Specific Distribution of GJB2 Mutations in Kurdistan Province of Iran; Report of a Relatively Isolated Population

Hearing Loss (HL) represents high genetic heterogeneity with an incidence of almost 1 out of 500 newborns in most populations. Approximately half of the cases have a genetic basis that most of them are autosomal recessive non-syndromic (ARNSHL) with DFNB1-related defect in many worldwide populations...

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Main Authors: T. Bahrami, N. Jalilian, G. Karbasi, M. R. Noori- Daloii
Format: Article
Language:English
Published: University of Tehran 2017-01-01
Series:Journal of Sciences, Islamic Republic of Iran
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Online Access:https://jsciences.ut.ac.ir/article_59397_5fd9118c9f55d6051b51e7e9a8ce5d38.pdf
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author T. Bahrami
N. Jalilian
G. Karbasi
M. R. Noori- Daloii
author_facet T. Bahrami
N. Jalilian
G. Karbasi
M. R. Noori- Daloii
author_sort T. Bahrami
collection DOAJ
description Hearing Loss (HL) represents high genetic heterogeneity with an incidence of almost 1 out of 500 newborns in most populations. Approximately half of the cases have a genetic basis that most of them are autosomal recessive non-syndromic (ARNSHL) with DFNB1-related defect in many worldwide populations. Given the heterogeneity of the trait together with the unique infrastructure of Iranian population, made it necessary to study other loci than GJB2 in various ethnic groups in order to elucidate the genetic etiology of HL in Iran. The present study was designed to determine the contribution of four DFNB loci in Kurdistan Province, west Iran. In this connection, we performed GJB2 analysis and homozygosity mapping using STR markers covering the DFNB21, DFNB4 and DFNB7/11 loci in 20 pedigrees with ARNSHL. GJB2 mutations were the cause of HL in 20% of the patients. However, surprisingly, we only observed 35delG and IVS1+1G>A mutation among the study population.  We also did not find any family linked to DFNB21, DFNB4 and DFNB7/11. Our results indicate the contribution of other loci in etiology of HL in Kurdistan that needs to be carefully investigated.
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spelling doaj-art-a535457660394da0b2aa72a68cea858c2025-08-20T02:25:54ZengUniversity of TehranJournal of Sciences, Islamic Republic of Iran1016-11042345-69142017-01-0128151159397Specific Distribution of GJB2 Mutations in Kurdistan Province of Iran; Report of a Relatively Isolated PopulationT. Bahrami0N. Jalilian1G. Karbasi2M. R. Noori- Daloii31 Department of Medical Genetics, Faculty of Medicine, Tehran University of Medical Sciences, Tehran, Islamic Republic of Iran2 Department of Clinical biochemistry, Faculty of medicine, Kermanshah University of Medical Sciences, Kermanshah, Islamic Republic of Iran3 Kurdistan Welfare and rehabilitation Organization, Sanandaj, Kurdistan, Islamic Republic of Iran1 Department of Medical Genetics, Faculty of Medicine, Tehran University of Medical Sciences, Tehran, Islamic Republic of IranHearing Loss (HL) represents high genetic heterogeneity with an incidence of almost 1 out of 500 newborns in most populations. Approximately half of the cases have a genetic basis that most of them are autosomal recessive non-syndromic (ARNSHL) with DFNB1-related defect in many worldwide populations. Given the heterogeneity of the trait together with the unique infrastructure of Iranian population, made it necessary to study other loci than GJB2 in various ethnic groups in order to elucidate the genetic etiology of HL in Iran. The present study was designed to determine the contribution of four DFNB loci in Kurdistan Province, west Iran. In this connection, we performed GJB2 analysis and homozygosity mapping using STR markers covering the DFNB21, DFNB4 and DFNB7/11 loci in 20 pedigrees with ARNSHL. GJB2 mutations were the cause of HL in 20% of the patients. However, surprisingly, we only observed 35delG and IVS1+1G>A mutation among the study population.  We also did not find any family linked to DFNB21, DFNB4 and DFNB7/11. Our results indicate the contribution of other loci in etiology of HL in Kurdistan that needs to be carefully investigated.https://jsciences.ut.ac.ir/article_59397_5fd9118c9f55d6051b51e7e9a8ce5d38.pdfarnshliranian kurdish peoplegjb2dfnbs
spellingShingle T. Bahrami
N. Jalilian
G. Karbasi
M. R. Noori- Daloii
Specific Distribution of GJB2 Mutations in Kurdistan Province of Iran; Report of a Relatively Isolated Population
Journal of Sciences, Islamic Republic of Iran
arnshl
iranian kurdish people
gjb2
dfnbs
title Specific Distribution of GJB2 Mutations in Kurdistan Province of Iran; Report of a Relatively Isolated Population
title_full Specific Distribution of GJB2 Mutations in Kurdistan Province of Iran; Report of a Relatively Isolated Population
title_fullStr Specific Distribution of GJB2 Mutations in Kurdistan Province of Iran; Report of a Relatively Isolated Population
title_full_unstemmed Specific Distribution of GJB2 Mutations in Kurdistan Province of Iran; Report of a Relatively Isolated Population
title_short Specific Distribution of GJB2 Mutations in Kurdistan Province of Iran; Report of a Relatively Isolated Population
title_sort specific distribution of gjb2 mutations in kurdistan province of iran report of a relatively isolated population
topic arnshl
iranian kurdish people
gjb2
dfnbs
url https://jsciences.ut.ac.ir/article_59397_5fd9118c9f55d6051b51e7e9a8ce5d38.pdf
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AT mrnooridaloii specificdistributionofgjb2mutationsinkurdistanprovinceofiranreportofarelativelyisolatedpopulation