Aicardi syndrome: Clinical spectrum of a rare disorder

Aicardi syndrome is a rare genetic syndrome reported exclusively in females, with reported incidence of approximately 1 in 1.1 lakh live births. The clinical condition comprises of triad of infantile spasms, and mental retardation with neuroimaging findings of complete corpus callosum, agenesis and...

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Main Authors: Sunisha Jakhar, Dinkar Yadav, Kapil Bhalla, Komal Jindal, Rohan Acharya
Format: Article
Language:English
Published: Wolters Kluwer Medknow Publications 2025-03-01
Series:Journal of Family Medicine and Primary Care
Subjects:
Online Access:https://journals.lww.com/10.4103/jfmpc.jfmpc_1065_24
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author Sunisha Jakhar
Dinkar Yadav
Kapil Bhalla
Komal Jindal
Rohan Acharya
author_facet Sunisha Jakhar
Dinkar Yadav
Kapil Bhalla
Komal Jindal
Rohan Acharya
author_sort Sunisha Jakhar
collection DOAJ
description Aicardi syndrome is a rare genetic syndrome reported exclusively in females, with reported incidence of approximately 1 in 1.1 lakh live births. The clinical condition comprises of triad of infantile spasms, and mental retardation with neuroimaging findings of complete corpus callosum, agenesis and presence of chorioretinal degeneration observed during on eye examination. Here, authors reported the case of a 2-year-old female who exhibited typical clinical features, including seizures, developmental delay, and distinctive ocular abnormalities. MRI showed corpus callosum agenesis, an interhemispheric fissure cyst, and polymicrogyria. EEG depicted high voltage, polymorphic rhythm with superimposed multifocal spikes and wave discharges. Fundus examination revealed chorioretinal degeneration. This case emphasizes the importance of early recognition, accurate diagnosis, and comprehensive management strategies to optimizing outcomes for individuals with Aicardi syndrome.
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2278-7135
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publishDate 2025-03-01
publisher Wolters Kluwer Medknow Publications
record_format Article
series Journal of Family Medicine and Primary Care
spelling doaj-art-8a635ca80916477da8b725f40c2421f02025-08-20T02:09:37ZengWolters Kluwer Medknow PublicationsJournal of Family Medicine and Primary Care2249-48632278-71352025-03-011431145114610.4103/jfmpc.jfmpc_1065_24Aicardi syndrome: Clinical spectrum of a rare disorderSunisha JakharDinkar YadavKapil BhallaKomal JindalRohan AcharyaAicardi syndrome is a rare genetic syndrome reported exclusively in females, with reported incidence of approximately 1 in 1.1 lakh live births. The clinical condition comprises of triad of infantile spasms, and mental retardation with neuroimaging findings of complete corpus callosum, agenesis and presence of chorioretinal degeneration observed during on eye examination. Here, authors reported the case of a 2-year-old female who exhibited typical clinical features, including seizures, developmental delay, and distinctive ocular abnormalities. MRI showed corpus callosum agenesis, an interhemispheric fissure cyst, and polymicrogyria. EEG depicted high voltage, polymorphic rhythm with superimposed multifocal spikes and wave discharges. Fundus examination revealed chorioretinal degeneration. This case emphasizes the importance of early recognition, accurate diagnosis, and comprehensive management strategies to optimizing outcomes for individuals with Aicardi syndrome.https://journals.lww.com/10.4103/jfmpc.jfmpc_1065_24chorioretinal degenerationcorpus callosum agenesisinfantile spasminterhemispheric fissure cyst
spellingShingle Sunisha Jakhar
Dinkar Yadav
Kapil Bhalla
Komal Jindal
Rohan Acharya
Aicardi syndrome: Clinical spectrum of a rare disorder
Journal of Family Medicine and Primary Care
chorioretinal degeneration
corpus callosum agenesis
infantile spasm
interhemispheric fissure cyst
title Aicardi syndrome: Clinical spectrum of a rare disorder
title_full Aicardi syndrome: Clinical spectrum of a rare disorder
title_fullStr Aicardi syndrome: Clinical spectrum of a rare disorder
title_full_unstemmed Aicardi syndrome: Clinical spectrum of a rare disorder
title_short Aicardi syndrome: Clinical spectrum of a rare disorder
title_sort aicardi syndrome clinical spectrum of a rare disorder
topic chorioretinal degeneration
corpus callosum agenesis
infantile spasm
interhemispheric fissure cyst
url https://journals.lww.com/10.4103/jfmpc.jfmpc_1065_24
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AT kapilbhalla aicardisyndromeclinicalspectrumofararedisorder
AT komaljindal aicardisyndromeclinicalspectrumofararedisorder
AT rohanacharya aicardisyndromeclinicalspectrumofararedisorder