What is the optimal assessment of speech? A multicentre, international evaluation of speech assessment in 2500 patients with a cleft

Objectives Speech problems in patients with a cleft palate are often complex and multifactorial. Finding the optimal way of monitoring these problems is challenging. The International Consortium of Health Outcomes Measurement (ICHOM) has developed a set of standardised outcome measures at specific a...

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Main Authors: Anne Klassen, Irene Mathijssen, Maarten Koudstaal, Saranda Ombashi, Melissa Srijanti Kurniawan, Alexander Allori, Banafsheh Sharif-Askary, Carolyn Rogers-Vizena, Marie-Christine Franken, Aebele B Mink van der Molen, Sarah Lisa Versnel
Format: Article
Language:English
Published: BMJ Publishing Group 2023-12-01
Series:BMJ Open
Online Access:https://bmjopen.bmj.com/content/13/12/e071571.full
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author Anne Klassen
Irene Mathijssen
Maarten Koudstaal
Saranda Ombashi
Melissa Srijanti Kurniawan
Alexander Allori
Banafsheh Sharif-Askary
Carolyn Rogers-Vizena
Marie-Christine Franken
Aebele B Mink van der Molen
Sarah Lisa Versnel
author_facet Anne Klassen
Irene Mathijssen
Maarten Koudstaal
Saranda Ombashi
Melissa Srijanti Kurniawan
Alexander Allori
Banafsheh Sharif-Askary
Carolyn Rogers-Vizena
Marie-Christine Franken
Aebele B Mink van der Molen
Sarah Lisa Versnel
author_sort Anne Klassen
collection DOAJ
description Objectives Speech problems in patients with a cleft palate are often complex and multifactorial. Finding the optimal way of monitoring these problems is challenging. The International Consortium of Health Outcomes Measurement (ICHOM) has developed a set of standardised outcome measures at specific ages for patients with a cleft lip and/or palate, including measures of speech assessment. This study evaluates the type and timing of speech outcome measures currently included in this ICHOM Standard Set. Additionally, speech assessments in other cleft protocols and initiatives are discussed.Design, setting and participants An international, multicentre study was set up including centres from the USA and the Netherlands. Outcomes of clinical measures and Patient Reported Outcome Measures (PROMs) were collected retrospectively according to the ICHOM set. PROM data from a field test of the CLEFT-Q, a questionnaire developed and validated for patients with a cleft, were collected, including participants from countries with all sorts of income statuses, to examine the value of additional moments of measurement that are used in other cleft initiatives.Data from 2500 patients were included. Measured outcomes contained univariate regression analyses, trend analyses, t-tests, correlations and floor and ceiling effects.Results PROMs correlated low to moderate with clinical outcome measures. Clinical outcome measures correlated low to moderate with each other too. In contrast, two CLEFT-Q Scales correlated strongly with each other. All PROMs and the Percent Consonants Correct (PCC) showed an effect of age. In patients with an isolated cleft palate, a ceiling effect was found in the Intelligibility in Context Scale.Conclusion Recommendations for an optimal speech outcome assessment in cleft patients are made. Measurement moments of different cleft protocols and initiatives are considered in this proposition. Concerning the type of measures, adjustment of the current PCC score outcome seems appropriate. For centres with adequate resources and specific interest in research, translation and validation of an upcoming tool, the Cleft Audit Protocol for Speech Augmented, is recommended.
