Persisting thrombomodulin resistance at 3 months after liver transplantation in children with cirrhosis

Background: The coagulation cascade in pediatric cirrhotic patients appears rebalanced, similar to adults, with few true hemostasis-related bleeds or thromboembolic events before liver transplantation. Vascular thrombosis is an important post–liver transplantation complication. Few papers have addre...

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Main Authors: Marie-Astrid van Dievoet, Clara David, Audrey Dieu, Cedric Hermans, Thierry Pirotte, Jonathan Douxfils, Ton Lisman, Xavier Stephenne
Format: Article
Language:English
Published: Elsevier 2025-02-01
Series:Research and Practice in Thrombosis and Haemostasis
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Online Access:http://www.sciencedirect.com/science/article/pii/S2475037925000330
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author Marie-Astrid van Dievoet
Clara David
Audrey Dieu
Cedric Hermans
Thierry Pirotte
Jonathan Douxfils
Ton Lisman
Xavier Stephenne
author_facet Marie-Astrid van Dievoet
Clara David
Audrey Dieu
Cedric Hermans
Thierry Pirotte
Jonathan Douxfils
Ton Lisman
Xavier Stephenne
author_sort Marie-Astrid van Dievoet
collection DOAJ
description Background: The coagulation cascade in pediatric cirrhotic patients appears rebalanced, similar to adults, with few true hemostasis-related bleeds or thromboembolic events before liver transplantation. Vascular thrombosis is an important post–liver transplantation complication. Few papers have addressed the recovery of the coagulation cascade after liver transplantation. Objectives: We aimed to assess the coagulation cascade, with both measurement of individual factors and a global hemostasis assay, before living donor liver transplantation and to investigate its recovery 3 months after transplantation, when liver function has normalized. Methods: From January 2022 to July 2023, pediatric cirrhotic patients were prospectively enrolled 1 day before liver transplantation. An age-matched control group was included for comparison. Routine hemostasis tests, levels of coagulation factors and natural anticoagulants, and thrombomodulin-modified thrombin generation were determined on automated coagulation analyzers at inclusion and 3 months after liver transplantation. Results: Twenty-seven pediatric patients with cirrhosis, primarily of cholestatic origin, and 10 controls were enrolled. Sixteen patients were sampled 3 months after liver transplantation. Pediatric end-stage liver disease scores ranged from −10 to 44. A rebalanced coagulation cascade was confirmed in cirrhotic children, indicated by a thrombomodulin-modified thrombin generation assay similar to controls, although with higher interpatient variability. Interestingly, 3 months posttransplant, coagulation was not completely normalized. In the majority of patients resistance to thrombomodulin persisted. Conclusion: This study confirmed a rebalanced coagulation system in pediatric cirrhotic patients before liver transplantation. Three months posttransplant thrombomodulin resistance persisted. Whereas this contributes to thrombotic complications observed after liver transplantation, remains to be elucidated.
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spelling doaj-art-c58b149ecded4ffca1fd0aeb63cb9ef72025-08-20T03:18:58ZengElsevierResearch and Practice in Thrombosis and Haemostasis2475-03792025-02-019210270910.1016/j.rpth.2025.102709Persisting thrombomodulin resistance at 3 months after liver transplantation in children with cirrhosisMarie-Astrid van Dievoet0Clara David1Audrey Dieu2Cedric Hermans3Thierry Pirotte4Jonathan Douxfils5Ton Lisman6Xavier Stephenne7Laboratory of Pediatric Hepatology and Cell Therapy, Institut de Recherche Expérimentale et Clinique (IREC), Université catholique de Louvain, Brussels, Belgium; Laboratory Department, Cliniques Universitaires Saint-Luc, Brussels, Belgium; Correspondence Marie-Astrid van Dievoet, Laboratory Department, Cliniques universitaires Saint-Luc, 54 Avenue Hippocrate, B-1200 Brussels, Belgium.Clinical Pharmacology and Toxicology Research Unit, Namur Research Institute for Life Sciences (NARILIS), University of Namur, Namur, Belgium; Research and Development Department, QUALIblood s.a., QUALIresearch, Liège, BelgiumDepartment of Anesthesiology, Cliniques Universitaires Saint-Luc, 