Persistent vs Recurrent Cushing’s Disease Diagnosed Four Weeks Postpartum

Background. Cushing’s disease (CD) recurrence in pregnancy is thought to be associated with estradiol fluctuations during gestation. CD recurrence in the immediate postpartum period in a patient with a documented dormant disease during pregnancy has never been reported. Case Report. A 30-year-old wo...

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Main Authors: Leena Shah, Emily V. Nosova, Joshua B. Bederson, Khadeen Christi Cheesman
Format: Article
Language:English
Published: Wiley 2022-01-01
Series:Case Reports in Endocrinology
Online Access:http://dx.doi.org/10.1155/2022/9236711
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author Leena Shah
Emily V. Nosova
Joshua B. Bederson
Khadeen Christi Cheesman
author_facet Leena Shah
Emily V. Nosova
Joshua B. Bederson
Khadeen Christi Cheesman
author_sort Leena Shah
collection DOAJ
description Background. Cushing’s disease (CD) recurrence in pregnancy is thought to be associated with estradiol fluctuations during gestation. CD recurrence in the immediate postpartum period in a patient with a documented dormant disease during pregnancy has never been reported. Case Report. A 30-year-old woman with CD had improvement of her symptoms after transsphenoidal resection (TSA) of her pituitary lesion. She conceived unexpectedly 3 months postsurgery and had no symptoms or biochemical evidence of recurrence during pregnancy. After delivering a healthy boy, she developed CD 4 weeks postpartum and underwent a repeat TSA. Despite repeat TSA, she continued to have elevated cortisol levels that were not well controlled with medical management. She eventually had a bilateral adrenalectomy. Discussion. CD recurrence may be higher in the peripartum period, but the link between pregnancy and CD recurrence and/or persistence is not well studied. Potential mechanisms of CD recurrence in the postpartum period are discussed below. Conclusion. We describe the first report of recurrent CD that was quiescent during pregnancy and diagnosed in the immediate postpartum period. Understanding the risk and mechanisms of CD recurrence in pregnancy allows us to counsel these otherwise healthy, reproductive-age women in the context of additional family planning.
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spelling doaj-art-92d14a2bdc094a9ab67adc07b2d80f982025-08-20T03:37:23ZengWileyCase Reports in Endocrinology2090-651X2022-01-01202210.1155/2022/9236711Persistent vs Recurrent Cushing’s Disease Diagnosed Four Weeks PostpartumLeena Shah0Emily V. Nosova1Joshua B. Bederson2Khadeen Christi Cheesman3Division of Endocrinology, Diabetes, and Bone DiseaseDivision of Endocrinology, Diabetes, and Bone DiseaseDepartment of NeurosurgeryDivision of Endocrinology, Diabetes, and Bone DiseaseBackground. Cushing’s disease (CD) recurrence in pregnancy is thought to be associated with estradiol fluctuations during gestation. CD recurrence in the immediate postpartum period in a patient with a documented dormant disease during pregnancy has never been reported. Case Report. A 30-year-old woman with CD had improvement of her symptoms after transsphenoidal resection (TSA) of her pituitary lesion. She conceived unexpectedly 3 months postsurgery and had no symptoms or biochemical evidence of recurrence during pregnancy. After delivering a healthy boy, she developed CD 4 weeks postpartum and underwent a repeat TSA. Despite repeat TSA, she continued to have elevated cortisol levels that were not well controlled with medical management. She eventually had a bilateral adrenalectomy. Discussion. CD recurrence may be higher in the peripartum period, but the link between pregnancy and CD recurrence and/or persistence is not well studied. Potential mechanisms of CD recurrence in the postpartum period are discussed below. Conclusion. We describe the first report of recurrent CD that was quiescent during pregnancy and diagnosed in the immediate postpartum period. Understanding the risk and mechanisms of CD recurrence in pregnancy allows us to counsel these otherwise healthy, reproductive-age women in the context of additional family planning.http://dx.doi.org/10.1155/2022/9236711
spellingShingle Leena Shah
Emily V. Nosova
Joshua B. Bederson
Khadeen Christi Cheesman
Persistent vs Recurrent Cushing’s Disease Diagnosed Four Weeks Postpartum
Case Reports in Endocrinology
title Persistent vs Recurrent Cushing’s Disease Diagnosed Four Weeks Postpartum
title_full Persistent vs Recurrent Cushing’s Disease Diagnosed Four Weeks Postpartum
title_fullStr Persistent vs Recurrent Cushing’s Disease Diagnosed Four Weeks Postpartum
title_full_unstemmed Persistent vs Recurrent Cushing’s Disease Diagnosed Four Weeks Postpartum
title_short Persistent vs Recurrent Cushing’s Disease Diagnosed Four Weeks Postpartum
title_sort persistent vs recurrent cushing s disease diagnosed four weeks postpartum
url http://dx.doi.org/10.1155/2022/9236711
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