnosis of epilepsy in children
title_full_unstemmed Significance of exome sequencing for diagnosis of epilepsy in children
title_short Significance of exome sequencing for diagnosis of epilepsy in children
title_sort significance of exome sequencing for diagnosis of epilepsy in children
topic epilepsy
epileptic encephalopathy
exome sequencing
genetic counseling
antiepileptic therapy
url https://www.epilepsia.su/jour/article/view/504
work_keys_str_mv AT tvkozhanova significanceofexomesequencingfordiagnosisofepilepsyinchildren
AT sszhilina significanceofexomesequencingfordiagnosisofepilepsyinchildren
AT timeshheryakova significanceofexomesequencingfordiagnosisofepilepsyinchildren
AT kvosipova significanceofexomesequencingfordiagnosisofepilepsyinchildren
AT soayvazyan significanceofexomesequencingfordiagnosisofepilepsyinchildren
AT agprityko significanceofexomesequencingfordiagnosisofepilepsyinchildren