1200 Brussels, BelgiumHaemostasis and Thrombosis Unit, Division of Haematology, Cliniques Universitaires Saint-Luc, Brussels, BelgiumDepartment of Anesthesiology, Cliniques Universitaires Saint-Luc, 1200 Brussels, BelgiumClinical Pharmacology and Toxicology Research Unit, Namur Research Institute for Life Sciences (NARILIS), University of Namur, Namur, Belgium; Research and Development Department, QUALIblood s.a., QUALIresearch, Liège, BelgiumSurgical Research Laboratory and Section of Hepatobiliary Surgery and Liver Transplantation, University of Groningen, University Medical Center Groningen, Groningen, NetherlandsLaboratory of Pediatric Hepatology and Cell Therapy, Institut de Recherche Expérimentale et Clinique (IREC), Université catholique de Louvain, Brussels, Belgium; Division of Pediatric Gastroenterology and Hepatology, Department of Pediatrics, Cliniques Universitaires Saint-Luc, Rare Liver ERN, Transplantchild ERN, Brussels, BelgiumBackground: The coagulation cascade in pediatric cirrhotic patients appears rebalanced, similar to adults, with few true hemostasis-related bleeds or thromboembolic events before liver transplantation. Vascular thrombosis is an important post–liver transplantation complication. Few papers have addressed the recovery of the coagulation cascade after liver transplantation. Objectives: We aimed to assess the coagulation cascade, with both measurement of individual factors and a global hemostasis assay, before living donor liver transplantation and to investigate its recovery 3 months after transplantation, when liver function has normalized. Methods: From January 2022 to July 2023, pediatric cirrhotic patients were prospectively enrolled 1 day before liver transplantation. An age-matched control group was included for comparison. Routine hemostasis tests, levels of coagulation factors and natural anticoagulants, and thrombomodulin-modified thrombin generation were determined on automated coagulation analyzers at inclusion and 3 months after liver transplantation. Results: Twenty-seven pediatric patients with cirrhosis, primarily of cholestatic origin, and 10 controls were enrolled. Sixteen patients were sampled 3 months after liver transplantation. Pediatric end-stage liver disease scores ranged from −10 to 44. A rebalanced coagulation cascade was confirmed in cirrhotic children, indicated by a thrombomodulin-modified thrombin generation assay similar to controls, although with higher interpatient variability. Interestingly, 3 months posttransplant, coagulation was not completely normalized. In the majority of patients resistance to thrombomodulin persisted. Conclusion: This study confirmed a rebalanced coagulation system in pediatric cirrhotic patients before liver transplantation. Three months posttransplant thrombomodulin resistance persisted. Whereas this contributes to thrombotic complications observed after liver transplantation, remains to be elucidated.http://www.sciencedirect.com/science/article/pii/S2475037925000330liver cirrhosisliver transplantationpediatricsthrombomodulinthrombin generation
spellingShingle Marie-Astrid van Dievoet
Clara David
Audrey Dieu
Cedric Hermans
Thierry Pirotte
Jonathan Douxfils
Ton Lisman
Xavier Stephenne
Persisting thrombomodulin resistance at 3 months after liver transplantation in children with cirrhosis
Research and Practice in Thrombosis and Haemostasis
liver cirrhosis
liver transplantation
pediatrics
thrombomodulin
thrombin generation
title Persisting thrombomodulin resistance at 3 months after liver transplantation in children with cirrhosis
title_full Persisting thrombomodulin resistance at 3 months after liver transplantation in children with cirrhosis
title_fullStr Persisting thrombomodulin resistance at 3 months after liver transplantation in children with cirrhosis
title_full_unstemmed Persisting thrombomodulin resistance at 3 months after liver transplantation in children with cirrhosis
title_short Persisting thrombomodulin resistance at 3 months after liver transplantation in children with cirrhosis
title_sort persisting thrombomodulin resistance at 3 months after liver transplantation in children with cirrhosis
topic liver cirrhosis
liver transplantation
pediatrics
thrombomodulin
thrombin generation
url http://www.sciencedirect.com/science/article/pii/S2475037925000330
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