Primary Cutaneous T-Cell Lymphoblastic Lymphoma: Case Report and Literature Review

Cutaneous involvement by precursor T-cell lymphoblastic leukemia/lymphoma (T-ALL/LBL) is rare, and almost all cases are seen in association with bone marrow, blood, and/or lymph node involvement. Presentation with isolated skin involvement is very rare. Literature review revealed only one case repor...

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Main Authors: Sharad Khurana, Manuel Beltran, Liuyan Jiang, Ernesto Ayala, Vivek Roy
Format: Article
Language:English
Published: Wiley 2019-01-01
Series:Case Reports in Hematology
Online Access:http://dx.doi.org/10.1155/2019/3540487
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author Sharad Khurana
Manuel Beltran
Liuyan Jiang
Ernesto Ayala
Vivek Roy
author_facet Sharad Khurana
Manuel Beltran
Liuyan Jiang
Ernesto Ayala
Vivek Roy
author_sort Sharad Khurana
collection DOAJ
description Cutaneous involvement by precursor T-cell lymphoblastic leukemia/lymphoma (T-ALL/LBL) is rare, and almost all cases are seen in association with bone marrow, blood, and/or lymph node involvement. Presentation with isolated skin involvement is very rare. Literature review revealed only one case report of primary cutaneous T-cell LBL. We discuss here another patient diagnosed with primary cutaneous T-cell LBL at our institute. This patient was initially misdiagnosed as having peripheral T-cell lymphoma NOS. Cytogenetic analysis showed the CDKN2A deletion (−9p21×2) in addition to three intact copies of ABL1 (+9q34). Although she failed multiple lines of intensive chemotherapy, her disease remained confined to the skin. We believe that this presentation of T-LBL is underreported, and many patients are likely misdiagnosed as having high-grade cutaneous T-cell lymphomas. With this case and literature review, we would like to highlight the importance of keeping lymphoblastic lymphoma on the differential diagnosis of cutaneous T-cell lymphoma-like lesions to avoid delay in diagnosis and inappropriate treatment of this aggressive disease.
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spelling doaj-art-d8022ef67fbc43108ca71a8410175da92025-08-20T03:23:52ZengWileyCase Reports in Hematology2090-65602090-65792019-01-01201910.1155/2019/35404873540487Primary Cutaneous T-Cell Lymphoblastic Lymphoma: Case Report and Literature ReviewSharad Khurana0Manuel Beltran1Liuyan Jiang2Ernesto Ayala3Vivek Roy4Mayo Clinic, Jacksonville, FL, USAMayo Clinic, Jacksonville, FL, USAMayo Clinic, Jacksonville, FL, USAMayo Clinic, Jacksonville, FL, USAMayo Clinic, Jacksonville, FL, USACutaneous involvement by precursor T-cell lymphoblastic leukemia/lymphoma (T-ALL/LBL) is rare, and almost all cases are seen in association with bone marrow, blood, and/or lymph node involvement. Presentation with isolated skin involvement is very rare. Literature review revealed only one case report of primary cutaneous T-cell LBL. We discuss here another patient diagnosed with primary cutaneous T-cell LBL at our institute. This patient was initially misdiagnosed as having peripheral T-cell lymphoma NOS. Cytogenetic analysis showed the CDKN2A deletion (−9p21×2) in addition to three intact copies of ABL1 (+9q34). Although she failed multiple lines of intensive chemotherapy, her disease remained confined to the skin. We believe that this presentation of T-LBL is underreported, and many patients are likely misdiagnosed as having high-grade cutaneous T-cell lymphomas. With this case and literature review, we would like to highlight the importance of keeping lymphoblastic lymphoma on the differential diagnosis of cutaneous T-cell lymphoma-like lesions to avoid delay in diagnosis and inappropriate treatment of this aggressive disease.http://dx.doi.org/10.1155/2019/3540487
spellingShingle Sharad Khurana
Manuel Beltran
Liuyan Jiang
Ernesto Ayala
Vivek Roy
Primary Cutaneous T-Cell Lymphoblastic Lymphoma: Case Report and Literature Review
Case Reports in Hematology
title Primary Cutaneous T-Cell Lymphoblastic Lymphoma: Case Report and Literature Review
title_full Primary Cutaneous T-Cell Lymphoblastic Lymphoma: Case Report and Literature Review
title_fullStr Primary Cutaneous T-Cell Lymphoblastic Lymphoma: Case Report and Literature Review
title_full_unstemmed Primary Cutaneous T-Cell Lymphoblastic Lymphoma: Case Report and Literature Review
title_short Primary Cutaneous T-Cell Lymphoblastic Lymphoma: Case Report and Literature Review
title_sort primary cutaneous t cell lymphoblastic lymphoma case report and literature review
url http://dx.doi.org/10.1155/2019/3540487
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AT manuelbeltran primarycutaneoustcelllymphoblasticlymphomacasereportandliteraturereview
AT liuyanjiang primarycutaneoustcelllymphoblasticlymphomacasereportandliteraturereview
AT ernestoayala primarycutaneoustcelllymphoblasticlymphomacasereportandliteraturereview
AT vivekroy primarycutaneoustcelllymphoblasticlymphomacasereportandliteraturereview