Successful Management of Blue Rubber Bleb Nevus Syndrome (BRBNS) with Sirolimus

Blue rubber bleb nevus syndrome (BRBNS) is a rare disease with vascular malformations in several systems of the body, most commonly the skin and gastrointestinal tract. Bleeding from the gastrointestinal (GI) tract is a major complication, which may lead to chronic iron deficiency anemia and the nee...

Full description

Saved in:
Bibliographic Details
Main Authors: Ugochi O. Ogu, Ghada Abusin, Rolla F. Abu-Arja, Janice M. Staber
Format: Article
Language:English
Published: Wiley 2018-01-01
Series:Case Reports in Pediatrics
Online Access:http://dx.doi.org/10.1155/2018/7654278
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1850165979912339456
author Ugochi O. Ogu
Ghada Abusin
Rolla F. Abu-Arja
Janice M. Staber
author_facet Ugochi O. Ogu
Ghada Abusin
Rolla F. Abu-Arja
Janice M. Staber
author_sort Ugochi O. Ogu
collection DOAJ
description Blue rubber bleb nevus syndrome (BRBNS) is a rare disease with vascular malformations in several systems of the body, most commonly the skin and gastrointestinal tract. Bleeding from the gastrointestinal (GI) tract is a major complication, which may lead to chronic iron deficiency anemia and the need for frequent blood transfusions due to ongoing gastrointestinal blood loss. In this case report, we describe a now 19-year-old female with BRBNS who required six blood transfusions per year and after starting sirolimus is symptom- and transfusion-free.
format Article
id doaj-art-daf82d5de6f249439ebe7dd842e9bf36
institution OA Journals
issn 2090-6803
2090-6811
language English
publishDate 2018-01-01
publisher Wiley
record_format Article
series Case Reports in Pediatrics
spelling doaj-art-daf82d5de6f249439ebe7dd842e9bf362025-08-20T02:21:35ZengWileyCase Reports in Pediatrics2090-68032090-68112018-01-01201810.1155/2018/76542787654278Successful Management of Blue Rubber Bleb Nevus Syndrome (BRBNS) with SirolimusUgochi O. Ogu0Ghada Abusin1Rolla F. Abu-Arja2Janice M. Staber3Division of Hematology, Department of Oncology, Montefiore Medical Center, Bronx, NY, USADivision of Pediatric Hematology/Oncology, Department of Pediatrics, University of Michigan, Ann Arbor, MI, USADivision of Pediatric Hematology/Oncology/BMT, Nationwide Children’s Hospital, Columbus, OH, USADivision of Pediatric Hematology/Oncology, Stead Family Department of Pediatrics, University of Iowa Carver College of Medicine, Iowa City, IA, USABlue rubber bleb nevus syndrome (BRBNS) is a rare disease with vascular malformations in several systems of the body, most commonly the skin and gastrointestinal tract. Bleeding from the gastrointestinal (GI) tract is a major complication, which may lead to chronic iron deficiency anemia and the need for frequent blood transfusions due to ongoing gastrointestinal blood loss. In this case report, we describe a now 19-year-old female with BRBNS who required six blood transfusions per year and after starting sirolimus is symptom- and transfusion-free.http://dx.doi.org/10.1155/2018/7654278
spellingShingle Ugochi O. Ogu
Ghada Abusin
Rolla F. Abu-Arja
Janice M. Staber
Successful Management of Blue Rubber Bleb Nevus Syndrome (BRBNS) with Sirolimus
Case Reports in Pediatrics
title Successful Management of Blue Rubber Bleb Nevus Syndrome (BRBNS) with Sirolimus
title_full Successful Management of Blue Rubber Bleb Nevus Syndrome (BRBNS) with Sirolimus
title_fullStr Successful Management of Blue Rubber Bleb Nevus Syndrome (BRBNS) with Sirolimus
title_full_unstemmed Successful Management of Blue Rubber Bleb Nevus Syndrome (BRBNS) with Sirolimus
title_short Successful Management of Blue Rubber Bleb Nevus Syndrome (BRBNS) with Sirolimus
title_sort successful management of blue rubber bleb nevus syndrome brbns with sirolimus
url http://dx.doi.org/10.1155/2018/7654278
work_keys_str_mv AT ugochioogu successfulmanagementofbluerubberblebnevussyndromebrbnswithsirolimus
AT ghadaabusin successfulmanagementofbluerubberblebnevussyndromebrbnswithsirolimus
AT rollafabuarja successfulmanagementofbluerubberblebnevussyndromebrbnswithsirolimus
AT janicemstaber successfulmanagementofbluerubberblebnevussyndromebrbnswithsirolimus