Mayer-Rokitansky-Küster-Hauser syndrome associated with 7q11.23 microduplication: A case report

Introduction: Mayer-Rokitansky-Küster-Hauser syndrome (MRKHS) is characterized by the congenital absence of the uterus and vagina in females with 46, XX karyotype. The genetic etiology remains poorly understood. Case presentation: We described a 29-year-old female patient with a main complaint of pr...

Full description

Saved in:
Bibliographic Details
Main Authors: Gabriela Corassa Rodrigues da Cunha, Vanessa Sodré de Souza, Marcus Von Zuben, Mara Santos Córdoba, Mayra Veloso Ayrimoraes Soares, Raphael Severino Bonadio, Daniela Mara de Oliveira, Silviene Fabiana de Oliveira, Juliana Forte de Mazzeu Araújo, Aline Pic-Taylor
Format: Article
Language:English
Published: KeAi Communications Co., Ltd. 2025-06-01
Series:Global Medical Genetics
Subjects:
Online Access:http://www.sciencedirect.com/science/article/pii/S2699940425000402
Tags: Add Tag
No Tags, Be the first to tag this record!
Description
Summary:Introduction: Mayer-Rokitansky-Küster-Hauser syndrome (MRKHS) is characterized by the congenital absence of the uterus and vagina in females with 46, XX karyotype. The genetic etiology remains poorly understood. Case presentation: We described a 29-year-old female patient with a main complaint of primary amenorrhea. The MRKHS diagnosis was confirmed, and molecular analysis revealed a 7q11.23 microduplication in the proband that was shown to be inherited from her mother. In the literature, müllerian malformations have been reported in only a few cases of 7q11.23 microduplication. However, the abnormalities observed in our patient have not been described previously. To the best of our knowledge, this is the first documented case of a patient with the coexistence of 7q11.23 microduplication syndrome and MRKHS. Discussion/conclusion: Identification of the 7q11.23 duplication could suggest a new candidate region for MRKHS and add to the already described signs of 7q11.23 microduplication syndrome.
ISSN:2699-9404