Prevalence and clinical implications of major and minor ANCAs in Tunisian (North African) patients with systemic lupus erythematosus

IntroductionAnti-neutrophil cytoplasmic antibodies (ANCAs) have been reported in systemic lupus erythematosus (SLE). Their clinical significance remains unclear especially in the African populations. This study aimed to assess the prevalence, antigenic targets, and clinical correlations of ANCAs in...

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Main Authors: Zeineb Meddeb, Houssem Abida, Dhouha Krir, Ahlem Ben Hmid, Raja Aouaidia, Cherifa Abdelkéfi, Yosra Nasri, Ines Ben Sghaier, Hayet Kebaier, Samar Samoud, Rim Goucha, Saloua B’Chir Hamzaoui, Mélika Ben Ahmed, Thara Larbi, Imen Zamali, Yousr Galai
Format: Article
Language:English
Published: Frontiers Media S.A. 2025-08-01
Series:Frontiers in Immunology
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Online Access:https://www.frontiersin.org/articles/10.3389/fimmu.2025.1657670/full
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author Zeineb Meddeb
Zeineb Meddeb
Zeineb Meddeb
Houssem Abida
Houssem Abida
Dhouha Krir
Dhouha Krir
Ahlem Ben Hmid
Ahlem Ben Hmid
Ahlem Ben Hmid
Raja Aouaidia
Raja Aouaidia
Cherifa Abdelkéfi
Cherifa Abdelkéfi
Yosra Nasri
Ines Ben Sghaier
Hayet Kebaier
Samar Samoud
Samar Samoud
Rim Goucha
Rim Goucha
Saloua B’Chir Hamzaoui
Saloua B’Chir Hamzaoui
Mélika Ben Ahmed
Mélika Ben Ahmed
Mélika Ben Ahmed
Thara Larbi
Thara Larbi
Imen Zamali
Imen Zamali
Imen Zamali
Yousr Galai
Yousr Galai
author_facet Zeineb Meddeb
Zeineb Meddeb
Zeineb Meddeb
Houssem Abida
Houssem Abida
Dhouha Krir
Dhouha Krir
Ahlem Ben Hmid
Ahlem Ben Hmid
Ahlem Ben Hmid
Raja Aouaidia
Raja Aouaidia
Cherifa Abdelkéfi
Cherifa Abdelkéfi
Yosra Nasri
Ines Ben Sghaier
Hayet Kebaier
Samar Samoud
Samar Samoud
Rim Goucha
Rim Goucha
Saloua B’Chir Hamzaoui
Saloua B’Chir Hamzaoui
Mélika Ben Ahmed
Mélika Ben Ahmed
Mélika Ben Ahmed
Thara Larbi
Thara Larbi
Imen Zamali
Imen Zamali
Imen Zamali
Yousr Galai
Yousr Galai
author_sort Zeineb Meddeb
collection DOAJ
description IntroductionAnti-neutrophil cytoplasmic antibodies (ANCAs) have been reported in systemic lupus erythematosus (SLE). Their clinical significance remains unclear especially in the African populations. This study aimed to assess the prevalence, antigenic targets, and clinical correlations of ANCAs in SLE patients in a Tunisian (North African) cohort. MethodsWe conducted a cross-sectional case-control study involving 30 patients with systemic lupus erythematosus (SLE) and 30 healthy controls. Blood samples were screened for antineutrophil cytoplasmic antibodies (ANCAs) using indirect immunofluorescence (IIF) (FA 1201-1005-13, Euroimmun®). Enzyme-linked immunosorbent assay (ELISA) (Euroimmun®) was performed on IIF-positive samples to assess six ANCA antigenic targets: proteinase 3, lactoferrin, myeloperoxidase, elastase, cathepsin G, and bactericidal/permeability-increasing protein (BPI). Clinical and immunological evaluations were conducted for all SLE patients at the time of the study. No ANCA- associated vasculitis-SLE overlap cases were identified.Results and discussionANCAs were detected in 16 of 30 SLE patients (53%) and in 1 of 30 healthy controls (3%). Among the ANCA-positive patients, nine showed reactivity to lactoferrin, while the antigenic target remained undetermined in 7 cases. The median SLEDAI-2K score at inclusion was 8 [1.75–12]. In univariate study, ANCA positivity was significantly associated with acute cutaneous manifestations (p=0.021), lupus nephritis (p=0.001), as well as use of glucocorticoids (p=0.014) and mycophenolate mofetil (p=0.009). Besides, it was associated with lower C3 (p=0.0036) and C4 (p=0.0032) titers and higher anti-dsDNA titers (p<0.0001). In multivariate analysis, ANCA positivity was correlated to anti-ds DNA (p=0.008). When comparing anti-LF positive and anti-LF negative patients, univariate analysis found an association with articular involvement (p=0.011), renal activity index (p=0.036) and ELISA titers (p=0.0004). ANCAs were frequent in our SLE cohort, with lactoferrin as the only identifiable antigenic target, unlike previous reports, which suggests a role to ethnicity and environment components. Their presence was associated with higher disease activity and more severe renal involvement.
