The landscape of human mutually exclusive splicing

Abstract Mutually exclusive splicing of exons is a mechanism of functional gene and protein diversification with pivotal roles in organismal development and diseases such as Timothy syndrome, cardiomyopathy and cancer in humans. In order to obtain a first genomewide estimate of the extent and biolog...

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Main Authors: Klas Hatje, Raza‐Ur Rahman, Ramon O Vidal, Dominic Simm, Björn Hammesfahr, Vikas Bansal, Ashish Rajput, Michel Edwar Mickael, Ting Sun, Stefan Bonn, Martin Kollmar
Format: Article
Language:English
Published: Springer Nature 2017-12-01
Series:Molecular Systems Biology
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Online Access:https://doi.org/10.15252/msb.20177728
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author Klas Hatje
Raza‐Ur Rahman
Ramon O Vidal
Dominic Simm
Björn Hammesfahr
Vikas Bansal
Ashish Rajput
Michel Edwar Mickael
Ting Sun
Stefan Bonn
Martin Kollmar
author_facet Klas Hatje
Raza‐Ur Rahman
Ramon O Vidal
Dominic Simm
Björn Hammesfahr
Vikas Bansal
Ashish Rajput
Michel Edwar Mickael
Ting Sun
Stefan Bonn
Martin Kollmar
author_sort Klas Hatje
collection DOAJ
description Abstract Mutually exclusive splicing of exons is a mechanism of functional gene and protein diversification with pivotal roles in organismal development and diseases such as Timothy syndrome, cardiomyopathy and cancer in humans. In order to obtain a first genomewide estimate of the extent and biological role of mutually exclusive splicing in humans, we predicted and subsequently validated mutually exclusive exons (MXEs) using 515 publically available RNA‐Seq datasets. Here, we provide evidence for the expression of over 855 MXEs, 42% of which represent novel exons, increasing the annotated human mutually exclusive exome more than fivefold. The data provide strong evidence for the existence of large and multi‐cluster MXEs in higher vertebrates and offer new insights into MXE evolution. More than 82% of the MXE clusters are conserved in mammals, and five clusters have homologous clusters in Drosophila. Finally, MXEs are significantly enriched in pathogenic mutations and their spatio‐temporal expression might predict human disease pathology.
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series Molecular Systems Biology
spelling doaj-art-d02e32155ae344f0aeb8d5b8bbe64ef02025-08-20T03:46:37ZengSpringer NatureMolecular Systems Biology1744-42922017-12-01131211910.15252/msb.20177728The landscape of human mutually exclusive splicingKlas Hatje0Raza‐Ur Rahman1Ramon O Vidal2Dominic Simm3Björn Hammesfahr4Vikas Bansal5Ashish Rajput6Michel Edwar Mickael7Ting Sun8Stefan Bonn9Martin Kollmar10Group Systems Biology of Motor Proteins, Department of NMR‐Based Structural Biology, Max‐Planck‐Institute for Biophysical ChemistryGroup of Computational Systems Biology, German Center for Neurodegenerative DiseasesGroup of Computational Systems Biology, German Center for Neurodegenerative DiseasesGroup Systems Biology of Motor Proteins, Department of NMR‐Based Structural Biology, Max‐Planck‐Institute for Biophysical ChemistryGroup Systems Biology of Motor Proteins, Department of NMR‐Based Structural Biology, Max‐Planck‐Institute for Biophysical ChemistryGroup of Computational Systems Biology, German Center for Neurodegenerative DiseasesGroup of Computational Systems Biology, German Center for Neurodegenerative DiseasesGroup of Computational Systems Biology, German Center for Neurodegenerative DiseasesGroup of Computational Systems Biology, German Center for Neurodegenerative DiseasesGroup of Computational Systems Biology, German Center for Neurodegenerative DiseasesGroup Systems Biology of Motor Proteins, Department of NMR‐Based Structural Biology, Max‐Planck‐Institute for Biophysical ChemistryAbstract Mutually exclusive splicing of exons is a mechanism of functional gene and protein diversification with pivotal roles in organismal development and diseases such as Timothy syndrome, cardiomyopathy and cancer in humans. In order to obtain a first genomewide estimate of the extent and biological role of mutually exclusive splicing in humans, we predicted and subsequently validated mutually exclusive exons (MXEs) using 515 publically available RNA‐Seq datasets. Here, we provide evidence for the expression of over 855 MXEs, 42% of which represent novel exons, increasing the annotated human mutually exclusive exome more than fivefold. The data provide strong evidence for the existence of large and multi‐cluster MXEs in higher vertebrates and offer new insights into MXE evolution. More than 82% of the MXE clusters are conserved in mammals, and five clusters have homologous clusters in Drosophila. Finally, MXEs are significantly enriched in pathogenic mutations and their spatio‐temporal expression might predict human disease pathology.https://doi.org/10.15252/msb.20177728alternative splicingdifferential expressionmutually exclusive splicingsplicing mechanisms
spellingShingle Klas Hatje
Raza‐Ur Rahman
Ramon O Vidal
Dominic Simm
Björn Hammesfahr
Vikas Bansal
Ashish Rajput
Michel Edwar Mickael
Ting Sun
Stefan Bonn
Martin Kollmar
The landscape of human mutually exclusive splicing
Molecular Systems Biology
alternative splicing
differential expression
mutually exclusive splicing
splicing mechanisms
title The landscape of human mutually exclusive splicing
title_full The landscape of human mutually exclusive splicing
title_fullStr The landscape of human mutually exclusive splicing
title_full_unstemmed The landscape of human mutually exclusive splicing
title_short The landscape of human mutually exclusive splicing
title_sort landscape of human mutually exclusive splicing
topic alternative splicing
differential expression
mutually exclusive splicing
splicing mechanisms
url https://doi.org/10.15252/msb.20177728
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