Pathogenesis and management of TRPV3-related Olmsted syndrome

Olmsted syndrome is characterized by symmetrically distributed, destructive, inflammatory palmoplantar keratoderma with periorificial keratotic plaques, most commonly due to gain-of-function mutations in the transient receptor potential vanilloid 3 (TRPV3) gene, which involves multiple pathological...

Full description

Saved in:
Bibliographic Details
Main Authors: Antong Lu, Kezhen Li, Cong Huang, Bo Yu, Weilong Zhong
Format: Article
Language:English
Published: Frontiers Media S.A. 2024-12-01
Series:Frontiers in Genetics
Subjects:
Online Access:https://www.frontiersin.org/articles/10.3389/fgene.2024.1459109/full
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1850249398701785088
author Antong Lu
Antong Lu
Antong Lu
Antong Lu
Kezhen Li
Kezhen Li
Kezhen Li
Kezhen Li
Cong Huang
Cong Huang
Cong Huang
Bo Yu
Bo Yu
Bo Yu
Bo Yu
Bo Yu
Weilong Zhong
Weilong Zhong
Weilong Zhong
author_facet Antong Lu
Antong Lu
Antong Lu
Antong Lu
Kezhen Li
Kezhen Li
Kezhen Li
Kezhen Li
Cong Huang
Cong Huang
Cong Huang
Bo Yu
Bo Yu
Bo Yu
Bo Yu
Bo Yu
Weilong Zhong
Weilong Zhong
Weilong Zhong
author_sort Antong Lu
collection DOAJ
description Olmsted syndrome is characterized by symmetrically distributed, destructive, inflammatory palmoplantar keratoderma with periorificial keratotic plaques, most commonly due to gain-of-function mutations in the transient receptor potential vanilloid 3 (TRPV3) gene, which involves multiple pathological functions of the skin, such as hyperkeratosis, dermatitis, hair loss, itching, and pain. Recent studies suggest that mutations of TRPV3 located in different structural domains lead to cases of varying severity, suggesting a potential genotype-phenotype correlation resulting from TRPV3 gene mutations. This paper reviews the genetics and pathogenesis of Olmsted syndrome, as well as the potential management and treatment. This review will lay a foundation for further developing the individualized treatment for TRPV3-related Olmsted syndrome.
format Article
id doaj-art-a82f7790c8884cd8a770c19d917be26b
institution OA Journals
issn 1664-8021
language English
publishDate 2024-12-01
publisher Frontiers Media S.A.
record_format Article
series Frontiers in Genetics
spelling doaj-art-a82f7790c8884cd8a770c19d917be26b2025-08-20T01:58:30ZengFrontiers Media S.A.Frontiers in Genetics1664-80212024-12-011510.3389/fgene.2024.14591091459109Pathogenesis and management of TRPV3-related Olmsted syndromeAntong Lu0Antong Lu1Antong Lu2Antong Lu3Kezhen Li4Kezhen Li5Kezhen Li6Kezhen Li7Cong Huang8Cong Huang9Cong Huang10Bo Yu11Bo Yu12Bo Yu13Bo Yu14Bo Yu15Weilong Zhong16Weilong Zhong17Weilong Zhong18Department of Dermatology, Peking University Shenzhen Hospital, Shenzhen, ChinaShenzhen Key Laboratory for Translational Medicine of Dermatology, Biomedical Research Institute, Shenzhen Peking University-The Hong Kong University of Science and Technology Medical Center, Shenzhen, ChinaInstitute of Dermatology, Shenzhen Peking University-The Hong Kong University of Science and Technology Medical Center, Shenzhen, ChinaShantou University Medical College, Shantou, ChinaDepartment of Dermatology, Peking University Shenzhen Hospital, Shenzhen, ChinaShenzhen Key Laboratory for Translational Medicine of Dermatology, Biomedical Research Institute, Shenzhen Peking University-The Hong Kong University of Science and Technology Medical Center, Shenzhen, ChinaInstitute of Dermatology, Shenzhen Peking University-The Hong Kong University of Science and Technology Medical Center, Shenzhen, ChinaShenzhen University Medical School, Shenzhen, ChinaDepartment of Dermatology, Peking University Shenzhen Hospital, Shenzhen, ChinaShenzhen Key Laboratory for Translational Medicine of Dermatology, Biomedical Research Institute, Shenzhen Peking University-The Hong Kong University of Science and Technology Medical Center, Shenzhen, ChinaInstitute of Dermatology, Shenzhen Peking University-The Hong Kong University of Science and Technology Medical Center, Shenzhen, ChinaDepartment