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spelling doaj-art-a90fd8a993bb412ea050380cd8916a7f2025-08-22T05:26:55ZengFrontiers Media S.A.Frontiers in Immunology1664-32242025-08-011610.3389/fimmu.2025.16576701657670Prevalence and clinical implications of major and minor ANCAs in Tunisian (North African) patients with systemic lupus erythematosusZeineb Meddeb0Zeineb Meddeb1Zeineb Meddeb2Houssem Abida3Houssem Abida4Dhouha Krir5Dhouha Krir6Ahlem Ben Hmid7Ahlem Ben Hmid8Ahlem Ben Hmid9Raja Aouaidia10Raja Aouaidia11Cherifa Abdelkéfi12Cherifa Abdelkéfi13Yosra Nasri14Ines Ben Sghaier15Hayet Kebaier16Samar Samoud17Samar Samoud18Rim Goucha19Rim Goucha20Saloua B’Chir Hamzaoui21Saloua B’Chir Hamzaoui22Mélika Ben Ahmed23Mélika Ben Ahmed24Mélika Ben Ahmed25Thara Larbi26Thara Larbi27Imen Zamali28Imen Zamali29Imen Zamali30Yousr Galai31Yousr Galai32Faculty of Medicine of Tunis, University of Tunis El Manar, Tunis, TunisiaInternal Medicine Department, Mongi Slim University Hospital, La Marsa, TunisiaLaboratory of Genetics, Immunology, and Human Pathology, Faculty of Sciences of Tunis, University of Tunis El Manar, Tunis, TunisiaFaculty of Medicine of Tunis, University of Tunis El Manar, Tunis, TunisiaInternal Medicine Department, Mongi Slim University Hospital, La Marsa, TunisiaFaculty of Medicine of Tunis, University of Tunis El Manar, Tunis, TunisiaClinical Immunology Department, Pasteur Institute of Tunis, Tunis, TunisiaFaculty of Medicine of Tunis, University of Tunis El Manar, Tunis, TunisiaClinical Immunology Department, Pasteur Institute of Tunis, Tunis, TunisiaLaboratory of Transmission, Control and Immunobiology of Infection, Pasteur Institute of Tunis, Tunis, TunisiaFaculty of Medicine of Tunis, University of Tunis El Manar, Tunis, TunisiaNephrology Department, Mongi Slim University Hospital, La Marsa, TunisiaFaculty of Medicine of Tunis, University of Tunis El Manar, Tunis, TunisiaInternal Medicine Department, Mongi Slim University Hospital, La Marsa, TunisiaClinical Immunology Department, Pasteur Institute of Tunis, Tunis, TunisiaClinical Immunology Department, Pasteur Institute of Tunis, Tunis, TunisiaClinical Immunology Department, Pasteur Institute of Tunis, Tunis, TunisiaClinical Immunology Department, Pasteur Institute of Tunis, Tunis, TunisiaLaboratory of Transmission, Control and Immunobiology of Infection, Pasteur Institute of Tunis, Tunis, TunisiaFaculty of Medicine of Tunis, University of Tunis El Manar, Tunis, TunisiaNephrology Department, Mongi Slim University Hospital, La Marsa, TunisiaFaculty of Medicine of Tunis, University of Tunis El Manar, Tunis, TunisiaInternal Medicine Department, Mongi Slim University Hospital, La Marsa, TunisiaFaculty of Medicine of Tunis, University of Tunis El Manar, Tunis, TunisiaClinical Immunology Department, Pasteur Institute of Tunis, Tunis, TunisiaLaboratory of Transmission, Control and Immunobiology of Infection, Pasteur Institute of Tunis, Tunis, TunisiaFaculty of Medicine of Tunis, University of Tunis El Manar, Tunis, TunisiaInternal Medicine Department, Mongi Slim University Hospital, La Marsa, TunisiaFaculty of Medicine of Tunis, University of Tunis El Manar, Tunis, TunisiaClinical Immunology Department, Pasteur Institute of Tunis, Tunis, TunisiaLaboratory of Transmission, Control and Immunobiology of Infection, Pasteur Institute of Tunis, Tunis, TunisiaClinical Immunology Department, Pasteur Institute of Tunis, Tunis, TunisiaFaculty of Pharmacy of Monastir, University of Monastir, Monastir, TunisiaIntroductionAnti-neutrophil cytoplasmic antibodies (ANCAs) have been reported in systemic lupus erythematosus (SLE). Their clinical significance remains unclear especially in the African populations. This study aimed to assess the prevalence, antigenic targets, and clinical correlations of ANCAs in SLE patients in a Tunisian (North African) cohort. MethodsWe conducted a cross-sectional