Feasibility, safety and tolerability of the CREB-binding protein/β-catenin inhibitor OP-724 in patients with advanced primary biliary cholangitis: an investigator-initiated, open-label, non-randomised, two-centre, phase 1 study

Objective This study aimed to evaluate the safety and tolerability of OP-724, a CREB-binding protein/β-catenin inhibitor, in patients with advanced primary biliary cholangitis (PBC).Design An open-label, non-randomised, phase 1 trial was conducted at two hospitals in Japan. Patients with advanced PB...

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Main Authors: Eiichi Ogawa, Atsushi Tanaka, Kenichi Harada, Hiroshi Yatsuhashi, Kazumoto Murata, Masamichi Kimura, Jun Imamura, Masanao Saio, Yoshihiro Ikura, Kouichi Miura, Ichiro Ieiri, Kiminori Kimura
Format: Article
Language:English
Published: BMJ Publishing Group 2022-10-01
Series:BMJ Open Gastroenterology
Online Access:https://bmjopengastro.bmj.com/content/9/1/e001001.full
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author Eiichi Ogawa
Atsushi Tanaka
Kenichi Harada
Hiroshi Yatsuhashi
Kazumoto Murata
Masamichi Kimura
Jun Imamura
Masanao Saio
Yoshihiro Ikura
Kouichi Miura
Ichiro Ieiri
Kiminori Kimura
author_facet Eiichi Ogawa
Atsushi Tanaka
Kenichi Harada
Hiroshi Yatsuhashi
Kazumoto Murata
Masamichi Kimura
Jun Imamura
Masanao Saio
Yoshihiro Ikura
Kouichi Miura
Ichiro Ieiri
Kiminori Kimura
author_sort Eiichi Ogawa
collection DOAJ
description Objective This study aimed to evaluate the safety and tolerability of OP-724, a CREB-binding protein/β-catenin inhibitor, in patients with advanced primary biliary cholangitis (PBC).Design An open-label, non-randomised, phase 1 trial was conducted at two hospitals in Japan. Patients with advanced PBC classified as stage III or higher according to the Scheuer classification by liver biopsy between 4 September 2019 and 21 September 2021 were enrolled. Seven patients received intravenous OP-724 infusions at escalating dosages of 280 and 380 mg/m2/4 hours two times weekly for 12 weeks. The primary endpoint was the incidence of serious adverse events (SAEs). The secondary endpoints were the incidence of AEs and the improvement in the modified Histological Activity Index (mHAI) score.Results Seven patients (median age, 68 years) were enrolled. Of these seven patients, five completed twelve cycles of treatment, one discontinued prematurely for personal reasons in the 280 mg/m2/4 hours cohort, and one in the 380 mg/m2/4 hours cohort was withdrawn from the study due to drug-induced liver injury (grade 2). Consequently, the recommended dosage was determined to be 280 mg/m2/4 hours. SAEs did not occur. The most common AEs were abdominal discomfort (29%) and abnormal hepatic function (43%). OP-724 treatment was associated with histological improvements in the fibrosis stage (2/5 (40%)) and mHAI score (3/5 (60%)) on histological analysis.Conclusion Administration of intravenous OP-724 infusion at a dosage of 280 mg/m2/4 hours two times weekly for 12 weeks was well tolerated by patients with advanced PBC. However, further evaluation of antifibrotic effects in patients with PBC is warranted.Trial registration number NCT04047160.
