Rapid Remission With Upadacitinib in a Child With Refractory Crohn's Disease and ATM Mutation: A Case Report

ABSTRACT: Managing pediatric Crohn's disease (PCD) presents challenges due to severe complications and higher biologic therapy needs. Transitioning from anti–tumor necrosis factor agents to off-label therapies adds complexity. Although upadacitinib has demonstrated efficacy and tolerability in...

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Main Authors: Yan Liu, MD, XiaoMei Song, MD, LingYa Xiang, MD, Wei Tan, MD, Min Zou, MD, Hong Guo, MD
Format: Article
Language:English
Published: Elsevier 2024-01-01
Series:Current Therapeutic Research
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Online Access:http://www.sciencedirect.com/science/article/pii/S0011393X24000262
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author Yan Liu, MD
XiaoMei Song, MD
LingYa Xiang, MD
Wei Tan, MD
Min Zou, MD
Hong Guo, MD
author_facet Yan Liu, MD
XiaoMei Song, MD
LingYa Xiang, MD
Wei Tan, MD
Min Zou, MD
Hong Guo, MD
author_sort Yan Liu, MD
collection DOAJ
description ABSTRACT: Managing pediatric Crohn's disease (PCD) presents challenges due to severe complications and higher biologic therapy needs. Transitioning from anti–tumor necrosis factor agents to off-label therapies adds complexity. Although upadacitinib has demonstrated efficacy and tolerability in adult inflammatory bowel disease and pediatric atopic dermatitis, there are limited data for its application in PCD. This case report delineates successful remission with upadacitinib in a child with CD refractory to infliximab, ustekinumab, adalimumab, thalidomide, and prednisone. Notably, the patient carried an ataxia telangiectasia mutated (ATM) gene mutation. These findings provide valuable evidence for PCD management and highlight the potential benefits of upadacitinib in this population.
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issn 0011-393X
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series Current Therapeutic Research
spelling doaj-art-ab6ab36dca754b9492caee53f265cb5f2025-08-20T01:56:49ZengElsevierCurrent Therapeutic Research0011-393X2024-01-0110110075610.1016/j.curtheres.2024.100756Rapid Remission With Upadacitinib in a Child With Refractory Crohn's Disease and ATM Mutation: A Case ReportYan Liu, MD0XiaoMei Song, MD1LingYa Xiang, MD2Wei Tan, MD3Min Zou, MD4Hong Guo, MD5Department of Gastroenterology, Chongqing General Hospital, Chongqing University, Chongqing, ChinaDepartment of Gastroenterology, Chongqing General Hospital, Chongqing University, Chongqing, ChinaDepartment of Gastroenterology, Chongqing General Hospital, Chongqing University, Chongqing, ChinaDepartment of Gastroenterology, Chongqing General Hospital, Chongqing University, Chongqing, ChinaDepartment of Gastroenterology, Chongqing General Hospital, Chongqing University, Chongqing, ChinaAddress correspondence to: Hong Guo, MD, Chongqing General Hospital, 118, Xingguang Avenue, Liangjiang New Area, Chongqing, 401147, China.; Department of Gastroenterology, Chongqing General Hospital, Chongqing University, Chongqing, ChinaABSTRACT: Managing pediatric Crohn's disease (PCD) presents challenges due to severe complications and higher biologic therapy needs. Transitioning from anti–tumor necrosis factor agents to off-label therapies adds complexity. Although upadacitinib has demonstrated efficacy and tolerability in adult inflammatory bowel disease and pediatric atopic dermatitis, there are limited data for its application in PCD. This case report delineates successful remission with upadacitinib in a child with CD refractory to infliximab, ustekinumab, adalimumab, thalidomide, and prednisone. Notably, the patient carried an ataxia telangiectasia mutated (ATM) gene mutation. These findings provide valuable evidence for PCD management and highlight the potential benefits of upadacitinib in this population.http://www.sciencedirect.com/science/article/pii/S0011393X24000262ataxia telangiectasia mutatedcase reportchildrefractory Crohn's diseaseupadacitinib
spellingShingle Yan Liu, MD
XiaoMei Song, MD
LingYa Xiang, MD
Wei Tan, MD
Min Zou, MD
Hong Guo, MD
Rapid Remission With Upadacitinib in a Child With Refractory Crohn's Disease and ATM Mutation: A Case Report
Current Therapeutic Research
ataxia telangiectasia mutated
case report
child
refractory Crohn's disease
upadacitinib
title Rapid Remission With Upadacitinib in a Child With Refractory Crohn's Disease and ATM Mutation: A Case Report
title_full Rapid Remission With Upadacitinib in a Child With Refractory Crohn's Disease and ATM Mutation: A Case Report
title_fullStr Rapid Remission With Upadacitinib in a Child With Refractory Crohn's Disease and ATM Mutation: A Case Report
title_full_unstemmed Rapid Remission With Upadacitinib in a Child With Refractory Crohn's Disease and ATM Mutation: A Case Report
title_short Rapid Remission With Upadacitinib in a Child With Refractory Crohn's Disease and ATM Mutation: A Case Report
title_sort rapid remission with upadacitinib in a child with refractory crohn s disease and atm mutation a case report
topic ataxia telangiectasia mutated
case report
child
refractory Crohn's disease
upadacitinib
url http://www.sciencedirect.com/science/article/pii/S0011393X24000262
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