α-Synuclein ubiquitination – functions in proteostasis and development of Lewy bodies

Synucleinopathies are neurodegenerative disorders characterized by the accumulation of α-synuclein containing Lewy bodies. Ubiquitination, a key post-translational modification, has been recognized as a pivotal regulator of α-synuclein’s cellular dynamics, influencing its degradation, aggregation, a...

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Main Authors: Hung-Hsiang Ho, Simon S. Wing
Format: Article
Language:English
Published: Frontiers Media S.A. 2024-11-01
Series:Frontiers in Molecular Neuroscience
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Online Access:https://www.frontiersin.org/articles/10.3389/fnmol.2024.1498459/full
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author Hung-Hsiang Ho
Hung-Hsiang Ho
Simon S. Wing
Simon S. Wing
author_facet Hung-Hsiang Ho
Hung-Hsiang Ho
Simon S. Wing
Simon S. Wing
author_sort Hung-Hsiang Ho
collection DOAJ
description Synucleinopathies are neurodegenerative disorders characterized by the accumulation of α-synuclein containing Lewy bodies. Ubiquitination, a key post-translational modification, has been recognized as a pivotal regulator of α-synuclein’s cellular dynamics, influencing its degradation, aggregation, and associated neurotoxicity. This review examines comprehensively the current understanding of α-synuclein ubiquitination and its role in the pathogenesis of synucleinopathies, particularly in the context of Parkinson’s disease. We explore the molecular mechanisms responsible for α-synuclein ubiquitination, with a focus on the roles of E3 ligases and deubiquitinases implicated in the degradation process which occurs primarily through the endosomal lysosomal pathway. The review further discusses how the dysregulation of these mechanisms contributes to α-synuclein aggregation and LB formation and offers suggestions for future investigations into the role of α-synuclein ubiquitination. Understanding these processes may shed light on potential therapeutic avenues that can modulate α-synuclein ubiquitination to alleviate its pathological impact in synucleinopathies.
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spelling doaj-art-af4bd9c715fb44778d19f2a9fdc58b232025-08-20T02:14:01ZengFrontiers Media S.A.Frontiers in Molecular Neuroscience1662-50992024-11-011710.3389/fnmol.2024.14984591498459α-Synuclein ubiquitination – functions in proteostasis and development of Lewy bodiesHung-Hsiang Ho0Hung-Hsiang Ho1Simon S. Wing2Simon S. Wing3Department of Medicine, McGill University and Research Institute of the McGill University Health Centre, Montreal, QC, CanadaIntegrated Program in Neuroscience, McGill University, Montreal, QC, CanadaDepartment of Medicine, McGill University and Research Institute of the McGill University Health Centre, Montreal, QC, CanadaIntegrated Program in Neuroscience, McGill University, Montreal, QC, CanadaSynucleinopathies are neurodegenerative disorders characterized by the accumulation of α-synuclein containing Lewy bodies. Ubiquitination, a key post-translational modification, has been recognized as a pivotal regulator of α-synuclein’s cellular dynamics, influencing its degradation, aggregation, and associated neurotoxicity. This review examines comprehensively the current understanding of α-synuclein ubiquitination and its role in the pathogenesis of synucleinopathies, particularly in the context of Parkinson’s disease. We explore the molecular mechanisms responsible for α-synuclein ubiquitination, with a focus on the roles of E3 ligases and deubiquitinases implicated in the degradation process which occurs primarily through the endosomal lysosomal pathway. The review further discusses how the dysregulation of these mechanisms contributes to α-synuclein aggregation and LB formation and offers suggestions for future investigations into the role of α-synuclein ubiquitination. Understanding these processes may shed light on potential therapeutic avenues that can modulate α-synuclein ubiquitination to alleviate its pathological impact in synucleinopathies.https://www.frontiersin.org/articles/10.3389/fnmol.2024.1498459/fullα-synucleinLewy bodyubiquitinParkinson’s diseaseendosomelysosome
spellingShingle Hung-Hsiang Ho
Hung-Hsiang Ho
Simon S. Wing
Simon S. Wing
α-Synuclein ubiquitination – functions in proteostasis and development of Lewy bodies
Frontiers in Molecular Neuroscience
α-synuclein
Lewy body
ubiquitin
Parkinson’s disease
endosome
lysosome
title α-Synuclein ubiquitination – functions in proteostasis and development of Lewy bodies
title_full α-Synuclein ubiquitination – functions in proteostasis and development of Lewy bodies
title_fullStr α-Synuclein ubiquitination – functions in proteostasis and development of Lewy bodies
title_full_unstemmed α-Synuclein ubiquitination – functions in proteostasis and development of Lewy bodies
title_short α-Synuclein ubiquitination – functions in proteostasis and development of Lewy bodies
title_sort α synuclein ubiquitination functions in proteostasis and development of lewy bodies
topic α-synuclein
Lewy body
ubiquitin
Parkinson’s disease
endosome
lysosome
url https://www.frontiersin.org/articles/10.3389/fnmol.2024.1498459/full
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