RNA transcripts serve as a template for double-strand break repair in human cells

Abstract Double-strand breaks (DSBs) are toxic lesions that lead to genome instability. While canonical DSB repair pathways typically operate independently of RNA, growing evidence suggests that RNA:DNA hybrids and nearby transcripts can influence repair outcomes. However, whether transcript RNA can...

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Main Authors: Manisha Jalan, Alessandra Brambati, Hina Shah, Niamh McDermott, Juber Patel, Yingjie Zhu, Ahmet Doymaz, Julius Wu, Kyrie S. Anderson, Andrea Gazzo, Fresia Pareja, Takafumi N. Yamaguchi, Theodore Vougiouklakis, Sana Ahmed-Seghir, Philippa Steinberg, Anna Neiman-Golden, Benura Azeroglu, Joan Gomez-Aguilar, Edaise M. da Silva, Suleman Hussain, Daniel Higginson, Paul C. Boutros, Nadeem Riaz, Jorge S. Reis-Filho, Simon N. Powell, Agnel Sfeir
Format: Article
Language:English
Published: Nature Portfolio 2025-05-01
Series:Nature Communications
Online Access:https://doi.org/10.1038/s41467-025-59510-x
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author Manisha Jalan
Alessandra Brambati
Hina Shah
Niamh McDermott
Juber Patel
Yingjie Zhu
Ahmet Doymaz
Julius Wu
Kyrie S. Anderson
Andrea Gazzo
Fresia Pareja
Takafumi N. Yamaguchi
Theodore Vougiouklakis
Sana Ahmed-Seghir
Philippa Steinberg
Anna Neiman-Golden
Benura Azeroglu
Joan Gomez-Aguilar
Edaise M. da Silva
Suleman Hussain
Daniel Higginson
Paul C. Boutros
Nadeem Riaz
Jorge S. Reis-Filho
Simon N. Powell
Agnel Sfeir
author_facet Manisha Jalan
Alessandra Brambati
Hina Shah
Niamh McDermott
Juber Patel
Yingjie Zhu
Ahmet Doymaz
Julius Wu
Kyrie S. Anderson
Andrea Gazzo
Fresia Pareja
Takafumi N. Yamaguchi
Theodore Vougiouklakis
Sana Ahmed-Seghir
Philippa Steinberg
Anna Neiman-Golden
Benura Azeroglu
Joan Gomez-Aguilar
Edaise M. da Silva
Suleman Hussain
Daniel Higginson
Paul C. Boutros
Nadeem Riaz
Jorge S. Reis-Filho
Simon N. Powell
Agnel Sfeir
author_sort Manisha Jalan
collection DOAJ
description Abstract Double-strand breaks (DSBs) are toxic lesions that lead to genome instability. While canonical DSB repair pathways typically operate independently of RNA, growing evidence suggests that RNA:DNA hybrids and nearby transcripts can influence repair outcomes. However, whether transcript RNA can directly serve as a template for DSB repair in human cells remains unclear. In this study, we develop fluorescence and sequencing-based assays to show that RNA-containing oligonucleotides and messenger RNA can serve as templates during DSB repair. We conduct a CRISPR/Cas9-based genetic screen to identify factors that promote RNA-templated DSB repair (RT-DSBR). Of the candidate polymerases, we identify DNA polymerase zeta (Polζ) as a potential reverse transcriptase that facilitates RT-DSBR. Furthermore, analysis of cancer genome sequencing data reveals whole intron deletions - a distinct genomic signature of RT-DSBR that occurs when spliced mRNA guides repair. Altogether, our findings highlight RT-DSBR as an alternative pathway for repairing DSBs in transcribed genes, with potential mutagenic consequences.