of Dermatology, Peking University Shenzhen Hospital, Shenzhen, ChinaShenzhen Key Laboratory for Translational Medicine of Dermatology, Biomedical Research Institute, Shenzhen Peking University-The Hong Kong University of Science and Technology Medical Center, Shenzhen, ChinaInstitute of Dermatology, Shenzhen Peking University-The Hong Kong University of Science and Technology Medical Center, Shenzhen, ChinaShantou University Medical College, Shantou, ChinaShenzhen University Medical School, Shenzhen, ChinaDepartment of Dermatology, Peking University Shenzhen Hospital, Shenzhen, ChinaShenzhen Key Laboratory for Translational Medicine of Dermatology, Biomedical Research Institute, Shenzhen Peking University-The Hong Kong University of Science and Technology Medical Center, Shenzhen, ChinaInstitute of Dermatology, Shenzhen Peking University-The Hong Kong University of Science and Technology Medical Center, Shenzhen, ChinaOlmsted syndrome is characterized by symmetrically distributed, destructive, inflammatory palmoplantar keratoderma with periorificial keratotic plaques, most commonly due to gain-of-function mutations in the transient receptor potential vanilloid 3 (TRPV3) gene, which involves multiple pathological functions of the skin, such as hyperkeratosis, dermatitis, hair loss, itching, and pain. Recent studies suggest that mutations of TRPV3 located in different structural domains lead to cases of varying severity, suggesting a potential genotype-phenotype correlation resulting from TRPV3 gene mutations. This paper reviews the genetics and pathogenesis of Olmsted syndrome, as well as the potential management and treatment. This review will lay a foundation for further developing the individualized treatment for TRPV3-related Olmsted syndrome.https://www.frontiersin.org/articles/10.3389/fgene.2024.1459109/fullOlmsted syndromeTRPV3hyperkeratosisitchmutation
spellingShingle Antong Lu
Antong Lu
Antong Lu
Antong Lu
Kezhen Li
Kezhen Li
Kezhen Li
Kezhen Li
Cong Huang
Cong Huang
Cong Huang
Bo Yu
Bo Yu
Bo Yu
Bo Yu
Bo Yu
Weilong Zhong
Weilong Zhong
Weilong Zhong
Pathogenesis and management of TRPV3-related Olmsted syndrome
Frontiers in Genetics
Olmsted syndrome
TRPV3
hyperkeratosis
itch
mutation
title Pathogenesis and management of TRPV3-related Olmsted syndrome
title_full Pathogenesis and management of TRPV3-related Olmsted syndrome
title_fullStr Pathogenesis and management of TRPV3-related Olmsted syndrome
title_full_unstemmed Pathogenesis and management of TRPV3-related Olmsted syndrome
title_short Pathogenesis and management of TRPV3-related Olmsted syndrome
title_sort pathogenesis and management of trpv3 related olmsted syndrome
topic Olmsted syndrome
TRPV3
hyperkeratosis
itch
mutation
url https://www.frontiersin.org/articles/10.3389/fgene.2024.1459109/full
work_keys_str_mv AT antonglu pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT antonglu pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT antonglu pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT antonglu pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT kezhenli pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT kezhenli pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT kezhenli pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT kezhenli pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT conghuang pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT conghuang pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT conghuang pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT boyu pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT boyu pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT boyu pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT boyu pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT boyu pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT weilongzhong pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT weilongzhong pathogenesisandmanagementoftrpv3relatedolmstedsyndrome
AT weilongzhong pathogenesisandmanagementoftrpv3relatedolmstedsyndrome