A Heterozygous Variant of TGFB3 in a Patient With an Atypical Presentation of Loeys–Dietz Syndrome: A Case Report

Loeys–Dietz syndrome (LDS) 5 is characterized by aortic aneurysms, hypertelorism, and cleft palate/bifid uvula. We describe a woman with a transforming growth factor beta3 (TGFβ3) mutation who displays a forme fruste phenotype of LDS5. A 43-year-old woman with joint pain and hypermobile joints under...

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Main Authors: Tarika D. Patel, Meagan N. McNicholas, Christina M. Laukaitis
Format: Article
Language:English
Published: American College of Physicians 2023-11-01
Series:Annals of Internal Medicine: Clinical Cases
Online Access:https://www.acpjournals.org/doi/10.7326/aimcc.2023.0035
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author Tarika D. Patel
Meagan N. McNicholas
Christina M. Laukaitis
author_facet Tarika D. Patel
Meagan N. McNicholas
Christina M. Laukaitis
author_sort Tarika D. Patel
collection DOAJ
description Loeys–Dietz syndrome (LDS) 5 is characterized by aortic aneurysms, hypertelorism, and cleft palate/bifid uvula. We describe a woman with a transforming growth factor beta3 (TGFβ3) mutation who displays a forme fruste phenotype of LDS5. A 43-year-old woman with joint pain and hypermobile joints underwent evaluation for hypermobile Ehlers–Danlos syndrome. Her features included pes planus, treated high-arched palate, and increased joint mobility. Genetic analysis identified a pathogenic TGFβ3 variant (c.427A>T, p.Arg143*), clarifying the diagnosis of LDS5. Comparing our patient with others with TGFB3 mutations illustrated the diversity of LDS5 features, often a milder forme fruste form, which warrants more investigation due to insufficient characterization.
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series Annals of Internal Medicine: Clinical Cases
spelling doaj-art-a0e442f83bc9425ea5aa30c59f7e81ae2025-08-20T02:27:22ZengAmerican College of PhysiciansAnnals of Internal Medicine: Clinical Cases2767-76642023-11-0121110.7326/aimcc.2023.0035A Heterozygous Variant of TGFB3 in a Patient With an Atypical Presentation of Loeys–Dietz Syndrome: A Case ReportTarika D. Patel0Meagan N. McNicholas1Christina M. Laukaitis21Carle Illinois College of Medicine, University of Illinois Urbana-Champaign, Urbana, Illinois1Carle Illinois College of Medicine, University of Illinois Urbana-Champaign, Urbana, Illinois1Carle Illinois College of Medicine, University of Illinois Urbana-Champaign, Urbana, IllinoisLoeys–Dietz syndrome (LDS) 5 is characterized by aortic aneurysms, hypertelorism, and cleft palate/bifid uvula. We describe a woman with a transforming growth factor beta3 (TGFβ3) mutation who displays a forme fruste phenotype of LDS5. A 43-year-old woman with joint pain and hypermobile joints underwent evaluation for hypermobile Ehlers–Danlos syndrome. Her features included pes planus, treated high-arched palate, and increased joint mobility. Genetic analysis identified a pathogenic TGFβ3 variant (c.427A>T, p.Arg143*), clarifying the diagnosis of LDS5. Comparing our patient with others with TGFB3 mutations illustrated the diversity of LDS5 features, often a milder forme fruste form, which warrants more investigation due to insufficient characterization.https://www.acpjournals.org/doi/10.7326/aimcc.2023.0035
spellingShingle Tarika D. Patel
Meagan N. McNicholas
Christina M. Laukaitis
A Heterozygous Variant of TGFB3 in a Patient With an Atypical Presentation of Loeys–Dietz Syndrome: A Case Report
Annals of Internal Medicine: Clinical Cases
title A Heterozygous Variant of TGFB3 in a Patient With an Atypical Presentation of Loeys–Dietz Syndrome: A Case Report
title_full A Heterozygous Variant of TGFB3 in a Patient With an Atypical Presentation of Loeys–Dietz Syndrome: A Case Report
title_fullStr A Heterozygous Variant of TGFB3 in a Patient With an Atypical Presentation of Loeys–Dietz Syndrome: A Case Report
title_full_unstemmed A Heterozygous Variant of TGFB3 in a Patient With an Atypical Presentation of Loeys–Dietz Syndrome: A Case Report
title_short A Heterozygous Variant of TGFB3 in a Patient With an Atypical Presentation of Loeys–Dietz Syndrome: A Case Report
title_sort heterozygous variant of tgfb3 in a patient with an atypical presentation of loeys dietz syndrome a case report
url https://www.acpjournals.org/doi/10.7326/aimcc.2023.0035
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