Muscle-Restricted Nicotinamide Adenine Dinucleotide Phosphate Oxidase 4 Knockout Partially Corrects Muscle Contractility After Spinal Cord Injury in Mice

Spinal cord injury (SCI) results in severe atrophy of skeletal muscle in paralyzed regions, and a decrease in the force generated by muscle per unit of cross-sectional area. Oxidation of skeletal muscle ryanodine 1 receptors (RyR1) reduces contractile force as a result of reduced binding of calstabi...

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Main Authors: Carlos A. Toro, Rita De Gasperi, Abdurrahman Aslan, Nicholas Johnson, Mustafa M. Siddiq, Christine Chow, Wei Zhao, Lauren Harlow, Zachary Graham, Xin-Hua Liu, Junichi Sadoshima, Ravi Iyengar, Christopher P. Cardozo
Format: Article
Language:English
Published: Mary Ann Liebert 2024-11-01
Series:Neurotrauma Reports
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Online Access:https://www.liebertpub.com/doi/10.1089/neur.2023.0089
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author Carlos A. Toro
Rita De Gasperi
Abdurrahman Aslan
Nicholas Johnson
Mustafa M. Siddiq
Christine Chow
Wei Zhao
Lauren Harlow
Zachary Graham
Xin-Hua Liu
Junichi Sadoshima
Ravi Iyengar
Christopher P. Cardozo
author_facet Carlos A. Toro
Rita De Gasperi
Abdurrahman Aslan
Nicholas Johnson
Mustafa M. Siddiq
Christine Chow
Wei Zhao
Lauren Harlow
Zachary Graham
Xin-Hua Liu
Junichi Sadoshima
Ravi Iyengar
Christopher P. Cardozo
author_sort Carlos A. Toro
collection DOAJ
description Spinal cord injury (SCI) results in severe atrophy of skeletal muscle in paralyzed regions, and a decrease in the force generated by muscle per unit of cross-sectional area. Oxidation of skeletal muscle ryanodine 1 receptors (RyR1) reduces contractile force as a result of reduced binding of calstabin 1 to RyR1. One cause of RyR1 oxidation is nicotinamide adenine dinucleotide phosphate (NADPH) oxidase 4 (Nox4). We have previously shown that, in rats, RyR1 was oxidized and bound less to calstabin 1 at 56 days after SCI by spinal cord transection. Here, we used a conditional knockout (KO) mouse model of Nox4 in skeletal muscle to investigate the role of Nox4 in reduced muscle specific force after SCI. Peak twitch force of extensor digitorum longus muscles in control mice after SCI was reduced by 42% compared with sham-operated controls, but was increased by ∼43% in SCI Nox4 conditional KO mice compared with SCI controls, although it remained less than that for sham-operated controls. Unlike what was previously observed in rats after SCI, the expression of Nox4 was not increased in gastrocnemius muscle, and binding of calstabin 1 to RyR1 was not reduced in this muscle. The results suggest that Nox4 is directly involved in reduction in muscle twitch force after SCI, although further studies are needed to understand the mechanistic basis for this linkage.
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spelling doaj-art-9b7a8b5dd1bb4decbb3b7052e1b2e22d2025-08-20T02:31:48ZengMary Ann LiebertNeurotrauma Reports2689-288X2024-11-015130431610.1089/neur.2023.0089Muscle-Restricted Nicotinamide Adenine Dinucleotide Phosphate Oxidase 4 Knockout Partially Corrects Muscle Contractility After Spinal Cord Injury in MiceCarlos A. Toro0Rita De Gasperi1Abdurrahman Aslan2Nicholas Johnson3Mustafa M. Siddiq4Christine Chow5Wei Zhao6Lauren Harlow7Zachary Graham8Xin-Hua Liu9Junichi Sadoshima10Ravi Iyengar11Christopher P. Cardozo12Spinal Cord Damage Research Center, James J Peters VA Medical Center, Departments of Icahn School of Medicine at Mount Sinai, Bronx, New York, USA.Spinal Cord Damage Research Center, James J Peters VA Medical Center, Departments of Icahn School of Medicine at Mount Sinai, Bronx, New York, USA.Spinal Cord Damage Research Center, James J Peters VA Medical Center, Departments of Icahn School of Medicine at Mount Sinai, Bronx, New York, USA.Spinal Cord Damage Research Center, James J Peters VA Medical Center, Departments of Icahn School of Medicine at Mount Sinai, Bronx, New York, USA.Pharmacological Science and Systems Biomedicine Institute, Icahn School of Medicine at Mount Sinai, Bronx, New York, USA.Spinal Cord Damage Research Center, James