Cryptic Temporal Bone Fibrous Dysplasia with Predominant Vestibular Symptoms: A Case Report
Background: Temporal bone fibrous dysplasia is relatively uncommon and typically manifests as a monostotic form of the disease. It often presents with noticeable temporal bone deformity, clinically appearing as a hard bony swelling behind or around the ear, external auditory canal stenosis, and con...
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Babcock Medical Society
2025-06-01
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| Series: | Babcock University Medical Journal |
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| Online Access: | https://bumj.babcock.edu.ng/index.php/bumj/article/view/545 |
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| author | kenechukwu Uche-Okonkwo Moses Ayodele Akinola John Ifeanyi Nwadiokwu Oluwapelumi Olusoga-Peters Babatunde Akinola Bamgboye |
| author_facet | kenechukwu Uche-Okonkwo Moses Ayodele Akinola John Ifeanyi Nwadiokwu Oluwapelumi Olusoga-Peters Babatunde Akinola Bamgboye |
| author_sort | kenechukwu Uche-Okonkwo |
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Background: Temporal bone fibrous dysplasia is relatively uncommon and typically manifests as a monostotic form of the disease. It often presents with noticeable temporal bone deformity, clinically appearing as a hard bony swelling behind or around the ear, external auditory canal stenosis, and conduction deafness. While symptoms such as aural fullness, tinnitus, and hearing loss are commonly reported, specific vestibular symptoms like vertigo and nystagmus are considerably less frequent.
Case Presentation: In this report, we describe the diagnostic features, management, and outcome of a 37-year-old Nigerian patient with fibrous dysplasia of the right temporal bone, who presented with recurrent debilitating vertigo, along with tinnitus and aural fullness, but without any obvious temporal bone deformity, which posed an initial diagnostic dilemma. She underwent an exploratory mastoidectomy and received a postoperative stat dose of IV zoledronate, along with oral dexamethasone tapered over 10 days, resulting in significant symptom resolution.
Conclusion: This unusual presentation underscores the importance of considering temporal bone dysplasia as a potential differential diagnosis for unilateral tinnitus, regardless of the presence of clear bony deformity.
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| format | Article |
| id | doaj-art-aff9834a4fb442b7b0d9cbeb3ff9e15e |
| institution | Kabale University |
| issn | 2465-6666 2756-4657 |
| language | English |
| publishDate | 2025-06-01 |
| publisher | Babcock Medical Society |
| record_format | Article |
| series | Babcock University Medical Journal |
| spelling | doaj-art-aff9834a4fb442b7b0d9cbeb3ff9e15e2025-08-20T03:31:20ZengBabcock Medical SocietyBabcock University Medical Journal2465-66662756-46572025-06-018110.38029/babcockuniv.med.j..v8i1.545Cryptic Temporal Bone Fibrous Dysplasia with Predominant Vestibular Symptoms: A Case Reportkenechukwu Uche-Okonkwo0Moses Ayodele Akinola1John Ifeanyi Nwadiokwu2Oluwapelumi Olusoga-Peters3Babatunde Akinola Bamgboye4Otorhinolaryngology unit, Department of Surgery, Ben Carson College of Health and Medical Sciences, Babcock University, Ilishan-Remo, Ogun state, NigeriaOtorhinolaryngology unit, Department of Surgery, Ben Carson College of Health and Medical Sciences, Babcock University, Ilishan-Remo, Ogun state, NigeriaDepartment of Anatomic Pathology, Ben Carson College of Health and Medical Sciences, Babcock University, Ilishan-Remo, Ogun state, NigeriaDepartment of ENT, Olabisi Onabanjo University Teaching Hospital, Sagamu, Ogun state, NigeriaENT Unit, Department of Surgery, College of Medicine, University of Lagos, Lagos state, Nigeria Background: Temporal bone fibrous dysplasia is relatively uncommon and typically manifests as a monostotic form of the disease. It often presents with noticeable temporal bone deformity, clinically appearing as a hard bony swelling behind or around the ear, external auditory canal stenosis, and conduction deafness. While symptoms such as aural fullness, tinnitus, and hearing loss are commonly reported, specific vestibular symptoms like vertigo and nystagmus are considerably less frequent. Case Presentation: In this report, we describe the diagnostic features, management, and outcome of a 37-year-old Nigerian patient with fibrous dysplasia of the right temporal bone, who presented with recurrent debilitating vertigo, along with tinnitus and aural fullness, but without any obvious temporal bone deformity, which posed an initial diagnostic dilemma. She underwent an exploratory mastoidectomy and received a postoperative stat dose of IV zoledronate, along with oral dexamethasone tapered over 10 days, resulting in significant symptom resolution. Conclusion: This unusual presentation underscores the importance of considering temporal bone dysplasia as a potential differential diagnosis for unilateral tinnitus, regardless of the presence of clear bony deformity. https://bumj.babcock.edu.ng/index.php/bumj/article/view/545Fibrous dysplasiaTemporal boneVestibular symptoms |
| spellingShingle | kenechukwu Uche-Okonkwo Moses Ayodele Akinola John Ifeanyi Nwadiokwu Oluwapelumi Olusoga-Peters Babatunde Akinola Bamgboye Cryptic Temporal Bone Fibrous Dysplasia with Predominant Vestibular Symptoms: A Case Report Babcock University Medical Journal Fibrous dysplasia Temporal bone Vestibular symptoms |
| title | Cryptic Temporal Bone Fibrous Dysplasia with Predominant Vestibular Symptoms: A Case Report |
| title_full | Cryptic Temporal Bone Fibrous Dysplasia with Predominant Vestibular Symptoms: A Case Report |
| title_fullStr | Cryptic Temporal Bone Fibrous Dysplasia with Predominant Vestibular Symptoms: A Case Report |
| title_full_unstemmed | Cryptic Temporal Bone Fibrous Dysplasia with Predominant Vestibular Symptoms: A Case Report |
| title_short | Cryptic Temporal Bone Fibrous Dysplasia with Predominant Vestibular Symptoms: A Case Report |
| title_sort | cryptic temporal bone fibrous dysplasia with predominant vestibular symptoms a case report |
| topic | Fibrous dysplasia Temporal bone Vestibular symptoms |
| url | https://bumj.babcock.edu.ng/index.php/bumj/article/view/545 |
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