The long-term survival in primary retroperitoneal mucinous cystadenocarcinoma: a case report

Abstract Background Primary retroperitoneal mucinous cystadenocarcinoma (PRMC) is extremely rare, and its biological behavior, pathogenesis, optimum treatments, and prognosis remain to be elucidated. We herein report a case of PRMC with an 80-month follow-up. Case presentation A 29-year-old woman wa...

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Main Authors: Hirotaka Tokai, Yasuhiro Nagata, Ken Taniguchi, Naomi Matsumura, Amane Kitasato, Takayuki Tokunaga, Hiroaki Takeshita, Tamotsu Kuroki, Shigeto Maeda, Masahiro Ito, Hikaru Fujioka
Format: Article
Language:English
Published: Japan Surgical Society 2017-11-01
Series:Surgical Case Reports
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Online Access:http://link.springer.com/article/10.1186/s40792-017-0394-z
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author Hirotaka Tokai
Yasuhiro Nagata
Ken Taniguchi
Naomi Matsumura
Amane Kitasato
Takayuki Tokunaga
Hiroaki Takeshita
Tamotsu Kuroki
Shigeto Maeda
Masahiro Ito
Hikaru Fujioka
author_facet Hirotaka Tokai
Yasuhiro Nagata
Ken Taniguchi
Naomi Matsumura
Amane Kitasato
Takayuki Tokunaga
Hiroaki Takeshita
Tamotsu Kuroki
Shigeto Maeda
Masahiro Ito
Hikaru Fujioka
author_sort Hirotaka Tokai
collection DOAJ
description Abstract Background Primary retroperitoneal mucinous cystadenocarcinoma (PRMC) is extremely rare, and its biological behavior, pathogenesis, optimum treatments, and prognosis remain to be elucidated. We herein report a case of PRMC with an 80-month follow-up. Case presentation A 29-year-old woman was diagnosed with unknown retroperitoneal tumor with benign right ovarian cyst and uterine fibroids, and she underwent laparotomy. The tumor was completely resected with a subsequent histopathological diagnosis of primary retroperitoneal mucinous cystadenocarcinoma (PRMC). Eighty months after surgery, she remains recurrence-free. Conclusion PRMC is an extremely rare tumor. Only around 60 cases have so far been published in the literature. The preoperative diagnosis of PRMC is difficult, and a definitive diagnosis can usually only be made based on the findings of histopathological examinations after surgery. Presently, only radical resection is useful for both diagnostic and therapeutic purposes. The optimal long-term management after surgery is still not well established. Further studies on PRMC are therefore needed to elucidate the etiology and establish effective treatments.
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issn 2198-7793
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publisher Japan Surgical Society
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spelling doaj-art-9bea08d370f148fcac43ea3c748a06382025-08-20T03:34:04ZengJapan Surgical SocietySurgical Case Reports2198-77932017-11-01311710.1186/s40792-017-0394-zThe long-term survival in primary retroperitoneal mucinous cystadenocarcinoma: a case reportHirotaka Tokai0Yasuhiro Nagata1Ken Taniguchi2Naomi Matsumura3Amane Kitasato4Takayuki Tokunaga5Hiroaki Takeshita6Tamotsu Kuroki7Shigeto Maeda8Masahiro Ito9Hikaru Fujioka10Department of Surgery, National Hospital Organization Nagasaki Medical CenterCenter for Comprehensive Community Care Education Nagasaki University Graduate School of Biomedical SciencesDepartment of Surgery, National Hospital Organization Nagasaki Medical CenterDepartment of Surgery, National Hospital Organization Nagasaki Medical CenterDepartment of Surgery, National Hospital Organization Nagasaki Medical CenterDepartment of Surgery, National Hospital Organization Nagasaki Medical CenterDepartment of Surgery, National Hospital Organization Nagasaki Medical CenterDepartment of Surgery, National Hospital Organization Nagasaki Medical CenterDepartment of Surgery, National Hospital Organization Nagasaki Medical CenterDepartment of pathology, National Hospital Organization Nagasaki Medical CenterDepartment of Surgery, National Hospital Organization Nagasaki Medical CenterAbstract Background Primary retroperitoneal mucinous cystadenocarcinoma (PRMC) is extremely rare, and its biological behavior, pathogenesis, optimum treatments, and prognosis remain to be elucidated. We herein report a case of PRMC with an 80-month follow-up. Case presentation A 29-year-old woman was diagnosed with unknown retroperitoneal tumor with benign right ovarian cyst and uterine fibroids, and she underwent laparotomy. The tumor was completely resected with a subsequent histopathological diagnosis of primary retroperitoneal mucinous cystadenocarcinoma (PRMC). Eighty months after surgery, she remains recurrence-free. Conclusion PRMC is an extremely rare tumor. Only around 60 cases have so far been published in the literature. The preoperative diagnosis of PRMC is difficult, and a definitive diagnosis can usually only be made based on the findings of histopathological examinations after surgery. Presently, only radical resection is useful for both diagnostic and therapeutic purposes. The optimal long-term management after surgery is still not well established. Further studies on PRMC are therefore needed to elucidate the etiology and establish effective treatments.http://link.springer.com/article/10.1186/s40792-017-0394-zRetroperitonealCystadenocarcinomaMucinous
spellingShingle Hirotaka Tokai
Yasuhiro Nagata
Ken Taniguchi
Naomi Matsumura
Amane Kitasato
Takayuki Tokunaga
Hiroaki Takeshita
Tamotsu Kuroki
Shigeto Maeda
Masahiro Ito
Hikaru Fujioka
The long-term survival in primary retroperitoneal mucinous cystadenocarcinoma: a case report
Surgical Case Reports
Retroperitoneal
Cystadenocarcinoma
Mucinous
title The long-term survival in primary retroperitoneal mucinous cystadenocarcinoma: a case report
title_full The long-term survival in primary retroperitoneal mucinous cystadenocarcinoma: a case report
title_fullStr The long-term survival in primary retroperitoneal mucinous cystadenocarcinoma: a case report
title_full_unstemmed The long-term survival in primary retroperitoneal mucinous cystadenocarcinoma: a case report
title_short The long-term survival in primary retroperitoneal mucinous cystadenocarcinoma: a case report
title_sort long term survival in primary retroperitoneal mucinous cystadenocarcinoma a case report
topic Retroperitoneal
Cystadenocarcinoma
Mucinous
url http://link.springer.com/article/10.1186/s40792-017-0394-z
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