Intestinal volvulus in utero causing torsion of dilated bowel with ileal atresia: a case report

Abstract Background In utero intestinal volvulus with intestinal atresia is a rare and life-threatening condition that can cause torsion of the dilated bowel. The management and outcomes of this disease remain unclear. Case presentation A 19-year-old woman noticed a decrease in fetal motion at 35 we...

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Main Authors: Chiyoshi Toyama, Yuki Segawa, Shigeo Iijima, Takeshi Murakoshi, Keigo Nara
Format: Article
Language:English
Published: Japan Surgical Society 2023-04-01
Series:Surgical Case Reports
Subjects:
Online Access:https://doi.org/10.1186/s40792-023-01645-4
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author Chiyoshi Toyama
Yuki Segawa
Shigeo Iijima
Takeshi Murakoshi
Keigo Nara
author_facet Chiyoshi Toyama
Yuki Segawa
Shigeo Iijima
Takeshi Murakoshi
Keigo Nara
author_sort Chiyoshi Toyama
collection DOAJ
description Abstract Background In utero intestinal volvulus with intestinal atresia is a rare and life-threatening condition that can cause torsion of the dilated bowel. The management and outcomes of this disease remain unclear. Case presentation A 19-year-old woman noticed a decrease in fetal motion at 35 weeks. Fetal ultrasound showed dilated fetal bowel and the whirlpool sign. The patient was referred to our hospital for an emergency cesarean section. The neonate’s abdomen was dark and severely distended, and a laparotomy was performed. Necrotic ileum and cord-type intestinal atresia (Type II) were observed in the dilated terminal ileum. The necrotic ileum was resected, and a second-look surgery was performed the following day. Then, we anastomosed the remaining intestine, and the total intestine length was 52 cm. There were no surgical complications, and the patient was discharged without requiring total parenteral nutrition or fluid infusion. The patient’s height and weight were within the − 2 standard deviation range of the growth curve at 5 months. Conclusions Emergency and appropriate management of intestinal volvulus in utero causing torsion of the dilated bowel resulted in good outcomes in a patient with intestinal atresia. Perinatal physicians should be aware of this emergency condition and plan their treatment approach accordingly.
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spelling doaj-art-9a11862397cf4d21aa43a363cb7410f12025-08-20T03:35:24ZengJapan Surgical SocietySurgical Case Reports2198-77932023-04-01911410.1186/s40792-023-01645-4Intestinal volvulus in utero causing torsion of dilated bowel with ileal atresia: a case reportChiyoshi Toyama0Yuki Segawa1Shigeo Iijima2Takeshi Murakoshi3Keigo Nara4Department of Pediatric Surgery, Hamamatsu University School of Medicine, University HospitalDepartment of Pediatrics, Hamamatsu University School of Medicine, University HospitalDepartment of Pediatrics, Hamamatsu University School of Medicine, University HospitalDepartment of Obstetrics and Gynecology, Seirei Hamamatsu General HospitalDepartment of Pediatric Surgery, Hamamatsu University School of Medicine, University HospitalAbstract Background In utero intestinal volvulus with intestinal atresia is a rare and life-threatening condition that can cause torsion of the dilated bowel. The management and outcomes of this disease remain unclear. Case presentation A 19-year-old woman noticed a decrease in fetal motion at 35 weeks. Fetal ultrasound showed dilated fetal bowel and the whirlpool sign. The patient was referred to our hospital for an emergency cesarean section. The neonate’s abdomen was dark and severely distended, and a laparotomy was performed. Necrotic ileum and cord-type intestinal atresia (Type II) were observed in the dilated terminal ileum. The necrotic ileum was resected, and a second-look surgery was performed the following day. Then, we anastomosed the remaining intestine, and the total intestine length was 52 cm. There were no surgical complications, and the patient was discharged without requiring total parenteral nutrition or fluid infusion. The patient’s height and weight were within the − 2 standard deviation range of the growth curve at 5 months. Conclusions Emergency and appropriate management of intestinal volvulus in utero causing torsion of the dilated bowel resulted in good outcomes in a patient with intestinal atresia. Perinatal physicians should be aware of this emergency condition and plan their treatment approach accordingly.https://doi.org/10.1186/s40792-023-01645-4Intestinal atresiaIn uteroIntestinal volvulusDilated bowelTorsion
spellingShingle Chiyoshi Toyama
Yuki Segawa
Shigeo Iijima
Takeshi Murakoshi
Keigo Nara
Intestinal volvulus in utero causing torsion of dilated bowel with ileal atresia: a case report
Surgical Case Reports
Intestinal atresia
In utero
Intestinal volvulus
Dilated bowel
Torsion
title Intestinal volvulus in utero causing torsion of dilated bowel with ileal atresia: a case report
title_full Intestinal volvulus in utero causing torsion of dilated bowel with ileal atresia: a case report
title_fullStr Intestinal volvulus in utero causing torsion of dilated bowel with ileal atresia: a case report
title_full_unstemmed Intestinal volvulus in utero causing torsion of dilated bowel with ileal atresia: a case report
title_short Intestinal volvulus in utero causing torsion of dilated bowel with ileal atresia: a case report
title_sort intestinal volvulus in utero causing torsion of dilated bowel with ileal atresia a case report
topic Intestinal atresia
In utero
Intestinal volvulus
Dilated bowel
Torsion
url https://doi.org/10.1186/s40792-023-01645-4
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