Clinic Case of Rare Type VI Osteogenesis Imperfecta

Osteogenesis imperfect is genetically heterogeneous group of diseases which are characterized by bone brittleness and fractures. It was thought for a long time that this is happening due to mutations in collagen genes. However, within past decade the understanding of osteogenesis imperfecta etiology...

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Main Authors: Olga N. Ignatovich, Leyla S. Namazova-Baranova, Tea V. Margieva, Natalia V. Zhurkova, Kirill V. Savostyanov, Alexander V. Pushkov
Format: Article
Language:Russian
Published: Union of pediatricians of Russia 2019-04-01
Series:Педиатрическая фармакология
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Online Access:https://www.pedpharma.ru/jour/article/view/1693
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author Olga N. Ignatovich
Leyla S. Namazova-Baranova
Tea V. Margieva
Natalia V. Zhurkova
Kirill V. Savostyanov
Alexander V. Pushkov
author_facet Olga N. Ignatovich
Leyla S. Namazova-Baranova
Tea V. Margieva
Natalia V. Zhurkova
Kirill V. Savostyanov
Alexander V. Pushkov
author_sort Olga N. Ignatovich
collection DOAJ
description Osteogenesis imperfect is genetically heterogeneous group of diseases which are characterized by bone brittleness and fractures. It was thought for a long time that this is happening due to mutations in collagen genes. However, within past decade the understanding of osteogenesis imperfecta etiology has changed as a result of genetics development. The majority of all cases is related to mutations in collagen genes whereas rare mostly recessive forms are related to mutations in genes encoding collagen post-translational modification. Mutations in SERPINF1 gene were chosen as molecular cause of osteogenesis imperfecta type VI in 2011. Thus the new pathophysiology of this disease was revealed. Children with osteogenesis imperfecta type VI have high-frequency of fractures despite the management with bisphosphonates because mineralized bone osteoid is considerably reduced.
format Article
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institution Kabale University
issn 1727-5776
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publishDate 2019-04-01
publisher Union of pediatricians of Russia
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series Педиатрическая фармакология
spelling doaj-art-a2f045dcae64455cb90c0763de04da742025-08-20T03:39:29ZrusUnion of pediatricians of RussiaПедиатрическая фармакология1727-57762500-30892019-04-01161303510.15690/pf.v16i1.20011622Clinic Case of Rare Type VI Osteogenesis ImperfectaOlga N. Ignatovich0Leyla S. Namazova-Baranova1Tea V. Margieva2Natalia V. Zhurkova3Kirill V. Savostyanov4Alexander V. Pushkov5National Medical Research Center of Children’s HealthPirogov Russian National Research Medical University; Central Clinical Hospital of the Russian Academy of SciencesNational Medical Research Center of Children’s HealthNational Medical Research Center of Children’s HealthNational Medical Research Center of Children’s HealthNational Medical Research Center of Children’s HealthOsteogenesis imperfect is genetically heterogeneous group of diseases which are characterized by bone brittleness and fractures. It was thought for a long time that this is happening due to mutations in collagen genes. However, within past decade the understanding of osteogenesis imperfecta etiology has changed as a result of genetics development. The majority of all cases is related to mutations in collagen genes whereas rare mostly recessive forms are related to mutations in genes encoding collagen post-translational modification. Mutations in SERPINF1 gene were chosen as molecular cause of osteogenesis imperfecta type VI in 2011. Thus the new pathophysiology of this disease was revealed. Children with osteogenesis imperfecta type VI have high-frequency of fractures despite the management with bisphosphonates because mineralized bone osteoid is considerably reduced.https://www.pedpharma.ru/jour/article/view/1693osteogenesis imperfecta type viserpinf1 genepigment epithelium-derived factor (pedf)children
spellingShingle Olga N. Ignatovich
Leyla S. Namazova-Baranova
Tea V. Margieva
Natalia V. Zhurkova
Kirill V. Savostyanov
Alexander V. Pushkov
Clinic Case of Rare Type VI Osteogenesis Imperfecta
Педиатрическая фармакология
osteogenesis imperfecta type vi
serpinf1 gene
pigment epithelium-derived factor (pedf)
children
title Clinic Case of Rare Type VI Osteogenesis Imperfecta
title_full Clinic Case of Rare Type VI Osteogenesis Imperfecta
title_fullStr Clinic Case of Rare Type VI Osteogenesis Imperfecta
title_full_unstemmed Clinic Case of Rare Type VI Osteogenesis Imperfecta
title_short Clinic Case of Rare Type VI Osteogenesis Imperfecta
title_sort clinic case of rare type vi osteogenesis imperfecta
topic osteogenesis imperfecta type vi
serpinf1 gene
pigment epithelium-derived factor (pedf)
children
url https://www.pedpharma.ru/jour/article/view/1693
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AT nataliavzhurkova cliniccaseofraretypeviosteogenesisimperfecta
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