Maternal immune activation followed by peripubertal stress combinedly produce reactive microglia and confine cerebellar cognition

Abstract The functional alteration of microglia arises in brains exposed to external stress during early development. Pathophysiological findings of neurodevelopmental disorders such as schizophrenia and autism spectrum disorder suggest cerebellar functional deficits. However, the link between stres...

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Main Authors: Momoka Hikosaka, Md Sorwer Alam Parvez, Yuki Yamawaki, Souichi Oe, Yuan Liang, Yayoi Wada, Yukie Hirahara, Taro Koike, Hirohiko Imai, Naoya Oishi, Sina M. Schalbetter, Asuka Kumagai, Mari Yoshida, Takeshi Sakurai, Masaaki Kitada, Urs Meyer, Shuh Narumiya, Gen Ohtsuki
Format: Article
Language:English
Published: Nature Portfolio 2025-03-01
Series:Communications Biology
Online Access:https://doi.org/10.1038/s42003-025-07566-2
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author Momoka Hikosaka
Md Sorwer Alam Parvez
Yuki Yamawaki
Souichi Oe
Yuan Liang
Yayoi Wada
Yukie Hirahara
Taro Koike
Hirohiko Imai
Naoya Oishi
Sina M. Schalbetter
Asuka Kumagai
Mari Yoshida
Takeshi Sakurai
Masaaki Kitada
Urs Meyer
Shuh Narumiya
Gen Ohtsuki
author_facet Momoka Hikosaka
Md Sorwer Alam Parvez
Yuki Yamawaki
Souichi Oe
Yuan Liang
Yayoi Wada
Yukie Hirahara
Taro Koike
Hirohiko Imai
Naoya Oishi
Sina M. Schalbetter
Asuka Kumagai
Mari Yoshida
Takeshi Sakurai
Masaaki Kitada
Urs Meyer
Shuh Narumiya
Gen Ohtsuki
author_sort Momoka Hikosaka
collection DOAJ
description Abstract The functional alteration of microglia arises in brains exposed to external stress during early development. Pathophysiological findings of neurodevelopmental disorders such as schizophrenia and autism spectrum disorder suggest cerebellar functional deficits. However, the link between stress-induced microglia reactivity and cerebellar dysfunction is missing. Here, we investigate the developmental immune environment in translational mouse models that combine two risk factors: maternal infection and repeated social defeat stress (2HIT). We find the synergy of inflammatory stress insults, leading to microglial increase specifically in the cerebellum of both sexes. Microglial turnover correlates with the Purkinje neuron loss in 2HIT mice. Highly multiplexed imaging-mass-cytometry identifies a cell transition to TREM2(+) stress-associated microglia in the cerebellum. Single-cell-proteomic clustering reveals IL-6- and TGFβ-signaling association with microglial cell transitions. Reduced excitability of remaining Purkinje cells, cerebellum-involved brain-wide functional dysconnectivity, and behavioral abnormalities indicate cerebellar cognitive dysfunctions in 2HIT animals, which are ameliorated by both systemic and cerebellum-specific microglia replacement.
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spelling doaj-art-961a5548bd7241598a805e4eccd1cc1f2025-08-20T01:57:48ZengNature PortfolioCommunications Biology2399-36422025-03-018112610.1038/s42003-025-07566-2Maternal immune activation followed by peripubertal stress combinedly produce reactive microglia and confine cerebellar cognitionMomoka Hikosaka0Md Sorwer Alam Parvez1Yuki Yamawaki2Souichi Oe3Yuan Liang4Yayoi Wada5Yukie Hirahara6Taro Koike7Hirohiko Imai8Naoya Oishi9Sina M. Schalbetter10Asuka Kumagai11Mari Yoshida12Takeshi Sakurai13Masaaki Kitada14Urs Meyer15Shuh Narumiya16Gen Ohtsuki17Department of Drug Discovery Medicine, Kyoto University, Graduate School of MedicineDepartment of Drug Discovery Medicine, Kyoto University, Graduate School of MedicineDepartment of Drug Discovery Medicine, Kyoto University, Graduate School of MedicineDepartment of Anatomy, Kansai Medical UniversityDepartment of Drug Discovery Medicine, Kyoto University, Graduate School of MedicineDepartment of Drug Discovery Medicine, Kyoto University, Graduate School of MedicineDepartment of Anatomy, Kansai Medical UniversityDepartment of Anatomy, Kansai Medical UniversityDepartment of Systems Science, Kyoto University Graduate School of Informatics, Yoshida-HonmachiDepartment of Psychiatry, Kyoto University Graduate School of MedicineInstitute of Veterinary Pharmacology and Toxicology, University of ZurichStandard BioTools Inc.Department of Neuropathology, Institute for Medical Science of Aging, Aichi Medical UniversityDepartment of Drug Discovery Medicine, Kyoto University, Graduate School of MedicineDepartment of Anatomy, Kansai Medical UniversityInstitute of Veterinary Pharmacology and Toxicology, University of ZurichDepartment of Drug Discovery Medicine, Kyoto University, Graduate School of MedicineDepartment of Drug Discovery Medicine, Kyoto University, Graduate School of MedicineAbstract The functional alteration of microglia arises in brains exposed to external stress during early development. Pathophysiological findings of neurodevelopmental disorders such as schizophrenia and autism spectrum disorder suggest cerebellar functional deficits. However, the link between stress-induced microglia reactivity and cerebellar dysfunction is missing. Here, we investigate the developmental immune environment in translational mouse models that combine two risk factors: maternal infection and repeated social defeat stress (2HIT). We find the synergy of inflammatory stress insults, leading to microglial increase specifically in the cerebellum of both sexes. Microglial turnover correlates with the Purkinje neuron loss in 2HIT mice. Highly multiplexed imaging-mass-cytometry identifies a cell transition to TREM2(+) stress-associated microglia in the cerebellum. Single-cell-proteomic clustering reveals IL-6- and TGFβ-signaling association with microglial cell transitions. Reduced excitability of remaining Purkinje cells, cerebellum-involved brain-wide functional dysconnectivity, and behavioral abnormalities indicate cerebellar cognitive dysfunctions in 2HIT animals, which are ameliorated by both systemic and cerebellum-specific microglia replacement.https://doi.org/10.1038/s42003-025-07566-2
spellingShingle Momoka Hikosaka
Md Sorwer Alam Parvez
Yuki Yamawaki
Souichi Oe
Yuan Liang
Yayoi Wada
Yukie Hirahara
Taro Koike
Hirohiko Imai
Naoya Oishi
Sina M. Schalbetter
Asuka Kumagai
Mari Yoshida
Takeshi Sakurai
Masaaki Kitada
Urs Meyer
Shuh Narumiya
Gen Ohtsuki
Maternal immune activation followed by peripubertal stress combinedly produce reactive microglia and confine cerebellar cognition
Communications Biology
title Maternal immune activation followed by peripubertal stress combinedly produce reactive microglia and confine cerebellar cognition
title_full Maternal immune activation followed by peripubertal stress combinedly produce reactive microglia and confine cerebellar cognition
title_fullStr Maternal immune activation followed by peripubertal stress combinedly produce reactive microglia and confine cerebellar cognition
title_full_unstemmed Maternal immune activation followed by peripubertal stress combinedly produce reactive microglia and confine cerebellar cognition
title_short Maternal immune activation followed by peripubertal stress combinedly produce reactive microglia and confine cerebellar cognition
title_sort maternal immune activation followed by peripubertal stress combinedly produce reactive microglia and confine cerebellar cognition
url https://doi.org/10.1038/s42003-025-07566-2
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