case-control study involving 30 patients with systemic lupus erythematosus (SLE) and 30 healthy controls. Blood samples were screened for antineutrophil cytoplasmic antibodies (ANCAs) using indirect immunofluorescence (IIF) (FA 1201-1005-13, Euroimmun®). Enzyme-linked immunosorbent assay (ELISA) (Euroimmun®) was performed on IIF-positive samples to assess six ANCA antigenic targets: proteinase 3, lactoferrin, myeloperoxidase, elastase, cathepsin G, and bactericidal/permeability-increasing protein (BPI). Clinical and immunological evaluations were conducted for all SLE patients at the time of the study. No ANCA- associated vasculitis-SLE overlap cases were identified.Results and discussionANCAs were detected in 16 of 30 SLE patients (53%) and in 1 of 30 healthy controls (3%). Among the ANCA-positive patients, nine showed reactivity to lactoferrin, while the antigenic target remained undetermined in 7 cases. The median SLEDAI-2K score at inclusion was 8 [1.75–12]. In univariate study, ANCA positivity was significantly associated with acute cutaneous manifestations (p=0.021), lupus nephritis (p=0.001), as well as use of glucocorticoids (p=0.014) and mycophenolate mofetil (p=0.009). Besides, it was associated with lower C3 (p=0.0036) and C4 (p=0.0032) titers and higher anti-dsDNA titers (p<0.0001). In multivariate analysis, ANCA positivity was correlated to anti-ds DNA (p=0.008). When comparing anti-LF positive and anti-LF negative patients, univariate analysis found an association with articular involvement (p=0.011), renal activity index (p=0.036) and ELISA titers (p=0.0004). ANCAs were frequent in our SLE cohort, with lactoferrin as the only identifiable antigenic target, unlike previous reports, which suggests a role to ethnicity and environment components. Their presence was associated with higher disease activity and more severe renal involvement.https://www.frontiersin.org/articles/10.3389/fimmu.2025.1657670/fullsystemic lupus erythematosusANCAlactoferrin antibodiesdisease activityorgan involvementlupus nephritis
spellingShingle Zeineb Meddeb
Zeineb Meddeb
Zeineb Meddeb
Houssem Abida
Houssem Abida
Dhouha Krir
Dhouha Krir
Ahlem Ben Hmid
Ahlem Ben Hmid
Ahlem Ben Hmid
Raja Aouaidia
Raja Aouaidia
Cherifa Abdelkéfi
Cherifa Abdelkéfi
Yosra Nasri
Ines Ben Sghaier
Hayet Kebaier
Samar Samoud
Samar Samoud
Rim Goucha
Rim Goucha
Saloua B’Chir Hamzaoui
Saloua B’Chir Hamzaoui
Mélika Ben Ahmed
Mélika Ben Ahmed
Mélika Ben Ahmed
Thara Larbi
Thara Larbi
Imen Zamali
Imen Zamali
Imen Zamali
Yousr Galai
Yousr Galai
Prevalence and clinical implications of major and minor ANCAs in Tunisian (North African) patients with systemic lupus erythematosus
Frontiers in Immunology
systemic lupus erythematosus
ANCA
lactoferrin antibodies
disease activity
organ involvement
lupus nephritis
title Prevalence and clinical implications of major and minor ANCAs in Tunisian (North African) patients with systemic lupus erythematosus
title_full Prevalence and clinical implications of major and minor ANCAs in Tunisian (North African) patients with systemic lupus erythematosus
title_fullStr Prevalence and clinical implications of major and minor ANCAs in Tunisian (North African) patients with systemic lupus erythematosus
title_full_unstemmed Prevalence and clinical implications of major and minor ANCAs in Tunisian (North African) patients with systemic lupus erythematosus
title_short Prevalence and clinical implications of major and minor ANCAs in Tunisian (North African) patients with systemic lupus erythematosus
title_sort prevalence and clinical implications of major and minor ancas in tunisian north african patients with systemic lupus erythematosus
topic systemic lupus erythematosus
ANCA
lactoferrin antibodies
disease activity
organ involvement
lupus nephritis
url https://www.frontiersin.org/articles/10.3389/fimmu.2025.1657670/full
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