Rapid enlargement of pulmonary benign metastasizing leiomyoma with fluid-containing cystic change: a case report

Abstract Background Pulmonary benign metastasizing leiomyoma (PBML) is a rare disease that can occur in women with a history of uterine leiomyoma. Despite its benign histological features, like a malignancy, leiomyomas can on rare occasion spread to the lung. Typically, PBML presents with asymptomat...

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Main Authors: Takahiro Yanagihara, Naohiro Kobayashi, Tomoyuki Kawamura, Shinji Kikuchi, Yukinobu Goto, Hideo Ichimura, Yukio Sato
Format: Article
Language:English
Published: Japan Surgical Society 2022-05-01
Series:Surgical Case Reports
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Online Access:https://doi.org/10.1186/s40792-022-01444-3
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author Takahiro Yanagihara
Naohiro Kobayashi
Tomoyuki Kawamura
Shinji Kikuchi
Yukinobu Goto
Hideo Ichimura
Yukio Sato
author_facet Takahiro Yanagihara
Naohiro Kobayashi
Tomoyuki Kawamura
Shinji Kikuchi
Yukinobu Goto
Hideo Ichimura
Yukio Sato
author_sort Takahiro Yanagihara
collection DOAJ
description Abstract Background Pulmonary benign metastasizing leiomyoma (PBML) is a rare disease that can occur in women with a history of uterine leiomyoma. Despite its benign histological features, like a malignancy, leiomyomas can on rare occasion spread to the lung. Typically, PBML presents with asymptomatic multiple solid lung nodules with slow tumor progression, following hysterectomy. Here, we present an atypical case with rapid enlargement of PBML with fluid-containing cystic change. Case presentation We experienced a case of a 49-year-old woman with bilateral lung nodules following hysterectomy. Two nodules in the right lung had cystic change with fluid in the tumors. Hormone therapy was initiated after surgical biopsy of the left lung confirmed a diagnosis of PBML. However, the cystic component of right upper lobe lesion enlarged rapidly over the following 7 months, and, considering the risk of malignant transformation or tumor rupture, right upper lobectomy was performed. Pathologically, the fluid-containing tumor was diagnosed as PBML. Conclusion Given the risk of rapid progression, we should carefully consider the surgical indications of fluid-containing PBML.
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institution Kabale University
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language English
publishDate 2022-05-01
publisher Japan Surgical Society
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series Surgical Case Reports
spelling doaj-art-c92a3d5824aa4d22a618d1daaca6e19b2025-08-20T03:36:06ZengJapan Surgical SocietySurgical Case Reports2198-77932022-05-01811510.1186/s40792-022-01444-3Rapid enlargement of pulmonary benign metastasizing leiomyoma with fluid-containing cystic change: a case reportTakahiro Yanagihara0Naohiro Kobayashi1Tomoyuki Kawamura2Shinji Kikuchi3Yukinobu Goto4Hideo Ichimura5Yukio Sato6Department of Thoracic Surgery, Faculty of Medicine, University of TsukubaDepartment of Thoracic Surgery, Faculty of Medicine, University of TsukubaDepartment of Thoracic Surgery, Faculty of Medicine, University of TsukubaDepartment of Thoracic Surgery, Faculty of Medicine, University of TsukubaDepartment of Thoracic Surgery, Faculty of Medicine, University of TsukubaDepartment of Thoracic Surgery, Faculty of Medicine, University of TsukubaDepartment of Thoracic Surgery, Faculty of Medicine, University of TsukubaAbstract Background Pulmonary benign metastasizing leiomyoma (PBML) is a rare disease that can occur in women with a history of uterine leiomyoma. Despite its benign histological features, like a malignancy, leiomyomas can on rare occasion spread to the lung. Typically, PBML presents with asymptomatic multiple solid lung nodules with slow tumor progression, following hysterectomy. Here, we present an atypical case with rapid enlargement of PBML with fluid-containing cystic change. Case presentation We experienced a case of a 49-year-old woman with bilateral lung nodules following hysterectomy. Two nodules in the right lung had cystic change with fluid in the tumors. Hormone therapy was initiated after surgical biopsy of the left lung confirmed a diagnosis of PBML. However, the cystic component of right upper lobe lesion enlarged rapidly over the following 7 months, and, considering the risk of malignant transformation or tumor rupture, right upper lobectomy was performed. Pathologically, the fluid-containing tumor was diagnosed as PBML. Conclusion Given the risk of rapid progression, we should carefully consider the surgical indications of fluid-containing PBML.https://doi.org/10.1186/s40792-022-01444-3Pulmonary benign metastasizing leiomyomaBenign metastasizing leiomyomaLeiomyomaCystic changeFluid-containing cystPulmonary metastasis
spellingShingle Takahiro Yanagihara
Naohiro Kobayashi
Tomoyuki Kawamura
Shinji Kikuchi
Yukinobu Goto
Hideo Ichimura
Yukio Sato
Rapid enlargement of pulmonary benign metastasizing leiomyoma with fluid-containing cystic change: a case report
Surgical Case Reports
Pulmonary benign metastasizing leiomyoma
Benign metastasizing leiomyoma
Leiomyoma
Cystic change
Fluid-containing cyst
Pulmonary metastasis
title Rapid enlargement of pulmonary benign metastasizing leiomyoma with fluid-containing cystic change: a case report
title_full Rapid enlargement of pulmonary benign metastasizing leiomyoma with fluid-containing cystic change: a case report
title_fullStr Rapid enlargement of pulmonary benign metastasizing leiomyoma with fluid-containing cystic change: a case report
title_full_unstemmed Rapid enlargement of pulmonary benign metastasizing leiomyoma with fluid-containing cystic change: a case report
title_short Rapid enlargement of pulmonary benign metastasizing leiomyoma with fluid-containing cystic change: a case report
title_sort rapid enlargement of pulmonary benign metastasizing leiomyoma with fluid containing cystic change a case report
topic Pulmonary benign metastasizing leiomyoma
Benign metastasizing leiomyoma
Leiomyoma
Cystic change
Fluid-containing cyst
Pulmonary metastasis
url https://doi.org/10.1186/s40792-022-01444-3
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