A Rare Case Report of Unilateral Congenital Ectropion Uveae (CEU) with Iridotrabecular Dysgenesis, Juvenile Glaucoma and Ptosis

Congenital ectropion uveae is a rare disorder resulting from proliferation of iris pigment epithelium on the anterior surface of iris. We describe a case of a 28-year-old female presenting with diminution of vision in the left eye. She was using topical drugs for high intraocular pressure. On examin...

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Main Authors: V.K. Harshavardhan, S. Mohapatra, Parul Priyambada, Rakesh A. Betdur
Format: Article
Language:English
Published: Wolters Kluwer Medknow Publications 2019-04-01
Series:Delhi Journal of Ophthalmology
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Online Access:https://journals.lww.com/10.7869/djo.448
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author V.K. Harshavardhan
S. Mohapatra
Parul Priyambada
Rakesh A. Betdur
author_facet V.K. Harshavardhan
S. Mohapatra
Parul Priyambada
Rakesh A. Betdur
author_sort V.K. Harshavardhan
collection DOAJ
description Congenital ectropion uveae is a rare disorder resulting from proliferation of iris pigment epithelium on the anterior surface of iris. We describe a case of a 28-year-old female presenting with diminution of vision in the left eye. She was using topical drugs for high intraocular pressure. On examination, visual acuity was 20/60. There was mild ptosis present along with ectropion uveae, 360 degrees around the pupillary border. Intraocular pressure was 32 mm Hg. On fundoscopy, there was glaucomatous cupping with superior notching of the disc. Gonioscopy revealed an open angle with anterior insertion of iris over trabecular meshwork. Visual field analysis showed inferior arcuate scotoma. Examination of the right eye revealed no abnormality and visual acuity was 20/20. No systemic illness was found. The fall in IOP in the left eye following medical treatment remained unsatisfactory. Hence, trabeculectomy was performed. Following a period of 3 months post trabeculectomy, control of IOP was achieved (15 mm Hg). It is important to evaluate for glaucoma in congenital ectropion uveae cases to prevent blindness in young patients and improve their prognosis.
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publishDate 2019-04-01
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series Delhi Journal of Ophthalmology
spelling doaj-art-9bb12cb9a39d46afb98befef689103e92025-08-20T02:10:57ZengWolters Kluwer Medknow PublicationsDelhi Journal of Ophthalmology0972-02002454-27842019-04-01294727310.7869/djo.448A Rare Case Report of Unilateral Congenital Ectropion Uveae (CEU) with Iridotrabecular Dysgenesis, Juvenile Glaucoma and PtosisV.K. HarshavardhanS. MohapatraParul PriyambadaRakesh A. BetdurCongenital ectropion uveae is a rare disorder resulting from proliferation of iris pigment epithelium on the anterior surface of iris. We describe a case of a 28-year-old female presenting with diminution of vision in the left eye. She was using topical drugs for high intraocular pressure. On examination, visual acuity was 20/60. There was mild ptosis present along with ectropion uveae, 360 degrees around the pupillary border. Intraocular pressure was 32 mm Hg. On fundoscopy, there was glaucomatous cupping with superior notching of the disc. Gonioscopy revealed an open angle with anterior insertion of iris over trabecular meshwork. Visual field analysis showed inferior arcuate scotoma. Examination of the right eye revealed no abnormality and visual acuity was 20/20. No systemic illness was found. The fall in IOP in the left eye following medical treatment remained unsatisfactory. Hence, trabeculectomy was performed. Following a period of 3 months post trabeculectomy, control of IOP was achieved (15 mm Hg). It is important to evaluate for glaucoma in congenital ectropion uveae cases to prevent blindness in young patients and improve their prognosis.https://journals.lww.com/10.7869/djo.448congenital ectropion uveaeiridotrabecular dysgenesisglaucomaptosis
spellingShingle V.K. Harshavardhan
S. Mohapatra
Parul Priyambada
Rakesh A. Betdur
A Rare Case Report of Unilateral Congenital Ectropion Uveae (CEU) with Iridotrabecular Dysgenesis, Juvenile Glaucoma and Ptosis
Delhi Journal of Ophthalmology
congenital ectropion uveae
iridotrabecular dysgenesis
glaucoma
ptosis
title A Rare Case Report of Unilateral Congenital Ectropion Uveae (CEU) with Iridotrabecular Dysgenesis, Juvenile Glaucoma and Ptosis
title_full A Rare Case Report of Unilateral Congenital Ectropion Uveae (CEU) with Iridotrabecular Dysgenesis, Juvenile Glaucoma and Ptosis
title_fullStr A Rare Case Report of Unilateral Congenital Ectropion Uveae (CEU) with Iridotrabecular Dysgenesis, Juvenile Glaucoma and Ptosis
title_full_unstemmed A Rare Case Report of Unilateral Congenital Ectropion Uveae (CEU) with Iridotrabecular Dysgenesis, Juvenile Glaucoma and Ptosis
title_short A Rare Case Report of Unilateral Congenital Ectropion Uveae (CEU) with Iridotrabecular Dysgenesis, Juvenile Glaucoma and Ptosis
title_sort rare case report of unilateral congenital ectropion uveae ceu with iridotrabecular dysgenesis juvenile glaucoma and ptosis
topic congenital ectropion uveae
iridotrabecular dysgenesis
glaucoma
ptosis
url https://journals.lww.com/10.7869/djo.448
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