DIAGNOSIS AND TREATMENT OF PATIENTS WITH CRYOPYRIN-ASSOCIATED PERIODIC SYNDROME

Cryopyrin-Associated Periodic Syndrome (CAPS) refers to a group of autoinflammatory diseases and is caused by autosomal dominant mutations of the NLRP3 gene coding. Relapsing fever, rash, laboratory changes and inflammatory lesions of various organs are typical manifestations of CAPS. Inhibitors of...

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Main Authors: A. L. Kozlova, B. S. Pershin, T. V. Varlamova, A. Yu. Shcherbina
Format: Article
Language:English
Published: "Paediatrician" Publishers LLC 2015-04-01
Series:Вопросы современной педиатрии
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Online Access:https://vsp.spr-journal.ru/jour/article/view/73
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author A. L. Kozlova
B. S. Pershin
T. V. Varlamova
A. Yu. Shcherbina
author_facet A. L. Kozlova
B. S. Pershin
T. V. Varlamova
A. Yu. Shcherbina
author_sort A. L. Kozlova
collection DOAJ
description Cryopyrin-Associated Periodic Syndrome (CAPS) refers to a group of autoinflammatory diseases and is caused by autosomal dominant mutations of the NLRP3 gene coding. Relapsing fever, rash, laboratory changes and inflammatory lesions of various organs are typical manifestations of CAPS. Inhibitors of interleukin 1, including canakinumab, are modern means of pathogenetic therapy of patients with CAPS. The article presents the treatment results in 5 pediatric patients with CAPS. Application of canakinumab led to the relief of all major symptoms (fever, inflammatory changes in the blood lymphoproliferation, signs of organ damage), and no relevant side effects was detected.
format Article
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institution DOAJ
issn 1682-5527
1682-5535
language English
publishDate 2015-04-01
publisher "Paediatrician" Publishers LLC
record_format Article
series Вопросы современной педиатрии
spelling doaj-art-bd32ff1d04c4485dabdac74aa51508812025-08-20T03:01:07Zeng"Paediatrician" Publishers LLCВопросы современной педиатрии1682-55271682-55352015-04-0114229229710.15690/vsp.v14i2.130173DIAGNOSIS AND TREATMENT OF PATIENTS WITH CRYOPYRIN-ASSOCIATED PERIODIC SYNDROMEA. L. Kozlova0B. S. Pershin1T. V. Varlamova2A. Yu. Shcherbina3D. Rogachev Federal Research and Clinical Centre of Pediatric Hematology, Oncology and Immunology, Moscow, Russian FederationD. Rogachev Federal Research and Clinical Centre of Pediatric Hematology, Oncology and Immunology, Moscow, Russian FederationD. Rogachev Federal Research and Clinical Centre of Pediatric Hematology, Oncology and Immunology, Moscow, Russian FederationD. Rogachev Federal Research and Clinical Centre of Pediatric Hematology, Oncology and Immunology, Moscow, Russian FederationCryopyrin-Associated Periodic Syndrome (CAPS) refers to a group of autoinflammatory diseases and is caused by autosomal dominant mutations of the NLRP3 gene coding. Relapsing fever, rash, laboratory changes and inflammatory lesions of various organs are typical manifestations of CAPS. Inhibitors of interleukin 1, including canakinumab, are modern means of pathogenetic therapy of patients with CAPS. The article presents the treatment results in 5 pediatric patients with CAPS. Application of canakinumab led to the relief of all major symptoms (fever, inflammatory changes in the blood lymphoproliferation, signs of organ damage), and no relevant side effects was detected.https://vsp.spr-journal.ru/jour/article/view/73autoinflammatory syndromescryopyrin-associated periodic syndromeinterleukin 1inhibitorscanakinumab
spellingShingle A. L. Kozlova
B. S. Pershin
T. V. Varlamova
A. Yu. Shcherbina
DIAGNOSIS AND TREATMENT OF PATIENTS WITH CRYOPYRIN-ASSOCIATED PERIODIC SYNDROME
Вопросы современной педиатрии
autoinflammatory syndromes
cryopyrin-associated periodic syndrome
interleukin 1
inhibitors
canakinumab
title DIAGNOSIS AND TREATMENT OF PATIENTS WITH CRYOPYRIN-ASSOCIATED PERIODIC SYNDROME
title_full DIAGNOSIS AND TREATMENT OF PATIENTS WITH CRYOPYRIN-ASSOCIATED PERIODIC SYNDROME
title_fullStr DIAGNOSIS AND TREATMENT OF PATIENTS WITH CRYOPYRIN-ASSOCIATED PERIODIC SYNDROME
title_full_unstemmed DIAGNOSIS AND TREATMENT OF PATIENTS WITH CRYOPYRIN-ASSOCIATED PERIODIC SYNDROME
title_short DIAGNOSIS AND TREATMENT OF PATIENTS WITH CRYOPYRIN-ASSOCIATED PERIODIC SYNDROME
title_sort diagnosis and treatment of patients with cryopyrin associated periodic syndrome
topic autoinflammatory syndromes
cryopyrin-associated periodic syndrome
interleukin 1
inhibitors
canakinumab
url https://vsp.spr-journal.ru/jour/article/view/73
work_keys_str_mv AT alkozlova diagnosisandtreatmentofpatientswithcryopyrinassociatedperiodicsyndrome
AT bspershin diagnosisandtreatmentofpatientswithcryopyrinassociatedperiodicsyndrome
AT tvvarlamova diagnosisandtreatmentofpatientswithcryopyrinassociatedperiodicsyndrome
AT ayushcherbina diagnosisandtreatmentofpatientswithcryopyrinassociatedperiodicsyndrome