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spelling doaj-art-c852bd2b372547f4af4314c578f562fa2025-08-20T03:52:16ZengBMJ Publishing GroupBMJ Open2044-60552023-12-01131210.1136/bmjopen-2023-071571What is the optimal assessment of speech? A multicentre, international evaluation of speech assessment in 2500 patients with a cleftAnne Klassen0Irene Mathijssen1Maarten Koudstaal2Saranda Ombashi3Melissa Srijanti Kurniawan4Alexander Allori5Banafsheh Sharif-Askary6Carolyn Rogers-Vizena7Marie-Christine Franken8Aebele B Mink van der Molen9Sarah Lisa Versnel10Pediatrics, McMaster University, Hamilton, Ontario, CanadaDepartment of Plastic and Reconstructive and Hand Surgery, The Dutch Craniofacial Centre, Erasmus MC Sophia-Childrens Hospital, Rotterdam, NetherlandsDepartment of Oral and Maxillofacial Surgery, The Dutch Craniofacial Centre, Erasmus MC-Sophia Childrens Hospital, Rotterdam, NetherlandsPlastic and Reconstructive Surgery, Erasmus Medical Center, Rotterdam, The NetherlandsPlastic and Reconstructive Surgery, Erasmus Medical Center, Rotterdam, The NetherlandsPlastic, Maxillofacial and Oral Surgery, Duke University Hospital and Children`s Health Center, Durham, North Carolina, USAPlastic, Maxillofacial and Oral Surgery, Duke University Hospital and Children`s Health Center, Durham, North Carolina, USAPlastic and Oral Surgery, Boston Children`s Hospital, Boston, Massachusetts, USAEar, Nose and Throat, Speech Therapy, Erasmus Medical Center, Rotterdam, The NetherlandsDepartment of Plastic Surgery, University Medical Center Utrecht, Utrecht, The NetherlandsPlastic and Reconstructive Surgery, Erasmus MC Sophia Children Hospital, Rotterdam, The NetherlandsObjectives Speech problems in patients with a cleft palate are often complex and multifactorial. Finding the optimal way of monitoring these problems is challenging. The International Consortium of Health Outcomes Measurement (ICHOM) has developed a set of standardised outcome measures at specific ages for patients with a cleft lip and/or palate, including measures of speech assessment. This study evaluates the type and timing of speech outcome measures currently included in this ICHOM Standard Set. Additionally, speech assessments in other cleft protocols and initiatives are discussed.Design, setting and participants An international, multicentre study was set up including centres from the USA and the Netherlands. Outcomes of clinical measures and Patient Reported Outcome Measures (PROMs) were collected retrospectively according to the ICHOM set. PROM data from a field test of the CLEFT-Q, a questionnaire developed and validated for patients with a cleft, were collected, including participants from countries with all sorts of income statuses, to examine the value of additional moments of measurement that are used in other cleft initiatives.Data from 2500 patients were included. Measured outcomes contained univariate regression analyses, trend analyses, t-tests, correlations and floor and ceiling effects.Results PROMs correlated low to moderate with clinical outcome measures. Clinical outcome measures correlated low to moderate with each other too. In contrast, two CLEFT-Q Scales correlated strongly with each other. All PROMs and the Percent Consonants Correct (PCC) showed an effect of age. In patients with an isolated cleft palate, a ceiling effect was found in the Intelligibility in Context Scale.Conclusion Recommendations for an optimal speech outcome assessment in cleft patients are made. Measurement moments of different cleft protocols and initiatives are considered in this proposition. Concerning the type of measures, adjustment of the current PCC score outcome seems appropriate. For centres with adequate resources and specific interest in research, translation and validation of an upcoming tool, the Cleft Audit Protocol for Speech Augmented, is recommended.https://bmjopen.bmj.com/content/13/12/e071571.full
spellingShingle Anne Klassen
Irene Mathijssen
Maarten Koudstaal
Saranda Ombashi
Melissa Srijanti Kurniawan
Alexander Allori
Banafsheh Sharif-Askary
Carolyn Rogers-Vizena
Marie-Christine Franken
Aebele B Mink van der Molen
Sarah Lisa Versnel
What is the optimal assessment of speech? A multicentre, international evaluation of speech assessment in 2500 patients with a cleft
BMJ Open
title What is the optimal assessment of speech? A multicentre, international evaluation of speech assessment in 2500 patients with a cleft
title_full What is the optimal assessment of speech? A multicentre, international evaluation of speech assessment in 2500 patients with a cleft
title_fullStr What is the optimal assessment of speech? A multicentre, international evaluation of speech assessment in 2500 patients with a cleft
title_full_unstemmed What is the optimal assessment of speech? A multicentre, international evaluation of speech assessment in 2500 patients with a cleft
title_short What is the optimal assessment of speech? A multicentre, international evaluation of speech assessment in 2500 patients with a cleft
title_sort what is the optimal assessment of speech a multicentre international evaluation of speech assessment in 2500 patients with a cleft
url https://bmjopen.bmj.com/content/13/12/e071571.full
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