Subacute Mastoiditis Without Verified Nontuberculous Mycobacteria—Still a Clinical Challenge

ABSTRACT Objective An indolent form of mastoiditis has gained increased attention lately, challenging clinicians both regarding diagnosis as well as treatment. The etiology behind this assumed infection herein named subacute mastoiditis (SAM) is unknown; however, a link to nontuberculous mycobacteri...

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Main Authors: Lara Kakabas, Anna Granath, Kaijsa Edholm, Julia Arebro
Format: Article
Language:English
Published: Wiley 2025-06-01
Series:Laryngoscope Investigative Otolaryngology
Subjects:
Online Access:https://doi.org/10.1002/lio2.70183
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author Lara Kakabas
Anna Granath
Kaijsa Edholm
Julia Arebro
author_facet Lara Kakabas
Anna Granath
Kaijsa Edholm
Julia Arebro
author_sort Lara Kakabas
collection DOAJ
description ABSTRACT Objective An indolent form of mastoiditis has gained increased attention lately, challenging clinicians both regarding diagnosis as well as treatment. The etiology behind this assumed infection herein named subacute mastoiditis (SAM) is unknown; however, a link to nontuberculous mycobacteria (NTM) infections has been seen. A survey on pediatric cases with SAM over 20 years was performed to investigate the typical clinical features and to identify optimal treatment strategies for this condition, causing aggressive temporal bone destructions along with intratemporal and intracranial complications. Methods A retrospective survey of pediatric patients (0–17 years) hospitalized with SAM during 2003–2023 at Karolinska University Hospital, Sweden, was conducted. Data collection included demographics, diagnostics (radiology, microbiology, histopathology), treatment, and clinical outcome. Results Sixteen cases (median age 7.5 years) with SAM were included. Longstanding otorrhea from ventilation tubes preceded clinical signs of mastoiditis in most cases. CT scan generally revealed cortical temporal bone destructions close to the ear canal and sigmoid sinus. Histopathological examination displayed a high incidence of granulomatous inflammation. Upon microbiological testing, six cases revealed NTM infection. All cases underwent mastoidectomy, and 11 cases received long‐term mycobacteria‐targeted antibiotics. No deaths occurred, but seven cases had a delayed recovery or relapsing disease, and several cases experienced complications. The long‐term outcomes were good. Two cases with Mycobacterium tuberculosis mastoiditis were identified, entailing diagnostic challenges. Conclusion Histopathological and microbiological sampling along with CT scan is crucial in diagnosing SAM. We suggest surgical intervention combined with empirical long‐term antimycobacterial treatment for optimal recovery and outcome in SAM. Level of Evidence 4
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spelling doaj-art-d9189653c45545d8bea4e59e1f78e9ff2025-08-20T03:30:04ZengWileyLaryngoscope Investigative Otolaryngology2378-80382025-06-01103n/an/a10.1002/lio2.70183Subacute Mastoiditis Without Verified Nontuberculous Mycobacteria—Still a Clinical ChallengeLara Kakabas0Anna Granath1Kaijsa Edholm2Julia Arebro3Division of Otorhinolaryngology, Department of Clinical Science, Intervention and Technology Karolinska Institutet Stockholm SwedenDivision of Otorhinolaryngology, Department of Clinical Science, Intervention and Technology Karolinska Institutet Stockholm SwedenDepartment of Neuroradiology Karolinska University Hospital Stockholm SwedenDivision of Otorhinolaryngology, Department of Clinical Science, Intervention and Technology Karolinska Institutet Stockholm SwedenABSTRACT Objective An indolent form of mastoiditis has gained increased attention lately, challenging clinicians both regarding diagnosis as well as treatment. The etiology behind this assumed infection herein named subacute mastoiditis (SAM) is unknown; however, a link to nontuberculous mycobacteria (NTM) infections has been seen. A survey on pediatric cases with SAM over 20 years was performed to investigate the typical clinical features and to identify optimal treatment strategies for this condition, causing aggressive temporal bone destructions along with intratemporal and intracranial complications. Methods A retrospective survey of pediatric patients (0–17 years) hospitalized with SAM during 2003–2023 at Karolinska University Hospital, Sweden, was conducted. Data collection included demographics, diagnostics (radiology, microbiology, histopathology), treatment, and clinical outcome. Results Sixteen cases (median age 7.5 years) with SAM were included. Longstanding otorrhea from ventilation tubes preceded clinical signs of mastoiditis in most cases. CT scan generally revealed cortical temporal bone destructions close to the ear canal and sigmoid sinus. Histopathological examination displayed a high incidence of granulomatous inflammation. Upon microbiological testing, six cases revealed NTM infection. All cases underwent mastoidectomy, and 11 cases received long‐term mycobacteria‐targeted antibiotics. No deaths occurred, but seven cases had a delayed recovery or relapsing disease, and several cases experienced complications. The long‐term outcomes were good. Two cases with Mycobacterium tuberculosis mastoiditis were identified, entailing diagnostic challenges. Conclusion Histopathological and microbiological sampling along with CT scan is crucial in diagnosing SAM. We suggest surgical intervention combined with empirical long‐term antimycobacterial treatment for optimal recovery and outcome in SAM. Level of Evidence 4https://doi.org/10.1002/lio2.70183Mycobacterium tuberculosisnontuberculous mycobacteriapediatricsubacute mastoiditisventilation tube
spellingShingle Lara Kakabas
Anna Granath
Kaijsa Edholm
Julia Arebro
Subacute Mastoiditis Without Verified Nontuberculous Mycobacteria—Still a Clinical Challenge
Laryngoscope Investigative Otolaryngology
Mycobacterium tuberculosis
nontuberculous mycobacteria
pediatric
subacute mastoiditis
ventilation tube
title Subacute Mastoiditis Without Verified Nontuberculous Mycobacteria—Still a Clinical Challenge
title_full Subacute Mastoiditis Without Verified Nontuberculous Mycobacteria—Still a Clinical Challenge
title_fullStr Subacute Mastoiditis Without Verified Nontuberculous Mycobacteria—Still a Clinical Challenge
title_full_unstemmed Subacute Mastoiditis Without Verified Nontuberculous Mycobacteria—Still a Clinical Challenge
title_short Subacute Mastoiditis Without Verified Nontuberculous Mycobacteria—Still a Clinical Challenge
title_sort subacute mastoiditis without verified nontuberculous mycobacteria still a clinical challenge
topic Mycobacterium tuberculosis
nontuberculous mycobacteria
pediatric
subacute mastoiditis
ventilation tube
url https://doi.org/10.1002/lio2.70183
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