Congenital Short Bowel Syndrome: A Case Report and Review of the Literature

Congenital short bowel syndrome (SBS) is a rare condition of the newborn, with several reports demonstrating high mortality. A six-week-old boy presented with chronic diarrhea and failure to thrive. An upper gastrointestinal endoscopy showed a straight duodenum, and multiple small bowel biopsies wer...

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Main Authors: Mohammed Hasosah, Daniel A Lemberg, Eric Skarsgard, Richard Schreiber
Format: Article
Language:English
Published: Wiley 2008-01-01
Series:Canadian Journal of Gastroenterology
Online Access:http://dx.doi.org/10.1155/2008/590143
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author Mohammed Hasosah
Daniel A Lemberg
Eric Skarsgard
Richard Schreiber
author_facet Mohammed Hasosah
Daniel A Lemberg
Eric Skarsgard
Richard Schreiber
author_sort Mohammed Hasosah
collection DOAJ
description Congenital short bowel syndrome (SBS) is a rare condition of the newborn, with several reports demonstrating high mortality. A six-week-old boy presented with chronic diarrhea and failure to thrive. An upper gastrointestinal endoscopy showed a straight duodenum, and multiple small bowel biopsies were histologically normal. An upper gastrointestinal series showed malrotation. At laparotomy, the small bowel was 50 cm in length, confirming the diagnosis of congenital SBS. Parenteral nutrition was initiated and enteral feeding with an amino acid-based formula containing long-chain fatty acids was introduced early and gradually advanced. At the last follow-up examination at 24 months, he was thriving on a regular diet, with normal growth and development. Long-term survival of children with congenital SBS is now possible if enteral feeds are introduced early to promote intestinal adaptation, with subsequent weaning off parenteral nutrition.
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publishDate 2008-01-01
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series Canadian Journal of Gastroenterology
spelling doaj-art-ae09befea7d64d4188fba6af9645c2862025-08-20T03:38:59ZengWileyCanadian Journal of Gastroenterology0835-79002008-01-01221717410.1155/2008/590143Congenital Short Bowel Syndrome: A Case Report and Review of the LiteratureMohammed Hasosah0Daniel A Lemberg1Eric Skarsgard2Richard Schreiber3Department of Gastroenterology, British Columbia Children’s Hospital, University of British Columbia, Vancouver, British Columbia, CanadaDepartment of Gastroenterology, British Columbia Children’s Hospital, University of British Columbia, Vancouver, British Columbia, CanadaDepartment of Surgery, British Columbia Children’s Hospital, University of British Columbia, Vancouver, British Columbia, CanadaDepartment of Gastroenterology, British Columbia Children’s Hospital, University of British Columbia, Vancouver, British Columbia, CanadaCongenital short bowel syndrome (SBS) is a rare condition of the newborn, with several reports demonstrating high mortality. A six-week-old boy presented with chronic diarrhea and failure to thrive. An upper gastrointestinal endoscopy showed a straight duodenum, and multiple small bowel biopsies were histologically normal. An upper gastrointestinal series showed malrotation. At laparotomy, the small bowel was 50 cm in length, confirming the diagnosis of congenital SBS. Parenteral nutrition was initiated and enteral feeding with an amino acid-based formula containing long-chain fatty acids was introduced early and gradually advanced. At the last follow-up examination at 24 months, he was thriving on a regular diet, with normal growth and development. Long-term survival of children with congenital SBS is now possible if enteral feeds are introduced early to promote intestinal adaptation, with subsequent weaning off parenteral nutrition.http://dx.doi.org/10.1155/2008/590143
spellingShingle Mohammed Hasosah
Daniel A Lemberg
Eric Skarsgard
Richard Schreiber
Congenital Short Bowel Syndrome: A Case Report and Review of the Literature
Canadian Journal of Gastroenterology
title Congenital Short Bowel Syndrome: A Case Report and Review of the Literature
title_full Congenital Short Bowel Syndrome: A Case Report and Review of the Literature
title_fullStr Congenital Short Bowel Syndrome: A Case Report and Review of the Literature
title_full_unstemmed Congenital Short Bowel Syndrome: A Case Report and Review of the Literature
title_short Congenital Short Bowel Syndrome: A Case Report and Review of the Literature
title_sort congenital short bowel syndrome a case report and review of the literature
url http://dx.doi.org/10.1155/2008/590143
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