Case Report: Tattoo sarcoidosis with epithelioid cell granuloma positive for Propionibacterium acnes

IntroductionTattoo sarcoidosis is characterized by a granulomatous reaction localized to the tattoo site and typical systemic symptoms of sarcoidosis. Herein, we report the case of a patient diagnosed with tattoo sarcoidosis.Case reportA 28-year-old man presented with subcutaneous nodules at two tat...

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Main Authors: Yuiko Masuda, Hiroko Okabayashi, Kimitaka Akaike, Shohei Hamada, Aiko Masunaga, Hidenori Ichiyasu, Kenichi Ohashi, Takuro Sakagami
Format: Article
Language:English
Published: Frontiers Media S.A. 2025-03-01
Series:Frontiers in Medicine
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Online Access:https://www.frontiersin.org/articles/10.3389/fmed.2025.1552114/full
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author Yuiko Masuda
Hiroko Okabayashi
Kimitaka Akaike
Shohei Hamada
Aiko Masunaga
Hidenori Ichiyasu
Kenichi Ohashi
Takuro Sakagami
author_facet Yuiko Masuda
Hiroko Okabayashi
Kimitaka Akaike
Shohei Hamada
Aiko Masunaga
Hidenori Ichiyasu
Kenichi Ohashi
Takuro Sakagami
author_sort Yuiko Masuda
collection DOAJ
description IntroductionTattoo sarcoidosis is characterized by a granulomatous reaction localized to the tattoo site and typical systemic symptoms of sarcoidosis. Herein, we report the case of a patient diagnosed with tattoo sarcoidosis.Case reportA 28-year-old man presented with subcutaneous nodules at two tattoo sites, bilateral hilar and mediastinal lymphadenopathy, multiple micronodules predominantly in the upper lobes of both lungs, elevated serum angiotensin-converting enzyme and soluble interleukin-2 receptor levels, hypercalcemia, and renal dysfunction. Skin biopsy of a subcutaneous nodule revealed epithelioid cell granulomas. Although periodic acid-Schiff, Grocott methenamine silver, and acid-fast staining showed negative results, antibody staining for Propionibacterium acnes within the epithelioid cell granuloma was positive. Remarkably, all lesions spontaneously resolved, and the systemic manifestations also improved without medical treatment.ConclusionThe pathogenesis of tattoo sarcoidosis remains unknown, although an immune response to tattoo pigments has been suspected. However, there is a theory that P. acnes is the causative agent of sarcoidosis. In the present case, the detection of P. acnes within the epithelioid cell granuloma suggests that the bacterium may play a role in the etiology of tattoo sarcoidosis.
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publisher Frontiers Media S.A.
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spelling doaj-art-d8cd737ff0c74c76b77cfaa6d2cdbab62025-08-20T03:02:37ZengFrontiers Media S.A.Frontiers in Medicine2296-858X2025-03-011210.3389/fmed.2025.15521141552114Case Report: Tattoo sarcoidosis with epithelioid cell granuloma positive for Propionibacterium acnesYuiko Masuda0Hiroko Okabayashi1Kimitaka Akaike2Shohei Hamada3Aiko Masunaga4Hidenori Ichiyasu5Kenichi Ohashi6Takuro Sakagami7Department of Respiratory Medicine, Kumamoto University Hospital, Faculty of Life, Sciences, Kumamoto University, Kumamoto, JapanDepartment of Respiratory Medicine, Kumamoto University Hospital, Faculty of Life, Sciences, Kumamoto University, Kumamoto, JapanDepartment of Respiratory Medicine, Kumamoto University Hospital, Faculty of Life, Sciences, Kumamoto University, Kumamoto, JapanDepartment of Respiratory Medicine, Kumamoto University Hospital, Faculty of Life, Sciences, Kumamoto University, Kumamoto, JapanDepartment of Respiratory Medicine, Kumamoto University Hospital, Faculty of Life, Sciences, Kumamoto University, Kumamoto, JapanDepartment of Respiratory Medicine, Kumamoto University Hospital, Faculty of Life, Sciences, Kumamoto University, Kumamoto, JapanDepartment of Human Pathology, Institute of Science Tokyo, Tokyo, JapanDepartment of Respiratory Medicine, Kumamoto University Hospital, Faculty of Life, Sciences, Kumamoto University, Kumamoto, JapanIntroductionTattoo sarcoidosis is characterized by a granulomatous reaction localized to the tattoo site and typical systemic symptoms of sarcoidosis. Herein, we report the case of a patient diagnosed with tattoo sarcoidosis.Case reportA 28-year-old man presented with subcutaneous nodules at two tattoo sites, bilateral hilar and mediastinal lymphadenopathy, multiple micronodules predominantly in the upper lobes of both lungs, elevated serum angiotensin-converting enzyme and soluble interleukin-2 receptor levels, hypercalcemia, and renal dysfunction. Skin biopsy of a subcutaneous nodule revealed epithelioid cell granulomas. Although periodic acid-Schiff, Grocott methenamine silver, and acid-fast staining showed negative results, antibody staining for Propionibacterium acnes within the epithelioid cell granuloma was positive. Remarkably, all lesions spontaneously resolved, and the systemic manifestations also improved without medical treatment.ConclusionThe pathogenesis of tattoo sarcoidosis remains unknown, although an immune response to tattoo pigments has been suspected. However, there is a theory that P. acnes is the causative agent of sarcoidosis. In the present case, the detection of P. acnes within the epithelioid cell granuloma suggests that the bacterium may play a role in the etiology of tattoo sarcoidosis.https://www.frontiersin.org/articles/10.3389/fmed.2025.1552114/fulltattoo sarcoidosissarcoidosistattooPropionibacterium acnesCutibacterium acnes
spellingShingle Yuiko Masuda
Hiroko Okabayashi
Kimitaka Akaike
Shohei Hamada
Aiko Masunaga
Hidenori Ichiyasu
Kenichi Ohashi
Takuro Sakagami
Case Report: Tattoo sarcoidosis with epithelioid cell granuloma positive for Propionibacterium acnes
Frontiers in Medicine
tattoo sarcoidosis
sarcoidosis
tattoo
Propionibacterium acnes
Cutibacterium acnes
title Case Report: Tattoo sarcoidosis with epithelioid cell granuloma positive for Propionibacterium acnes
title_full Case Report: Tattoo sarcoidosis with epithelioid cell granuloma positive for Propionibacterium acnes
title_fullStr Case Report: Tattoo sarcoidosis with epithelioid cell granuloma positive for Propionibacterium acnes
title_full_unstemmed Case Report: Tattoo sarcoidosis with epithelioid cell granuloma positive for Propionibacterium acnes
title_short Case Report: Tattoo sarcoidosis with epithelioid cell granuloma positive for Propionibacterium acnes
title_sort case report tattoo sarcoidosis with epithelioid cell granuloma positive for propionibacterium acnes
topic tattoo sarcoidosis
sarcoidosis
tattoo
Propionibacterium acnes
Cutibacterium acnes
url https://www.frontiersin.org/articles/10.3389/fmed.2025.1552114/full
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