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spelling doaj-art-cabfe85f53b94df4a8a96a71c3bfa66f2025-08-20T03:45:14ZengBMJ Publishing GroupBMJ Open Gastroenterology2054-47742022-10-019110.1136/bmjgast-2022-001001Feasibility, safety and tolerability of the CREB-binding protein/β-catenin inhibitor OP-724 in patients with advanced primary biliary cholangitis: an investigator-initiated, open-label, non-randomised, two-centre, phase 1 studyEiichi Ogawa0Atsushi Tanaka1Kenichi Harada2Hiroshi Yatsuhashi3Kazumoto Murata4Masamichi Kimura5Jun Imamura6Masanao Saio7Yoshihiro Ikura8Kouichi Miura9Ichiro Ieiri10Kiminori Kimura11Department of General Internal Medicine, Kyushu University Hospital, Fukuoka, Japan6 Saint Mother Hospital Infertility Clinic, Kitakyushu, Fukuoka, JapanDepartment of Urology, University of Occupational and Environmental Health, Kitakyushu, JapanClinical Research Center, National Hospital Organisation Nagasaki Medical Center, Omura, Nagasaki, JapanDivision of Virology, Department of Infection and Immunity, Jichi Medical University School of Medicine Graduate School of Medicine, Shimotsuke, Tochigi, JapanDepartment of Hepatology, Tokyo Metropolitan Cancer and Infectious Diseases Center Komagome Hospital, Bunkyo-ku, Tokyo, JapanDepartment of Hepatology, Tokyo Metropolitan Cancer and Infectious Diseases Center Komagome Hospital, Bunkyo-ku, Tokyo, JapanDepartment of Laboratory Sciences, Gunma University Graduate School of Health Sciences, Maebashi, JapanDepartment of Pathology, Takatsuki General Hospital, Takatsuki, Osaka, JapanDivision of Gastroenterology, Department of Medicine, Jichi Medical University, Shimotsuke, Tochigi, JapanDepartment of Clinical Pharmacokinetics, Division of Clinical Pharmacy, Graduate School of Pharmaceutical Sciences, Kyushu University, Fukuoka, JapanDepartment of Hepatology, Tokyo Metropolitan Cancer and Infectious Diseases Center Komagome Hospital, Bunkyo-ku, Tokyo, JapanObjective This study aimed to evaluate the safety and tolerability of OP-724, a CREB-binding protein/β-catenin inhibitor, in patients with advanced primary biliary cholangitis (PBC).Design An open-label, non-randomised, phase 1 trial was conducted at two hospitals in Japan. Patients with advanced PBC classified as stage III or higher according to the Scheuer classification by liver biopsy between 4 September 2019 and 21 September 2021 were enrolled. Seven patients received intravenous OP-724 infusions at escalating dosages of 280 and 380 mg/m2/4 hours two times weekly for 12 weeks. The primary endpoint was the incidence of serious adverse events (SAEs). The secondary endpoints were the incidence of AEs and the improvement in the modified Histological Activity Index (mHAI) score.Results Seven patients (median age, 68 years) were enrolled. Of these seven patients, five completed twelve cycles of treatment, one discontinued prematurely for personal reasons in the 280 mg/m2/4 hours cohort, and one in the 380 mg/m2/4 hours cohort was withdrawn from the study due to drug-induced liver injury (grade 2). Consequently, the recommended dosage was determined to be 280 mg/m2/4 hours. SAEs did not occur. The most common AEs were abdominal discomfort (29%) and abnormal hepatic function (43%). OP-724 treatment was associated with histological improvements in the fibrosis stage (2/5 (40%)) and mHAI score (3/5 (60%)) on histological analysis.Conclusion Administration of intravenous OP-724 infusion at a dosage of 280 mg/m2/4 hours two times weekly for 12 weeks was well tolerated by patients with advanced PBC. However, further evaluation of antifibrotic effects in patients with PBC is warranted.Trial registration number NCT04047160.https://bmjopengastro.bmj.com/content/9/1/e001001.full
spellingShingle Eiichi Ogawa
Atsushi Tanaka
Kenichi Harada
Hiroshi Yatsuhashi
Kazumoto Murata
Masamichi Kimura
Jun Imamura
Masanao Saio
Yoshihiro Ikura
Kouichi Miura
Ichiro Ieiri
Kiminori Kimura
Feasibility, safety and tolerability of the CREB-binding protein/β-catenin inhibitor OP-724 in patients with advanced primary biliary cholangitis: an investigator-initiated, open-label, non-randomised, two-centre, phase 1 study
BMJ Open Gastroenterology
title Feasibility, safety and tolerability of the CREB-binding protein/β-catenin inhibitor OP-724 in patients with advanced primary biliary cholangitis: an investigator-initiated, open-label, non-randomised, two-centre, phase 1 study
title_full Feasibility, safety and tolerability of the CREB-binding protein/β-catenin inhibitor OP-724 in patients with advanced primary biliary cholangitis: an investigator-initiated, open-label, non-randomised, two-centre, phase 1 study
title_fullStr Feasibility, safety and tolerability of the CREB-binding protein/β-catenin inhibitor OP-724 in patients with advanced primary biliary cholangitis: an investigator-initiated, open-label, non-randomised, two-centre, phase 1 study
title_full_unstemmed Feasibility, safety and tolerability of the CREB-binding protein/β-catenin inhibitor OP-724 in patients with advanced primary biliary cholangitis: an investigator-initiated, open-label, non-randomised, two-centre, phase 1 study
title_short Feasibility, safety and tolerability of the CREB-binding protein/β-catenin inhibitor OP-724 in patients with advanced primary biliary cholangitis: an investigator-initiated, open-label, non-randomised, two-centre, phase 1 study
title_sort feasibility safety and tolerability of the creb binding protein β catenin inhibitor op 724 in patients with advanced primary biliary cholangitis an investigator initiated open label non randomised two centre phase 1 study
url https://bmjopengastro.bmj.com/content/9/1/e001001.full
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