Morphological abnormalities in mitochondria of the skin of patients with sporadic amyotrophic lateral sclerosis

OBJECTIVES: Mitochondrial dysfunction has been reported in the central nervous system, hepatocytes and peripheral blood lymphocytes from patients with sporadic amyotrophic lateral sclerosis (SALS). However, the status of skin mitochondria has not been reported, in spite of the fact that SALS patient...

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Main Authors: Gabriel E. Rodríguez, Deniselle M. Claudia González, Gisella M. Gargiulo Monachelli, Juan J. López Costa, Alejandro F. de Nicola, Roberto E. P. Sica
Format: Article
Language:English
Published: Thieme Revinter Publicações 2012-01-01
Series:Arquivos de Neuro-Psiquiatria
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Online Access:http://www.scielo.br/scielo.php?script=sci_arttext&pid=S0004-282X2012000100010&lng=en&tlng=en
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author Gabriel E. Rodríguez
Deniselle M. Claudia González
Gisella M. Gargiulo Monachelli
Juan J. López Costa
Alejandro F. de Nicola
Roberto E. P. Sica
author_facet Gabriel E. Rodríguez
Deniselle M. Claudia González
Gisella M. Gargiulo Monachelli
Juan J. López Costa
Alejandro F. de Nicola
Roberto E. P. Sica
author_sort Gabriel E. Rodríguez
collection DOAJ
description OBJECTIVES: Mitochondrial dysfunction has been reported in the central nervous system, hepatocytes and peripheral blood lymphocytes from patients with sporadic amyotrophic lateral sclerosis (SALS). However, the status of skin mitochondria has not been reported, in spite of the fact that SALS patients present skin abnormalities. The objective of the present study was to compare mitochondrial ultrastructural parameters in keratinocytes from patients with SALS and healthy controls. METHODS: Our study was based on the analysis of 112 skin mitochondria from 5 SALS patients and 99 organelles from 4 control subjects by electron microscopy. RESULTS: Computerized image analysis showed that mitochondrial major axis length, area and perimeter of the organelle were significantly smaller in SALS respect of healthy control subjects. Morphologically, SALS mitochondria presented cristolysis and breakage of the outer membrane. CONCLUSIONS: Mitochondrial dysfunction in the skin may possibly reflect changes occurring in mitochondria of the central nervous system. The analysis of mitochondrial morphology in this tissue may be of value to follow disease progression and, eventually, the effectiveness of current therapies for SALS.
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series Arquivos de Neuro-Psiquiatria
spelling doaj-art-a9bd2271ea3347c780c172021f5b7daf2025-08-20T02:20:41ZengThieme Revinter PublicaçõesArquivos de Neuro-Psiquiatria1678-42272012-01-01701404410.1590/S0004-282X2012000100010S0004-282X2012000100010Morphological abnormalities in mitochondria of the skin of patients with sporadic amyotrophic lateral sclerosisGabriel E. Rodríguez0Deniselle M. Claudia González1Gisella M. Gargiulo Monachelli2Juan J. López Costa3Alejandro F. de Nicola4Roberto E. P. Sica5Hospital General de Agudos J. M. Ramos MejíaUniversidad de Buenos AiresHospital General de Agudos J. M. Ramos MejíaUniversidad de Buenos AiresUniversidad de Buenos AiresUniversidad de Buenos AiresOBJECTIVES: Mitochondrial dysfunction has been reported in the central nervous system, hepatocytes and peripheral blood lymphocytes from patients with sporadic amyotrophic lateral sclerosis (SALS). However, the status of skin mitochondria has not been reported, in spite of the fact that SALS patients present skin abnormalities. The objective of the present study was to compare mitochondrial ultrastructural parameters in keratinocytes from patients with SALS and healthy controls. METHODS: Our study was based on the analysis of 112 skin mitochondria from 5 SALS patients and 99 organelles from 4 control subjects by electron microscopy. RESULTS: Computerized image analysis showed that mitochondrial major axis length, area and perimeter of the organelle were significantly smaller in SALS respect of healthy control subjects. Morphologically, SALS mitochondria presented cristolysis and breakage of the outer membrane. CONCLUSIONS: Mitochondrial dysfunction in the skin may possibly reflect changes occurring in mitochondria of the central nervous system. The analysis of mitochondrial morphology in this tissue may be of value to follow disease progression and, eventually, the effectiveness of current therapies for SALS.http://www.scielo.br/scielo.php?script=sci_arttext&pid=S0004-282X2012000100010&lng=en&tlng=enesclerosis amiotrófica lateralmicroscopía electrónicaqueratinocitosmitocondria
spellingShingle Gabriel E. Rodríguez
Deniselle M. Claudia González
Gisella M. Gargiulo Monachelli
Juan J. López Costa
Alejandro F. de Nicola
Roberto E. P. Sica
Morphological abnormalities in mitochondria of the skin of patients with sporadic amyotrophic lateral sclerosis
Arquivos de Neuro-Psiquiatria
esclerosis amiotrófica lateral
microscopía electrónica
queratinocitos
mitocondria
title Morphological abnormalities in mitochondria of the skin of patients with sporadic amyotrophic lateral sclerosis
title_full Morphological abnormalities in mitochondria of the skin of patients with sporadic amyotrophic lateral sclerosis
title_fullStr Morphological abnormalities in mitochondria of the skin of patients with sporadic amyotrophic lateral sclerosis
title_full_unstemmed Morphological abnormalities in mitochondria of the skin of patients with sporadic amyotrophic lateral sclerosis
title_short Morphological abnormalities in mitochondria of the skin of patients with sporadic amyotrophic lateral sclerosis
title_sort morphological abnormalities in mitochondria of the skin of patients with sporadic amyotrophic lateral sclerosis
topic esclerosis amiotrófica lateral
microscopía electrónica
queratinocitos
mitocondria
url http://www.scielo.br/scielo.php?script=sci_arttext&pid=S0004-282X2012000100010&lng=en&tlng=en
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