Emery-Dreifuss muscular dystrophy: anatomical-clinical correlation (case report)

We report on a man that had weakness of humeroperoneal distribution associated with limited range of motion of the cervical spine and elbows since he was 5 years old . At age 26 he developed tachycardia episodes. A complex arrhythmia was discovered, and a nodal ablation was done with a cardiac pacem...

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Main Authors: ALZIRA ALVES DE SIQUEIRA CARVALHO, JOSÉ ANTONIO LEVY, PAULO S. GUTIERREZ, SUELY KAZUE NAGAHASHI MARIE, EDUARDO ARGENTINO SOSA, MAURÍCIO SCANAVACA
Format: Article
Language:English
Published: Thieme Revinter Publicações 2000-12-01
Series:Arquivos de Neuro-Psiquiatria
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Online Access:http://www.scielo.br/scielo.php?script=sci_arttext&pid=S0004-282X2000000600023&tlng=en
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author ALZIRA ALVES DE SIQUEIRA CARVALHO
JOSÉ ANTONIO LEVY
PAULO S. GUTIERREZ
SUELY KAZUE NAGAHASHI MARIE
EDUARDO ARGENTINO SOSA
MAURÍCIO SCANAVACA
author_facet ALZIRA ALVES DE SIQUEIRA CARVALHO
JOSÉ ANTONIO LEVY
PAULO S. GUTIERREZ
SUELY KAZUE NAGAHASHI MARIE
EDUARDO ARGENTINO SOSA
MAURÍCIO SCANAVACA
author_sort ALZIRA ALVES DE SIQUEIRA CARVALHO
collection DOAJ
description We report on a man that had weakness of humeroperoneal distribution associated with limited range of motion of the cervical spine and elbows since he was 5 years old . At age 26 he developed tachycardia episodes. A complex arrhythmia was discovered, and a nodal ablation was done with a cardiac pacemaker implanted. The patient had an arrhythmia and sudden death followed this. Emery-Dreifuss muscular dystrophy is a rare recessive X-linked muscular disorder where mixed patterns in electromyography and muscle histology (neurogenic and/or myopathic) have caused nosological confusion. The autopsy findings are here described and correlated to the clinical features in an attempt to better understand the ambiguous findings concerning the process etiology .
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issn 1678-4227
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publisher Thieme Revinter Publicações
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series Arquivos de Neuro-Psiquiatria
spelling doaj-art-9cc7fed5c97d4ba5a217ef250934c2462025-08-20T03:38:14ZengThieme Revinter PublicaçõesArquivos de Neuro-Psiquiatria1678-42272000-12-015841123112710.1590/S0004-282X2000000600023Emery-Dreifuss muscular dystrophy: anatomical-clinical correlation (case report)ALZIRA ALVES DE SIQUEIRA CARVALHO0JOSÉ ANTONIO LEVY1PAULO S. GUTIERREZ2SUELY KAZUE NAGAHASHI MARIE3EDUARDO ARGENTINO SOSA4MAURÍCIO SCANAVACA5Universidade de São PauloUniversidade de São PauloUniversidade de São PauloUniversidade de São PauloUniversidade de São PauloUniversidade de São PauloWe report on a man that had weakness of humeroperoneal distribution associated with limited range of motion of the cervical spine and elbows since he was 5 years old . At age 26 he developed tachycardia episodes. A complex arrhythmia was discovered, and a nodal ablation was done with a cardiac pacemaker implanted. The patient had an arrhythmia and sudden death followed this. Emery-Dreifuss muscular dystrophy is a rare recessive X-linked muscular disorder where mixed patterns in electromyography and muscle histology (neurogenic and/or myopathic) have caused nosological confusion. The autopsy findings are here described and correlated to the clinical features in an attempt to better understand the ambiguous findings concerning the process etiology .http://www.scielo.br/scielo.php?script=sci_arttext&pid=S0004-282X2000000600023&tlng=enmuscular dystrophyarrhythmiamusclebiopsy
spellingShingle ALZIRA ALVES DE SIQUEIRA CARVALHO
JOSÉ ANTONIO LEVY
PAULO S. GUTIERREZ
SUELY KAZUE NAGAHASHI MARIE
EDUARDO ARGENTINO SOSA
MAURÍCIO SCANAVACA
Emery-Dreifuss muscular dystrophy: anatomical-clinical correlation (case report)
Arquivos de Neuro-Psiquiatria
muscular dystrophy
arrhythmia
muscle
biopsy
title Emery-Dreifuss muscular dystrophy: anatomical-clinical correlation (case report)
title_full Emery-Dreifuss muscular dystrophy: anatomical-clinical correlation (case report)
title_fullStr Emery-Dreifuss muscular dystrophy: anatomical-clinical correlation (case report)
title_full_unstemmed Emery-Dreifuss muscular dystrophy: anatomical-clinical correlation (case report)
title_short Emery-Dreifuss muscular dystrophy: anatomical-clinical correlation (case report)
title_sort emery dreifuss muscular dystrophy anatomical clinical correlation case report
topic muscular dystrophy
arrhythmia
muscle
biopsy
url http://www.scielo.br/scielo.php?script=sci_arttext&pid=S0004-282X2000000600023&tlng=en
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AT paulosgutierrez emerydreifussmusculardystrophyanatomicalclinicalcorrelationcasereport
AT suelykazuenagahashimarie emerydreifussmusculardystrophyanatomicalclinicalcorrelationcasereport
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