Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception
Enteric duplication cysts are rare malformations mostly diagnosed before the age of two, with varied clinical presentations. Ectopic gastrointestinal epithelium can be present, and management involves surgical resection. A three-month-old girl presented with rectal bleeding due to an ileocolic intus...
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| Format: | Article |
| Language: | English |
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Wiley
2020-01-01
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| Series: | Case Reports in Pediatrics |
| Online Access: | http://dx.doi.org/10.1155/2020/6898795 |
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| author | Filomena Valentina Paradiso Laura Merli Sara Silvaroli Vincenzo Fiorentino Riccardo Ricci Lorenzo Nanni |
| author_facet | Filomena Valentina Paradiso Laura Merli Sara Silvaroli Vincenzo Fiorentino Riccardo Ricci Lorenzo Nanni |
| author_sort | Filomena Valentina Paradiso |
| collection | DOAJ |
| description | Enteric duplication cysts are rare malformations mostly diagnosed before the age of two, with varied clinical presentations. Ectopic gastrointestinal epithelium can be present, and management involves surgical resection. A three-month-old girl presented with rectal bleeding due to an ileocolic intussusception. Abdominal ultrasound revealed a target sign in the right upper part of the abdomen. At hydrostatic contrast enema, an incomplete reduction of the intussusception was obtained: only a trickle of contrast material entered the terminal ileum. An exploratory laparotomy ensued with manual reduction of the intussusception. At the end of the maneuver, a soft intraluminal mass was palpated within the ileocecal valve. Thus, an ileocecal resection was performed. At histology, an intraluminal enteric duplication cyst was documented, containing ectopic gastric mucosa. Secondary intussusception should be suspected even in infants in case of abnormal findings at hydrostatic contrast enema. Intraluminal enteric duplication cysts may be a rare cause of intussusception. |
| format | Article |
| id | doaj-art-95fa104d67de49afb4db686f0a2d2f9b |
| institution | Kabale University |
| issn | 2090-6803 2090-6811 |
| language | English |
| publishDate | 2020-01-01 |
| publisher | Wiley |
| record_format | Article |
| series | Case Reports in Pediatrics |
| spelling | doaj-art-95fa104d67de49afb4db686f0a2d2f9b2025-02-03T06:06:44ZengWileyCase Reports in Pediatrics2090-68032090-68112020-01-01202010.1155/2020/68987956898795Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of IntussusceptionFilomena Valentina Paradiso0Laura Merli1Sara Silvaroli2Vincenzo Fiorentino3Riccardo Ricci4Lorenzo Nanni5Division of Pediatric Surgery, Fondazione Policlinico Universitario “Agostino Gemelli” IRCCS, Largo Agostino Gemelli 8, 00168 Rome, ItalyDivision of Pediatric Surgery, Fondazione Policlinico Universitario “Agostino Gemelli” IRCCS, Largo Agostino Gemelli 8, 00168 Rome, ItalyDivision of Pediatric Surgery, Fondazione Policlinico Universitario “Agostino Gemelli” IRCCS, Largo Agostino Gemelli 8, 00168 Rome, ItalyDepartment of Pathology, Università Cattolica del Sacro Cuore, Largo Vito 1, 00168 Rome, ItalyUOC di Anatomia Patologica, Fondazione Policlinico Universitario “A Gemelli” IRCCS, Largo A. Gemelli 8, 00168 Rome, ItalyDivision of Pediatric Surgery, Fondazione Policlinico Universitario “Agostino Gemelli” IRCCS, Largo Agostino Gemelli 8, 00168 Rome, ItalyEnteric duplication cysts are rare malformations mostly diagnosed before the age of two, with varied clinical presentations. Ectopic gastrointestinal epithelium can be present, and management involves surgical resection. A three-month-old girl presented with rectal bleeding due to an ileocolic intussusception. Abdominal ultrasound revealed a target sign in the right upper part of the abdomen. At hydrostatic contrast enema, an incomplete reduction of the intussusception was obtained: only a trickle of contrast material entered the terminal ileum. An exploratory laparotomy ensued with manual reduction of the intussusception. At the end of the maneuver, a soft intraluminal mass was palpated within the ileocecal valve. Thus, an ileocecal resection was performed. At histology, an intraluminal enteric duplication cyst was documented, containing ectopic gastric mucosa. Secondary intussusception should be suspected even in infants in case of abnormal findings at hydrostatic contrast enema. Intraluminal enteric duplication cysts may be a rare cause of intussusception.http://dx.doi.org/10.1155/2020/6898795 |
| spellingShingle | Filomena Valentina Paradiso Laura Merli Sara Silvaroli Vincenzo Fiorentino Riccardo Ricci Lorenzo Nanni Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception Case Reports in Pediatrics |
| title | Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception |
| title_full | Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception |
| title_fullStr | Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception |
| title_full_unstemmed | Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception |
| title_short | Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception |
| title_sort | intraluminal duplication of the terminal ileum with ectopic gastric mucosa in an infant a rare cause of intussusception |
| url | http://dx.doi.org/10.1155/2020/6898795 |
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