The small molecule ML233 is a direct inhibitor of tyrosinase function

Abstract Melanogenesis is the biological process regulating the synthesis of melanin pigments in melanocytes. Defective melanogenesis is associated with numerous human skin diseases, including, but not limited to, albinism, vitiligo, melasma, and hypo- and hyperpigmentation disorders. Tyrosinase is...

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Main Authors: Romain Menard, Aissette Baanannou, Caroline Halluin, Dexter Morse, Sadie Kuhn, Joel H. Graber, James Strickland, Romain Madelaine
Format: Article
Language:English
Published: Nature Portfolio 2025-03-01
Series:Communications Biology
Online Access:https://doi.org/10.1038/s42003-025-07973-5
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author Romain Menard
Aissette Baanannou
Caroline Halluin
Dexter Morse
Sadie Kuhn
Joel H. Graber
James Strickland
Romain Madelaine
author_facet Romain Menard
Aissette Baanannou
Caroline Halluin
Dexter Morse
Sadie Kuhn
Joel H. Graber
James Strickland
Romain Madelaine
author_sort Romain Menard
collection DOAJ
description Abstract Melanogenesis is the biological process regulating the synthesis of melanin pigments in melanocytes. Defective melanogenesis is associated with numerous human skin diseases, including, but not limited to, albinism, vitiligo, melasma, and hypo- and hyperpigmentation disorders. Tyrosinase is the rate-limiting enzyme controlling melanogenesis, and hence tremendous efforts have been made to identify potent and safe inhibitors of tyrosinase function. However, despite decades of research, currently there is no effective treatment that inhibits melanogenesis or tyrosinase activity with no adverse side effects. In this study, we report the characterization of the ML233 chemical as a potent inhibitor of tyrosinase activity in vivo and in vitro. We demonstrate that ML233 reduces melanin production in the zebrafish model with no observable significant toxic side effects, and in murine melanoma cells. We also predict that these effects are mediated through direct tyrosinase-ML233 interaction, i.e., binding of the ML233 molecule to the active site of the protein to inhibit its function. Together, our results reveal that ML233 plays roles in both healthy and pathological skin cells via inhibition of melanin production. ML233-mediated tyrosinase inhibition is a potentially safe and effective approach to alleviate the symptoms of melanocyte-associated diseases and thereby substantially improve human health.
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spelling doaj-art-bf51ecf891b8435692f01db785f2e12f2025-08-20T03:40:47ZengNature PortfolioCommunications Biology2399-36422025-03-018111610.1038/s42003-025-07973-5The small molecule ML233 is a direct inhibitor of tyrosinase functionRomain Menard0Aissette Baanannou1Caroline Halluin2Dexter Morse3Sadie Kuhn4Joel H. Graber5James Strickland6Romain Madelaine7MDI Biological Laboratory, Kathryn W. Davis Center for Regenerative Biology and AgingMDI Biological Laboratory, Kathryn W. Davis Center for Regenerative Biology and AgingMDI Biological Laboratory, Kathryn W. Davis Center for Regenerative Biology and AgingMDI Biological Laboratory, Kathryn W. Davis Center for Regenerative Biology and AgingMDI BioscienceMDI Biological Laboratory, Kathryn W. Davis Center for Regenerative Biology and AgingMDI BioscienceMDI Biological Laboratory, Kathryn W. Davis Center for Regenerative Biology and AgingAbstract Melanogenesis is the biological process regulating the synthesis of melanin pigments in melanocytes. Defective melanogenesis is associated with numerous human skin diseases, including, but not limited to, albinism, vitiligo, melasma, and hypo- and hyperpigmentation disorders. Tyrosinase is the rate-limiting enzyme controlling melanogenesis, and hence tremendous efforts have been made to identify potent and safe inhibitors of tyrosinase function. However, despite decades of research, currently there is no effective treatment that inhibits melanogenesis or tyrosinase activity with no adverse side effects. In this study, we report the characterization of the ML233 chemical as a potent inhibitor of tyrosinase activity in vivo and in vitro. We demonstrate that ML233 reduces melanin production in the zebrafish model with no observable significant toxic side effects, and in murine melanoma cells. We also predict that these effects are mediated through direct tyrosinase-ML233 interaction, i.e., binding of the ML233 molecule to the active site of the protein to inhibit its function. Together, our results reveal that ML233 plays roles in both healthy and pathological skin cells via inhibition of melanin production. ML233-mediated tyrosinase inhibition is a potentially safe and effective approach to alleviate the symptoms of melanocyte-associated diseases and thereby substantially improve human health.https://doi.org/10.1038/s42003-025-07973-5
spellingShingle Romain Menard
Aissette Baanannou
Caroline Halluin
Dexter Morse
Sadie Kuhn
Joel H. Graber
James Strickland
Romain Madelaine
The small molecule ML233 is a direct inhibitor of tyrosinase function
Communications Biology
title The small molecule ML233 is a direct inhibitor of tyrosinase function
title_full The small molecule ML233 is a direct inhibitor of tyrosinase function
title_fullStr The small molecule ML233 is a direct inhibitor of tyrosinase function
title_full_unstemmed The small molecule ML233 is a direct inhibitor of tyrosinase function
title_short The small molecule ML233 is a direct inhibitor of tyrosinase function
title_sort small molecule ml233 is a direct inhibitor of tyrosinase function
url https://doi.org/10.1038/s42003-025-07973-5
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