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spelling doaj-art-b26f5d46ee024eacba7094f2bd77fac62025-08-20T03:53:12ZengNature PortfolioNature Communications2041-17232025-05-0116111610.1038/s41467-025-59510-xRNA transcripts serve as a template for double-strand break repair in human cellsManisha Jalan0Alessandra Brambati1Hina Shah2Niamh McDermott3Juber Patel4Yingjie Zhu5Ahmet Doymaz6Julius Wu7Kyrie S. Anderson8Andrea Gazzo9Fresia Pareja10Takafumi N. Yamaguchi11Theodore Vougiouklakis12Sana Ahmed-Seghir13Philippa Steinberg14Anna Neiman-Golden15Benura Azeroglu16Joan Gomez-Aguilar17Edaise M. da Silva18Suleman Hussain19Daniel Higginson20Paul C. Boutros21Nadeem Riaz22Jorge S. Reis-Filho23Simon N. Powell24Agnel Sfeir25Department of Radiation Oncology, Memorial Sloan Kettering Cancer CenterMolecular Biology Program, Sloan Kettering Institute, Memorial Sloan Kettering Cancer CenterMolecular Biology Program, Sloan Kettering Institute, Memorial Sloan Kettering Cancer CenterDepartment of Radiation Oncology, Memorial Sloan Kettering Cancer CenterDepartment of Radiation Oncology, Memorial Sloan Kettering Cancer CenterDepartment of Pathology and Laboratory Medicine, Memorial Sloan Kettering Cancer CenterMolecular Biology Program, Sloan Kettering Institute, Memorial Sloan Kettering Cancer CenterMolecular Biology Program, Sloan Kettering Institute, Memorial Sloan Kettering Cancer CenterDepartment of Radiation Oncology, Memorial Sloan Kettering Cancer CenterDepartment of Pathology and Laboratory Medicine, Memorial Sloan Kettering Cancer CenterDepartment of Pathology and Laboratory Medicine, Memorial Sloan Kettering Cancer CenterDepartment of Human Genetics, University of CaliforniaDepartment of Pathology and Laboratory Medicine, Memorial Sloan Kettering Cancer CenterDepartment of Radiation Oncology, Memorial Sloan Kettering Cancer CenterDepartment of Human Genetics, University of CaliforniaDepartment of Human Genetics, University of CaliforniaLaboratory of Genome Integrity, National Cancer Institute (NCI), National Institutes of Health (NIH)Department of Radiation Oncology, Memorial Sloan Kettering Cancer CenterDepartment of Pathology and Laboratory Medicine, Memorial Sloan Kettering Cancer CenterDepartment of Radiation Oncology, Memorial Sloan Kettering Cancer CenterDepartment of Radiation Oncology, Memorial Sloan Kettering Cancer CenterDepartment of Human Genetics, University of CaliforniaDepartment of Radiation Oncology, Memorial Sloan Kettering Cancer CenterDepartment of Pathology and Laboratory Medicine, Memorial Sloan Kettering Cancer CenterDepartment of Radiation Oncology, Memorial Sloan Kettering Cancer CenterMolecular Biology Program, Sloan Kettering Institute, Memorial Sloan Kettering Cancer CenterAbstract Double-strand breaks (DSBs) are toxic lesions that lead to genome instability. While canonical DSB repair pathways typically operate independently of RNA, growing evidence suggests that RNA:DNA hybrids and nearby transcripts can influence repair outcomes. However, whether transcript RNA can directly serve as a template for DSB repair in human cells remains unclear. In this study, we develop fluorescence and sequencing-based assays to show that RNA-containing oligonucleotides and messenger RNA can serve as templates during DSB repair. We conduct a CRISPR/Cas9-based genetic screen to identify factors that promote RNA-templated DSB repair (RT-DSBR). Of the candidate polymerases, we identify DNA polymerase zeta (Polζ) as a potential reverse transcriptase that facilitates RT-DSBR. Furthermore, analysis of cancer genome sequencing data reveals whole intron deletions - a distinct genomic signature of RT-DSBR that occurs when spliced mRNA guides repair. Altogether, our findings highlight RT-DSBR as an alternative pathway for repairing DSBs in transcribed genes, with potential mutagenic consequences.https://doi.org/10.1038/s41467-025-59510-x
spellingShingle Manisha Jalan
Alessandra Brambati
Hina Shah
Niamh McDermott
Juber Patel
Yingjie Zhu
Ahmet Doymaz
Julius Wu
Kyrie S. Anderson
Andrea Gazzo
Fresia Pareja
Takafumi N. Yamaguchi
Theodore Vougiouklakis
Sana Ahmed-Seghir
Philippa Steinberg
Anna Neiman-Golden
Benura Azeroglu
Joan Gomez-Aguilar
Edaise M. da Silva
Suleman Hussain
Daniel Higginson
Paul C. Boutros
Nadeem Riaz
Jorge S. Reis-Filho
Simon N. Powell
Agnel Sfeir
RNA transcripts serve as a template for double-strand break repair in human cells
Nature Communications
title RNA transcripts serve as a template for double-strand break repair in human cells
title_full RNA transcripts serve as a template for double-strand break repair in human cells
title_fullStr RNA transcripts serve as a template for double-strand break repair in human cells
title_full_unstemmed RNA transcripts serve as a template for double-strand break repair in human cells
title_short RNA transcripts serve as a template for double-strand break repair in human cells
title_sort rna transcripts serve as a template for double strand break repair in human cells
url https://doi.org/10.1038/s41467-025-59510-x
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