Dental amalgam associated with SAPHO syndrome and IgA nephropathy: a case report and literature review

Abstract Background Exposure to metals is associated with adverse health effects, including multiorgan damage and dysregulation of systemic immune responses. The increasing use of metallic implants in humans, such as dental materials and orthopedic devices, has resulted in chronic endogenous exposur...

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Main Authors: Yan Cai, Qingqing You, Weina Jiang, Xuyan Liu, Leping Shao
Format: Article
Language:English
Published: BMC 2025-06-01
Series:BMC Nephrology
Subjects:
Online Access:https://doi.org/10.1186/s12882-025-04208-x
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author Yan Cai
Qingqing You
Weina Jiang
Xuyan Liu
Leping Shao
author_facet Yan Cai
Qingqing You
Weina Jiang
Xuyan Liu
Leping Shao
author_sort Yan Cai
collection DOAJ
description Abstract Background Exposure to metals is associated with adverse health effects, including multiorgan damage and dysregulation of systemic immune responses. The increasing use of metallic implants in humans, such as dental materials and orthopedic devices, has resulted in chronic endogenous exposure to metal ions. The pathophysiological mechanisms underlying implant-related complications and their clinical implications have not been fully elucidated. Case presentation We present a case of synovitis, acne, pustulosis, hyperostosis, and osteitis (SAPHO) syndrome coexisting with IgA nephropathy (IgAN) in the context of dental amalgam exposure. Following amalgam placement, the patient developed palmoplantar pustulosis (PPP) and sternoclavicular arthritis, with a subsequent diagnosis of IgAN. Notably, all the clinical manifestations were markedly resolved after amalgam removal. Conclusion This case suggests a potential link between SAPHO syndrome, IgAN, and dental amalgam exposure. To our knowledge, this is the first reported case linking these conditions. Further studies are needed to elucidate the mechanisms and clinical implications of metal-induced autoimmune or inflammatory responses. Clinical trial number Not applicable.
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institution Kabale University
issn 1471-2369
language English
publishDate 2025-06-01
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series BMC Nephrology
spelling doaj-art-d54955c1a2364385ba9232bfa2bf59142025-08-20T03:47:24ZengBMCBMC Nephrology1471-23692025-06-012611910.1186/s12882-025-04208-xDental amalgam associated with SAPHO syndrome and IgA nephropathy: a case report and literature reviewYan Cai0Qingqing You1Weina Jiang2Xuyan Liu3Leping Shao4Department of Nephrology, Qingdao Municipal Hospital, University of Health and Rehabilitation SciencesDepartment of Nephrology, Qingdao Municipal Hospital, University of Health and Rehabilitation SciencesDepartment of Pathology, Qingdao Municipal Hospital, University of Health and Rehabilitation SciencesDepartment of Nephrology, The Affiliated Qingdao Municipal Hospital of Qingdao UniversityDepartment of Nephrology (Fujian Provincial Clinical Research Center for Glomerular Nephritis), The First Affiliated Hospital of Xiamen University, School of Medicine, Xiamen UniversityAbstract Background Exposure to metals is associated with adverse health effects, including multiorgan damage and dysregulation of systemic immune responses. The increasing use of metallic implants in humans, such as dental materials and orthopedic devices, has resulted in chronic endogenous exposure to metal ions. The pathophysiological mechanisms underlying implant-related complications and their clinical implications have not been fully elucidated. Case presentation We present a case of synovitis, acne, pustulosis, hyperostosis, and osteitis (SAPHO) syndrome coexisting with IgA nephropathy (IgAN) in the context of dental amalgam exposure. Following amalgam placement, the patient developed palmoplantar pustulosis (PPP) and sternoclavicular arthritis, with a subsequent diagnosis of IgAN. Notably, all the clinical manifestations were markedly resolved after amalgam removal. Conclusion This case suggests a potential link between SAPHO syndrome, IgAN, and dental amalgam exposure. To our knowledge, this is the first reported case linking these conditions. Further studies are needed to elucidate the mechanisms and clinical implications of metal-induced autoimmune or inflammatory responses. Clinical trial number Not applicable.https://doi.org/10.1186/s12882-025-04208-xDental amalgamMetalSAPHO syndromeIgA nephropathy
spellingShingle Yan Cai
Qingqing You
Weina Jiang
Xuyan Liu
Leping Shao
Dental amalgam associated with SAPHO syndrome and IgA nephropathy: a case report and literature review
BMC Nephrology
Dental amalgam
Metal
SAPHO syndrome
IgA nephropathy
title Dental amalgam associated with SAPHO syndrome and IgA nephropathy: a case report and literature review
title_full Dental amalgam associated with SAPHO syndrome and IgA nephropathy: a case report and literature review
title_fullStr Dental amalgam associated with SAPHO syndrome and IgA nephropathy: a case report and literature review
title_full_unstemmed Dental amalgam associated with SAPHO syndrome and IgA nephropathy: a case report and literature review
title_short Dental amalgam associated with SAPHO syndrome and IgA nephropathy: a case report and literature review
title_sort dental amalgam associated with sapho syndrome and iga nephropathy a case report and literature review
topic Dental amalgam
Metal
SAPHO syndrome
IgA nephropathy
url https://doi.org/10.1186/s12882-025-04208-x
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AT qingqingyou dentalamalgamassociatedwithsaphosyndromeandiganephropathyacasereportandliteraturereview
AT weinajiang dentalamalgamassociatedwithsaphosyndromeandiganephropathyacasereportandliteraturereview
AT xuyanliu dentalamalgamassociatedwithsaphosyndromeandiganephropathyacasereportandliteraturereview
AT lepingshao dentalamalgamassociatedwithsaphosyndromeandiganephropathyacasereportandliteraturereview