J Peters VA Medical Center, Departments of Icahn School of Medicine at Mount Sinai, Bronx, New York, USA.Spinal Cord Damage Research Center, James J Peters VA Medical Center, Departments of Icahn School of Medicine at Mount Sinai, Bronx, New York, USA.Spinal Cord Damage Research Center, James J Peters VA Medical Center, Departments of Icahn School of Medicine at Mount Sinai, Bronx, New York, USA.Healthspan, Resilience, and Performance, Florida Institute for Human and Machine Cognition, Pensacola, Florida, USA.Spinal Cord Damage Research Center, James J Peters VA Medical Center, Departments of Icahn School of Medicine at Mount Sinai, Bronx, New York, USA.Department of Cell Biology and Molecular Medicine, Rutgers New Jersey Medical School, Newark, New Jersey, USA.Pharmacological Science and Systems Biomedicine Institute, Icahn School of Medicine at Mount Sinai, Bronx, New York, USA.Spinal Cord Damage Research Center, James J Peters VA Medical Center, Departments of Icahn School of Medicine at Mount Sinai, Bronx, New York, USA.Spinal cord injury (SCI) results in severe atrophy of skeletal muscle in paralyzed regions, and a decrease in the force generated by muscle per unit of cross-sectional area. Oxidation of skeletal muscle ryanodine 1 receptors (RyR1) reduces contractile force as a result of reduced binding of calstabin 1 to RyR1. One cause of RyR1 oxidation is nicotinamide adenine dinucleotide phosphate (NADPH) oxidase 4 (Nox4). We have previously shown that, in rats, RyR1 was oxidized and bound less to calstabin 1 at 56 days after SCI by spinal cord transection. Here, we used a conditional knockout (KO) mouse model of Nox4 in skeletal muscle to investigate the role of Nox4 in reduced muscle specific force after SCI. Peak twitch force of extensor digitorum longus muscles in control mice after SCI was reduced by 42% compared with sham-operated controls, but was increased by ∼43% in SCI Nox4 conditional KO mice compared with SCI controls, although it remained less than that for sham-operated controls. Unlike what was previously observed in rats after SCI, the expression of Nox4 was not increased in gastrocnemius muscle, and binding of calstabin 1 to RyR1 was not reduced in this muscle. The results suggest that Nox4 is directly involved in reduction in muscle twitch force after SCI, although further studies are needed to understand the mechanistic basis for this linkage.https://www.liebertpub.com/doi/10.1089/neur.2023.0089muscle cKOmuscle contractilityNox4SCI mouse modelstransection SCI
spellingShingle Carlos A. Toro
Rita De Gasperi
Abdurrahman Aslan
Nicholas Johnson
Mustafa M. Siddiq
Christine Chow
Wei Zhao
Lauren Harlow
Zachary Graham
Xin-Hua Liu
Junichi Sadoshima
Ravi Iyengar
Christopher P. Cardozo
Muscle-Restricted Nicotinamide Adenine Dinucleotide Phosphate Oxidase 4 Knockout Partially Corrects Muscle Contractility After Spinal Cord Injury in Mice
Neurotrauma Reports
muscle cKO
muscle contractility
Nox4
SCI mouse models
transection SCI
title Muscle-Restricted Nicotinamide Adenine Dinucleotide Phosphate Oxidase 4 Knockout Partially Corrects Muscle Contractility After Spinal Cord Injury in Mice
title_full Muscle-Restricted Nicotinamide Adenine Dinucleotide Phosphate Oxidase 4 Knockout Partially Corrects Muscle Contractility After Spinal Cord Injury in Mice
title_fullStr Muscle-Restricted Nicotinamide Adenine Dinucleotide Phosphate Oxidase 4 Knockout Partially Corrects Muscle Contractility After Spinal Cord Injury in Mice
title_full_unstemmed Muscle-Restricted Nicotinamide Adenine Dinucleotide Phosphate Oxidase 4 Knockout Partially Corrects Muscle Contractility After Spinal Cord Injury in Mice
title_short Muscle-Restricted Nicotinamide Adenine Dinucleotide Phosphate Oxidase 4 Knockout Partially Corrects Muscle Contractility After Spinal Cord Injury in Mice
title_sort muscle restricted nicotinamide adenine dinucleotide phosphate oxidase 4 knockout partially corrects muscle contractility after spinal cord injury in mice
topic muscle cKO
muscle contractility
Nox4
SCI mouse models
transection SCI
url https://www.liebertpub.com/doi/10.1089/neur.2023.0089
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