Confirmation of the reported association of clonal chromosomal mosaicism with an increased risk of incident hematologic cancer.

Chromosomal abnormalities provide clinical utility in the diagnosis and treatment of hematologic malignancies, and may be predictive of malignant transformation in individuals without apparent clinical presentation of a hematologic cancer. In an effort to confirm previous reports of an association b...

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Main Authors: Ursula M Schick, Andrew McDavid, Paul K Crane, Noah Weston, Kelly Ehrlich, Katherine M Newton, Robert Wallace, Ebony Bookman, Tabitha Harrison, Aaron Aragaki, David R Crosslin, Sophia S Wang, Alex P Reiner, Rebecca D Jackson, Ulrike Peters, Eric B Larson, Gail P Jarvik, Christopher S Carlson
Format: Article
Language:English
Published: Public Library of Science (PLoS) 2013-01-01
Series:PLoS ONE
Online Access:https://journals.plos.org/plosone/article/file?id=10.1371/journal.pone.0059823&type=printable
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author Ursula M Schick
Andrew McDavid
Paul K Crane
Noah Weston
Kelly Ehrlich
Katherine M Newton
Robert Wallace
Ebony Bookman
Tabitha Harrison
Aaron Aragaki
David R Crosslin
Sophia S Wang
Alex P Reiner
Rebecca D Jackson
Ulrike Peters
Eric B Larson
Gail P Jarvik
Christopher S Carlson
author_facet Ursula M Schick
Andrew McDavid
Paul K Crane
Noah Weston
Kelly Ehrlich
Katherine M Newton
Robert Wallace
Ebony Bookman
Tabitha Harrison
Aaron Aragaki
David R Crosslin
Sophia S Wang
Alex P Reiner
Rebecca D Jackson
Ulrike Peters
Eric B Larson
Gail P Jarvik
Christopher S Carlson
author_sort Ursula M Schick
collection DOAJ
description Chromosomal abnormalities provide clinical utility in the diagnosis and treatment of hematologic malignancies, and may be predictive of malignant transformation in individuals without apparent clinical presentation of a hematologic cancer. In an effort to confirm previous reports of an association between clonal mosaicism and incident hematologic cancer, we applied the anomDetectBAF algorithm to call chromosomal anomalies in genotype data from previously conducted Genome Wide Association Studies (GWAS). The genotypes were initially collected from DNA derived from peripheral blood of 12,176 participants in the Group Health electronic Medical Records and Genomics study (eMERGE) and the Women's Health Initiative (WHI). We detected clonal mosaicism in 169 individuals (1.4%) and large clonal mosaic events (>2 mb) in 117 (1.0%) individuals. Though only 9.5% of clonal mosaic carriers had an incident diagnosis of hematologic cancer (multiple myeloma, myelodysplastic syndrome, lymphoma, or leukemia), the carriers had a 5.5-fold increased risk (95% CI: 3.3-9.3; p-value = 7.5×10(-11)) of developing these cancers subsequently. Carriers of large mosaic anomalies showed particularly pronounced risk of subsequent leukemia (HR = 19.2, 95% CI: 8.9-41.6; p-value = 7.3×10(-14)). Thus we independently confirm the association between detectable clonal mosaicism and hematologic cancer found previously in two recent publications.
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spelling doaj-art-c207b0e202d54167a97757e22cb2b3212025-08-20T03:25:08ZengPublic Library of Science (PLoS)PLoS ONE1932-62032013-01-0183e5982310.1371/journal.pone.0059823Confirmation of the reported association of clonal chromosomal mosaicism with an increased risk of incident hematologic cancer.Ursula M SchickAndrew McDavidPaul K CraneNoah WestonKelly EhrlichKatherine M NewtonRobert WallaceEbony BookmanTabitha HarrisonAaron AragakiDavid R CrosslinSophia S WangAlex P ReinerRebecca D JacksonUlrike PetersEric B LarsonGail P JarvikChristopher S CarlsonChromosomal abnormalities provide clinical utility in the diagnosis and treatment of hematologic malignancies, and may be predictive of malignant transformation in individuals without apparent clinical presentation of a hematologic cancer. In an effort to confirm previous reports of an association between clonal mosaicism and incident hematologic cancer, we applied the anomDetectBAF algorithm to call chromosomal anomalies in genotype data from previously conducted Genome Wide Association Studies (GWAS). The genotypes were initially collected from DNA derived from peripheral blood of 12,176 participants in the Group Health electronic Medical Records and Genomics study (eMERGE) and the Women's Health Initiative (WHI). We detected clonal mosaicism in 169 individuals (1.4%) and large clonal mosaic events (>2 mb) in 117 (1.0%) individuals. Though only 9.5% of clonal mosaic carriers had an incident diagnosis of hematologic cancer (multiple myeloma, myelodysplastic syndrome, lymphoma, or leukemia), the carriers had a 5.5-fold increased risk (95% CI: 3.3-9.3; p-value = 7.5×10(-11)) of developing these cancers subsequently. Carriers of large mosaic anomalies showed particularly pronounced risk of subsequent leukemia (HR = 19.2, 95% CI: 8.9-41.6; p-value = 7.3×10(-14)). Thus we independently confirm the association between detectable clonal mosaicism and hematologic cancer found previously in two recent publications.https://journals.plos.org/plosone/article/file?id=10.1371/journal.pone.0059823&type=printable
spellingShingle Ursula M Schick
Andrew McDavid
Paul K Crane
Noah Weston
Kelly Ehrlich
Katherine M Newton
Robert Wallace
Ebony Bookman
Tabitha Harrison
Aaron Aragaki
David R Crosslin
Sophia S Wang
Alex P Reiner
Rebecca D Jackson
Ulrike Peters
Eric B Larson
Gail P Jarvik
Christopher S Carlson
Confirmation of the reported association of clonal chromosomal mosaicism with an increased risk of incident hematologic cancer.
PLoS ONE
title Confirmation of the reported association of clonal chromosomal mosaicism with an increased risk of incident hematologic cancer.
title_full Confirmation of the reported association of clonal chromosomal mosaicism with an increased risk of incident hematologic cancer.
title_fullStr Confirmation of the reported association of clonal chromosomal mosaicism with an increased risk of incident hematologic cancer.
title_full_unstemmed Confirmation of the reported association of clonal chromosomal mosaicism with an increased risk of incident hematologic cancer.
title_short Confirmation of the reported association of clonal chromosomal mosaicism with an increased risk of incident hematologic cancer.
title_sort confirmation of the reported association of clonal chromosomal mosaicism with an increased risk of incident hematologic cancer
url https://journals.plos.org/plosone/article/file?id=10.1371/journal.pone.0059823&type=printable
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